Ashdin Publishing
Journal of Neuroinfectious Diseases
Vol. 4 (2013), Article ID 235712, 2 pages
doi:10.4303/jnd/235712
ASHDIN
publishing
Case Report
Natural History of Multiple Giant Cysts in Neurocysticercosis
M. Puccioni-Sohler,
1,2
D. A. Benevenuto,
1
R. H. S. Peralta,
3
and J. M. Peralta
3
1
Escola de Medicina e Cirurgia, Universidade Federal do Estado do Rio de Janeiro, Rio de Janeiro, Brazil
2
CSF Laboratory, Clinical Pathology Service, Hospital Universit´ ario Clementino Fraga Filho/Universidade Federal do Rio de Janeiro,
Rio de Janeiro, Brazil
3
Microbiology Institute, Universidade Federal do Rio de Janeiro, Rio de Janeiro, Brazil
Address correspondence to M. Puccioni-Sohler, mpuccioni@hucff.ufrj.br
Received 4 March 2013; Accepted 16 April 2013
Copyright © 2013 M. Puccioni-Sohler et al. This is an open access article distributed under the terms of the Creative Commons Attribution License,
which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited.
Abstract Teniasis and cysticercosis represent a considerable public
health issue and have been estimated to affect more than 50 million
people worldwide per year. Neurocysticercosis is the most common
parasitic infection of the central nervous system and acquired epilepsy
is a frequent manifestation of the disease in developing countries. The
growth of cysticercus more than 50 mm in diameter is called giant
cysts, and they are considered an expansive lesion. Some of them can
induce mass effect and development of hydrocephalus and intracranial
hypertension. We report a case of neurocysticercosis, characterized by
extensive and multiple giant cysts, which coped with balanced intracra-
nial hypertension.
Keywords neurocysticercosis; epilepsy; headache; intracranial hyper-
tension; giant cysts; subarachnoid cysts
1. Introduction
Neurocysticercosis (NCC) is caused by Taenia solium infec-
tion in the central nervous system (CNS) [3, 6]. NCC rep-
resents an important cause of acquired epilepsy in devel-
oping countries. Seizures, headache, psychiatric symptoms,
intracranial hypertension, and cysticercotic meningitis are
common manifestations [7]. Giant cysts (more than 5 cm in
diameter) are not frequent in NCC, occurring in approxi-
mately 10% of cases [5].
We present a patient from a non-endemic area who had
extensive neurocysticercosis characterized by giant cysts,
with apparent compensation of intracranial hypertension.
2. Case report
A 47-year-old Brazilian black man from Rio de Janeiro,
Brazil, was admitted to our hospital in 2008. The patient
reported a strong, daily holocranial headache that were
relieved by analgesics and exacerbated by anxiety. He
had history from 1989 to 2004 of generalized tonic-clonic
seizures associated with sialorrhea and disturbance of
consciousness that were preceded by scintillating scotoma
and paresthesiae in the left upper limb. The patient had
childhood contact with pigs. The neurological examination
and funduscopy were normal. A serum Western blot for
Taenia solium and Taenia crassiceps were both positive. A
cerebrospinal fluid (CSF) analysis was performed 2 months
before admission to our hospital and revealed pleocytosis
(21 cells/mm
3
, 92% lymphocytes), hyperproteinorrachia
(66 mg/dL) and reactive hemagglutination, immunofluo-
rescence, and ELISA tests for NCC. The EEG exhibited
diffuse slow waves. Soft tissue (thigh) simple radiography
demonstrated calcifications compatible with cysticercosis.
A brain CT/MRI scan exposed multiple infratentorial,
supratentorial, and subarachnoid ring-like enhancing and
nodular lesions. Some of these were calcified, and others
appeared with scolex (Figure 1). Additionally, the patient’s
condition escalated with anxiety, depressive symptoms,
insomnia, and daily episodes of sweating that lasted a
few seconds. Chlordiazepoxide and amitriptyline were
successfully prescribed.
3. Discussion
We report a case characterized by contact with pigs dur-
ing childhood, suggestive clinical manifestations of NCC,
a positive serum Western blot for T. solium, and a reactive
ELISA test of CSF [3]. The CT and MR imaging showed
multiple large, bilateral cystic lesions, with scolex. Some of
these lesions caused midline shift, representing a tumoral
form of NCC [5]. In accordance with other reports of NCC,
seizures were the first manifestations of the disease, proba-
ble associated with intraparechymal lesions. However, mass
effect became apparent only some years later, due to the
late development and growth of intraparenchymal and extra-
parenchymal (Sylvian fissure) cysticercosis. We hypothesize
that there was a compensation of the intracranial pressure
due to the presence of the bilateral lesions and the slow
growth of the cysts, contributing to the control of the ini-
tial intracranial hypertension [4]. Otherwise, the detection of