Copyright © 2015 Wolters Kluwer Health, Inc. Unauthorized reproduction of this article is prohibited.
The Pediatric Infectious Disease Journal • Volume 35, Number 1, January 2016 www.pidj.com | 13
ORIGINAL STUDIES
Background: Few data relate Mycobacterium tuberculosis (Mtb) lineage
and disease phenotype in the pediatric population or examine the contribu-
tion of travel to the tuberculosis (TB)-endemic country in North America.
We examined clinical, demographic and Mtb genotype data from patients
with TB who were treated in Toronto between 2002 and 2012.
Methods: Consecutive Mtb culture-positive, pediatric patients were
included. Clinical data were collected from a prospectively populated
clinical database. Mtb case isolate genotypes were identified using Myco-
bacterial Interspersed Repetitive Units–Variable Number Tandem Repeat
(MIRU-VNTR) and spoligotyping and were categorized into phylogeo-
graphic lineages for analysis.
Results: The 77 patients included 30.4% of all culture-positive pediatric TB
cases in Ontario from 2002 to 2012. Seventy-six (99%) patients were first or
second generation Canadians. Foreign-born patients were more likely to have
extrathoracic disease [odds ratios (OR) = 3.0; 95% confidence interval (CI):
1.04–8.71; P < 0.05] and less likely to have a genotype match in the Pub-
lic Health Ontario Laboratories database [OR = 0.32 (95% CI: 0.11–0.90);
P < 0.05] than Canadian-born patients. For those without a known TB con-
tact, Canadian-born patients were more likely to have travelled to a TB-
endemic country [OR = 13.0 (95% CI: 2.5–78.5); P < 0.001]. Extrathoracic
disease was less likely in patients infected with the East Asian Mtb lineage
[OR = 0.1 (95% CI: 0.01–0.9); P < 0.05] and more likely in those infected
with the Indo-Oceanic Mtb lineage [OR = 5.4 (95% CI: 1.5–19.2); P < 0.05].
Conclusions: Travel to TB-endemic countries likely plays an important part
in the etiology of pediatric TB infection and disease, especially in Cana-
dian-born children. Mtb lineage seems to contribute to disease phenotype in
children as it has been described in adults.
Key Words: tuberculosis, pediatric, lineage, travel
(Pediatr Infect Dis J 2016;35:13–18)
T
he clinical manifestations of pediatric tuberculosis (TB) dis-
ease are wide ranging and distinct from adult disease.
1
Host
factors that contribute to TB disease phenotype include age,
socioeconomic status, nutritional status and comorbid medical
conditions, especially HIV infection.
1
Specific polymorphisms
of genes involved in the host immune response have been
associated with disease phenotypes (reviewed by Di Pietranto-
nio and Schurr
2
).
Different strain types or lineages of Mycobacterium tuber-
culosis (Mtb) vary in virulence.
3
Advances in genetic and bioin-
formatic techniques have allowed for standardized classification of
Mtb isolates into phylogeographic lineages,
4,5
and the intrinsic biol-
ogy of these lineages may play a role in the clinical manifestations
of TB disease.
6–9
There are few data linking Mtb lineage and clinical
disease phenotype in the pediatric population.
10
History of host travel to a TB-endemic country is an impor-
tant risk factor for TB infection and disease.
11,12
However, a detailed
travel history is not systematically collected on patients with TB in
the US and Canada.
Our institution is a major pediatric TB referral centre in
Ontario, treating approximately 15–20 new cases of TB disease per
year (30%–40% of all pediatric cases in Ontario). Demographic
and other data including travel history are prospectively collected
at clinic entry for all TB patients. In addition, Public Health Ontario
Laboratories (PHOL) have maintained a database [the Ontario Uni-
versal Typing-Tuberculosis (OUT-TB) program
13
] and an archive of
all isolates from culture-positive TB cases in Ontario since 1997.
Genotype data are available since 1997 and for 92% of culture-
confirmed cases since 2007.
This study is a retrospective analysis of all culture-positive
pediatric TB cases managed at our institution over an 11-year
period, between 2002 and 2012. The objectives of this study were
to describe the clinical and patient demographic features of these
cases, to determine the Mtb lineage distribution of the case isolates
and to identify potential associations of these features with disease
phenotype. We also compared the Mtb lineage distribution of the
case isolates in our population with the adult data collected in OUT-
TB. Finally, we sought to explore the differences between foreign-
born and Canadian-born patients in their disease characteristics and
potential sources of TB acquisition.
MATERIALS AND METHODS
Study Setting
This study was undertaken at The Hospital for Sick Children
(SickKids) in Toronto, Ontario, Canada. Public health units in the
Greater Toronto Area make referrals to the SickKids TB program
for evaluation of childhood TB contacts and for management of
TB disease.
Study Design
This was a retrospective study that included consecutive
patients with a clinical diagnosis of TB and a positive culture for
Mtb between January 1, 2002 and December 31, 2012. Inclusion
criteria were a clinical diagnosis of TB, age younger than 18 years
at the time of diagnosis, at least 1 TB clinic visit at SickKids or
1 inpatient infectious disease service consultation and at least 1
Copyright © 2015 Wolters Kluwer Health, Inc. All rights reserved.
ISSN: 0891-3668/16/3501-0013
DOI: 10.1097/INF.0000000000000915
Culture-positive Pediatric Tuberculosis in Toronto, Ontario
Sources of Infection and Relationship of Birthplace and
Mycobacterial Lineage to Phenotype
Jonathan H. Rayment, MDCM, MSc,* Jennifer L. Guthrie, MSc,‡ Karen Lam, BSc,‡ Michael Whelan, MSc,‡
Brenda Lee, MHSc,‡ Frances B. Jamieson, MD, MHSc, FRCP(C),‡§ and Ian Kitai, MB, BCh, FRCP(C)†¶
Accepted for publication September 9, 2015.
From the Divisions of *Respiratory Medicine and †Infectious Diseases, The
Hospital For Sick Children; ‡Public Health Ontario Laboratories, Public
Health Ontario; and Departments of §Laboratory Medicine and Pathobiology
and ¶Pediatrics, University of Toronto, Toronto, Ontario, Canada.
J.H.R. and J.L.G. contributed equally to this work.
The authors have no funding or conflicts of interest to disclose.
Address for correspondence: Jonathan H Rayment, MDCM, MSc, The Hospital
For Sick Children, 555 University Avenue, Toronto, Ontario, Canada M5G
1X8. E-mail: jonathan.rayment@sickkids.ca.
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