Received: 28 April 2020 Revised: 5 June 2020 Accepted: 9 June 2020
DOI: 10.1111/scd.12492
REVIEW
Systemic sclerosis: Update for oral health care providers
Fatmah J. Alhendi
1
Victoria P. Werth
2
Thomas P. Sollecito
1
Eric T. Stoopler
1
1
Department of Oral Medicine, Penn
Dental Medicine, Philadelphia,
Pennsylvania
2
Department of Dermatology,
Philadelphia V.A. Hospital, Hospital of
the University of Pennsylvania and the
Veteran’s Administration Medical Center,
Philadelphia, Pennsylvania
Correspondence
Eric T. Stoopler, DMD, FDSRCS, FDSR-
CPS, University of Pennsylvania School of
Dental Medicine, University in Philadel-
phia, 240 South 40th Street, Room 206,
Philadelphia, PA 19104.
Email: ets@upenn.edu
Abstract
Systemic sclerosis (SSc), also known as scleroderma, is an autoimmune disease of
unknown origin characterized by an uncontrolled inflammatory process result-
ing in fibrosis of the skin, internal organs and vasculopathy. Manifestations of SSc
are heterogenous and can include pulmonary, cardiac, neural, renal, muscular,
cutaneous and orofacial complications. Recent scientific advances have led to a
better understanding of disease etiopathogenesis and the development of a new
classification system. Therapeutic management is often multidisciplinary and
targeted toward the affected organs. Oral health care providers (OHCPs) should
be familiar with SSc, particularly as it relates to its impact on the orofacial region
and modifications to delivery of oral health care for patients with this condition.
KEYWORDS
dental treatment, physical disability, rheumatology
1 INTRODUCTION
Systemic sclerosis (SSc), also called scleroderma, is an
immune-mediated, complex, multisystem disease charac-
terized by fibrosis of the skin, internal organs and vascu-
lopathy. In recent years, the nomenclature of this disease
has been replaced by more accurate terminology describ-
ing a heterogenous group of diseases that are defined by
clinical features, serology, and prognosis.
1
Although recent
advances have resulted in improved survival in some types
of SSc, it continues to have the highest mortality com-
pared to any other rheumatic disease.
2,3
SSc is associ-
ated with significant morbidity with variable outcomes.
4
A systematic review to assess the oral-health-related qual-
ity of life (OHRQoL) of adult patients with rheumatic dis-
eases concluded that rheumatic diseases with oral involve-
ment, such as SSc, has lower OHRQoL due to oral and
psychosocial impairments compared to other rheumatic
diseases.
5
A web-based survey by Leader et al (2014) sug-
gested approximately 50% of dentists (n = 269) felt they
might cause harm to SSc patients because of their insuf-
© 2020 Special Care Dentistry Association and Wiley Periodicals, Inc.
ficient knowledge of the disease.
6
In this review, we aim to
update oral health care providers (OHCPs) regarding SSc
and considerations for provision of safe and effective oral
health care for this patient population.
2 EPIDEMIOLOGY
Epidemiological studies of SSc are inconsistent due to
prior variable classification criteria and rarity of the
disease.
7
It is, however, estimated that approximately 1 in
10 000 people are affected by SSc worldwide with reported
prevalence between 38 and 341 total cases/million.
7,8
Inci-
dence and prevalence are highest in Europe and North
America and lowest in Asiatic areas, suggesting the role
of population and environmental factors.
8,9
SSc frequency
peaks between 45-64 years of age
10
and is approximately
8-9 times more frequent in females.
11,12
Systematic reviews
of cohort studies and meta-analysis showed a cumulative
survival rate of 75% at 5 years and 62.5% at 10 years in SSc
from the time of diagnosis
13,14
with severe heart failure or
Spec Care Dentist. 2020;1–13. wileyonlinelibrary.com/journal/scd 1