Malignant Paraganglioma of Urinary Bladder 363 Case Report
363
Department of
1
Laboratory
Medicine,
2
Urology,
and
3
Endocrinology,
St. Michael’s Hospital,
University of Toronto, Toronto,
Ontario, Canada.
Address correspondence to
Dr. Kalman Kovacs, Department
of Laboratory Medicine, 2CC,
30 Bond Street, Toronto,
Ontario, M5B 1W8, Canada.
E-mail: kovacsk@smh.
toronto.on.ca
Endocrine Pathology, vol. 16,
no. 4, 363–370, Winter 2005
© Copyright 2005 by Humana
Press Inc. All rights of any
nature whatsoever reserved.
1046–3976/1559-0097 (Online)/
05/16:363–370/$30.00
Malignant Paraganglioma of the Urinary Bladder:
Immunohistochemical Study of Prognostic Indicators
Kalman Kovacs, MD, PHD,
1
C. David Bell, MD,
1
Geoffrey W. Gardiner, MD,
1
R. John Honey, MD,
2
Jeannette Goguen, MD,
3
and Fabio Rotondo, BRT
1
Abstract
Using various immunohistochemical markers, the objective of our study was to assess
whether correlation exists between growth potential of paraganglioma (pheochromo-
cytoma) cells and formation of metastasis. The patient was a 28-yr-old man who pre-
sented with intermittent episodes of gross hematuria due to a mass in the urinary bladder.
He had no constitutional symptoms to suggest paraganglioma. Histologic, immunohis-
tochemical, and electron microscopic investigation of the surgically removed tissue proved
that the tumor was a malignant paraganglioma with metastases in the regional lymph
nodes. The immunohistochemical tests were not supportive of high cell proliferation index,
indicating that metastases can develop in the absence of rapid multiplication of the tumor
cells. Abnormalities in vascular architecture and marked expression of VEGF in the tumor
cells may be regarded as prognostic signs to predict the formation of metastases.
Key Words: Extra-adrenal paraganglioma; immunohistochemistry; pathology; progno-
sis; urinary bladder neoplasms.
to the regional lymph nodes. Elevations of
urinary catecholamine levels were demon-
strated after a transurethral biopsy was car-
ried out and the surgical pathological
diagnosis was reached. Several immunohis-
tochemical tests were performed to assess
whether correlation exists between growth
potential of the tumor cells and the for-
mation of metastasis.
Report of the Case
Clinical Findings
This 28-yr-old man presented with a
2-yr history of intermittent episodes of
severe gross hematuria and difficulties of
voiding. Family history was unremarkable
and he had no previous medical problems.
He was asymptomatic except for hematuria
Introduction
Pheochromocytomas are neuroendo-
crine tumors secreting catecholamines and
causing various clinical symptoms such as
hypertension, tachycardia, hypermetabo-
lism, and, in some cases, heart failure, pul-
monary edema, and death [1,2]. They arise
most often in the adrenal medulla and less
frequently in various extra-adrenal sites
including the urinary bladder [3–8]. For
these tumors, the term paraganglioma
seems to be more appropriate. The sub-
stantial majority of pheochromocytomas
are benign tumors. Approximately 10% of
them, however, are malignant giving rise
to metastases [2,6]. We report here a case
of malignant paraganglioma (pheochro-
mocytoma) in a 28-yr-old man originat-
ing in the urinary bladder and spreading