Vol. 184, No. 3, 1992
May 15, 1992
BIOCHEMICAL AND BIOPHYSICAL RESEARCHCOMMUNICATIONS
Pages ]357-]363
FAMILIAL ADENOMATOUS POLYPOSIS: IDENTIFICATION OF A NEW
FRAMESHIFT MUTATION OF THE APC GENE IN AN ITALIAN FAMILY
Alessandro Stella^°,Angelo Lonoce ~ , Nicoletta Resta ^ ,
Mattia Gentile °, Francesco Susca^,Cristina Mareni§,
Giuseppina Brescia ^ , Paola Origoni §, Maria Pina Montero §,
and Ginevra Guanti ~*
^Institute of Genetics, University of Bari, Via Amendola 165 A,
70126 Bari Italy
°IRCCS De Bellis,Castellana Grotte Italy
§Dept of Internal Medicine, Via Benedetto XV,6 16132 Genova Italy
Received March 26, 1992
Summary: Familial Adenoma£ous Polyposis (FAP) is a premalignant
disease of the gastrointestinal tract inherited as an autosomal
dominant trait assigned to chromosome 5q21. The 15 exons of the
APC gene responsible for the defect were amplified from the DNA
of one FAP patient. SSCP analysis of the amplified DNA revealed
a variant conformer of exon i0. The sequencing of the cloned PCR
product showed a 1 base insertion at position 1370, creating a
stop codon four nucleotides downstream. SSCP analysis of 20 family
members and nucleotide sequencing of exon i0 in three affected
members confirmed the Mendelian inheritance of the mutant allele.
© 1992 Academic Press, Inc.
Familial adenomatous polyposis (FAP) is a premalignant
disease of the gastrointestinal tract inherited as an autosomal
dominant trait. The age of onset and clinical presentation of the
first symptoms of the disease are variable. Without a definitive
marker for the defect, offspring and siblings at risk cannot be
diagnosed as affected until multiple adenomas are detected in
the colorectum. These polyps, which usually exceed 500 in number
* To whom correspondence should be addressed.
Abbreviations:FAP,familial adenomatous polyposis;APC,adenomatous
polyposis coli;SSCP,single strand conformation polymorphism;TBE
buffer, 89mM Tris, 89mM boric acid, pH 8.3 and 2mM EDTA ; RFLP,
restriction fragment lenght polymorphism; GS,Gardner's
syndrome;PCR,polymerase chain reaction.
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Copyright © 1992 by Academic Press, Inc.
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