CLINICAL AND
LABORATORY OBSERVATIONS
Critical illness neuromuscular disease in children
manifested as ventilatory dependence
Raj D. Sheth, MD, William E. M. Pryse-Phillips, MD, Jack E. Riggs, MD, and
John B. Bodensteiner, MD
From the Departments of Neurology and Pediatrics, West Virginia University Health Sciences
Center, Morgantown, and the Department of Medicine (Neurology), Memorial University of
Newfoundland, St. John's, Canada
Four children with prolonged dependency on a ventilator were found to have
reversible quadriparesis, muscle wasting, and hyporeflexia after 8 to 20 days of
assisted ventilation for life-threatening sepsis or respiratory failure. Critical
illness neuromuscular disease, which was recently recognized as a distinct clin-
ical syndrome in adults, may also be manifested in children by prolonged ven-
tilatory dependency. (J PEDIATR 1995;126:259-61)
Prolonged dependence on a ventilator occurs in 30% of
adults recovering from sepsis and multiple organ failure 1
and was initially attributed to nutritional or steroid myop-
athy, toxic effects of gentamicin or pancuronium bromide,
acute inflammatory demyelinating polyneuropathy, or pan-
creatic dysfunction. 2 Subsequently a distinctive syndrome
involving an underlying polyneuropathy or myopathy was
identified, 3 which is herein referred to as critical illness
neuromuscular disease. Similar problems have not been
well characterized in children.
METHODS
The medical records of all patients who underwent elec-
trophysiologic studies for failure to be weaned from venti-
latory support in a tertiary care pediatric intensive care unit
during a 6-year period were reviewed. Many patients had
difficulty being weaned from ventilatory support during this
period, but only four patients had electrophysiologic studies.
CASE REPORTS
Patient 1. A 15-year-old girl had septic shock as a result of group
C Neisseria meningitidis, and she had associated bilateral adrenal
hemorrhages. Two days later acute kidney failure necessitated
peritoneal dialysis for 72 hours. Medications administered included
midazolam, cefotaxime, dopamine, and methylprednisolone. In-
termittent doses of vecuronium, 0.03 mg/kg, provided neuromus-
cular blockade for 48 hours. Although the patient's mental status
Submitted for publication July 20, 1994; accepted Sept. 6, 1994.
Reprint requests: Raj D. Sheth, MD, West Virginia University
Health Science Center, Box 9180, Morgantown, WV 26506-9180.
Copyright © 1995 by Mosby-Year Book, Inc.
0022-3476/95/$3.00 + 0 9/22/60449
returned to normal, she could not undergo extubation until 6
days after vecuronium was discontinued because she had profound
hyporeflexic muscle weakness. Serum creatine kinase activity
(116 mmol/L) and results of cerebrospinal fluid analysis (protein,
0.39 gm/L; no cells) were normal. Electrophysiologic studies on
day 8 demonstrated small compound muscle action potentials
over the abductor pollicis brevis muscle. Median and peroneal
motor nerve conduction velocities were normal. Electromyogra-
phy of the deltoid muscle demonstrated a poor recruitment pattern.
Additional electromyography on day 16 demonstrated promi-
nent fibrillations in the first dorsal interosseous muscle with a
slight excess of polyphasic units of increased duration. The pa-
tient's strength returned to normal 6 weeks after the onset of ill-
ness.
Patient 2. A 15-year-old boy with septic shock as a result of group
B N. meningitidis required vigorous fluid resuscitation and venti-
latory support. He received ampicillin, chloramphenicol, midazo-
lam, dopamine, and methylprednisolone. Intermittent doses of
vecuronium, 0.04 mg/kg, provided neuromuscular blockade for 5
days. The patient's mental status was normal when vecuronium was
discontinued. An extubation attempt on day 8 was unsuccessful
because of severe quadriparesis. Diffuse muscle atrophy was
present, and muscle stretch reflexes were absent. Serum creatine
kinase activity (116 mmol/L) and results of cerebrospinal fluid
analysis (protein, 0.29 gm/L; no cells) were normal. Cranial com-
puted tomography and abdominal ultrasonography findings were
normal. Three days later a second attempt at extubation was suc-
cessful. A gradual return to normal muscle strength occurred dur-
ing the next 3 months, although hyporeflexia remained. Seventeen
months later, the patient's reflexes were normal. At that time, mo-
tor nerve conduction velocities were normal in the median and
common peroneal nerves, although compound muscle action po-
tentials were dispersed. Electromyography demonstrated motor
unit potential amplitudes to 11 mV in the tibialis anterior, vastus
lateralis, and extensor digitorum communis muscles, suggesting
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