Journal of Cutaneous Medicine and Surgery
1–5
© The Author(s) 2016
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DOI: 10.1177/1203475416639018
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Introduction
There is still widespread confusion regarding the clinical
presentation, aetiology, and diagnostic criteria of erythema
multiforme (EM), in particular EM major (EMM) and
Stevens-Johnson syndrome (SJS), in paediatric patients.
Previous literature has considered EMM and SJS inter-
changeably or as “variants” of each other.
1
In a large pro-
spective study, Auquier-Dunant et al
2
brought clarity to these
entities, separating them on the basis of the underlying aeti-
ology and clinical presentation into EMM, SJS, SJS and
toxic epidermal necrolysis (TEN) overlap, TEN, and unclas-
sified EMM or SJS. Patients with EMM were younger
(median age, 24 years), presented with fever, often had
involvement of 2 or more mucous membranes, and had typi-
cal or atypical acrally distributed target lesions affecting
<10% of the body.
2
Herpes aetiology was present in 46% of
patients with EMM, while Mycoplasma pneumoniae was
noted in only 3% of cases.
2
Our clinical experience suggested that M pneumoniae is
more commonly seen in the paediatric population presenting
with EMM, particularly a phenotype characterized by atypi-
cal target lesions with central blistering. Given implications
for management and prognostication, our objective was the
determine if this presentation is more indicative of underly-
ing M pneumoniae infection by examining a retrospective
cohort of patients labeled as having EMM or SJS.
Methods
This was a retrospective cohort study conducted at the Hospital
for Sick Children in Toronto, a tertiary academic centre. The
study received the institution’s ethics board approval. The data
were collected from the electronic charts of patients admitted
from June 1999 to July 2013. The inclusion criteria were age 3
months to 18 years and a discharge diagnosis of EM minor,
EMM, or SJS. Children with diagnoses of TEN were excluded
from our study because it was felt that the primary confusion
lies in the distinction between EMM and SJS. Data collected
included prodromal symptoms such as fever, sore throat,
cough, and respiratory distress; time from prodromal symp-
toms to skin presentation and diagnosis; medications prior to
presentation; appearance and distribution of rash; number of
mucous membranes involved; aetiological laboratory investi-
gations; treatment; and prognosis.
The case definitions used for EM minor, EMM, and SJS
were as follows: for EM minor, abrupt onset of acrally
Original Article
639018CMS XX X 10.1177/1203475416639018Journal of Cutaneous Medicine and SurgeryLangley et al
research-article 2016
1
The Hospital for Sick Children, Toronto, ON, Canada
2
St Joseph Hospital, Toronto, ON, Canada
3
University of Toronto, Toronto, ON, Canada
Corresponding Author:
Elena Pope, MD, The Hospital for Sick Children, Division of Paediatric
Medicine, 555 University Avenue, Toronto, ON M5G 1X8, Canada
Email: elena.pope@sickkids.ca
Erythema Multiforme in Children and
Mycoplasma pneumoniae Aetiology
Annie Langley
1
, Niloofar Anooshiravani
1
, Sarah Kwan
1
,
Jeanne Zeller
2,3
, and Elena Pope
1,3
Abstract
Erythema multiforme (EM) in children is understudied and confused with Stevens-Johnson syndrome (SJS) despite their being
separate diseases with unique aetiologies and clinical presentations. The goal of this study was to determine the prevalence
of Mycoplasma pneumoniae in paediatric patients with EM minor, EM major (EMM), and SJS. This retrospective cohort at The
Hospital for Sick Children accrued all cases of EM minor, EMM, and SJS from 1999 to 2013. Sixty-five cases were identified:
20 of EM minor, 23 of EMM, and 22 of SJS. Aetiologies were attributed in 58% of cases: 79% infection and 21% drug aetiology.
Sixty-one percent of patients with EMM were M pneumoniae positive, compared with 14% of those with SJS and 22% of those
with EM minor (P < .01). M pneumoniae patients were older at presentation (P = .03) and more frequently had sore throat
(P < .01) and atypical targets with central blistering (P < .01). These findings suggest that M pneumoniae should be suspected
and treated until laboratory confirmation becomes available in patients presenting with atypical target lesions with central
blistering.
Keywords
paediatric dermatology, erythema multiforme, Mycoplasma pneumoniae