Multifocal ERG Reveals Several Patterns of Cone
Degeneration in Retinitis Pigmentosa with Concentric
Narrowing of the Visual Field
Ma´rta Jana´ky,
1
Andrea Pa´lffy,
1
Andrea Dea´k,
1
Mo´nika Szila´gyi,
1
and Gyo¨rgy Benedek
2
PURPOSE. To analyze multifocal ERGs (mfERGs) in patients with
retinitis pigmentosa (RP), with constricted visual fields and
visual acuity satisfactory for steady fixation.
METHODS. The mfERGs of 86 eyes of 43 patients with various
forms of inheritance and durations of RP were analyzed. A
retinal scanning system with a 20-in. monitor was used to map
central cone function. Electrical signals of the retina were
detected by using DTL fiber electrodes.
RESULTS. The site of the best response density of the mfERGs in
the patients with RP was found in a central or eccentric
position of the trace array. Depending on the position of the
best response density in the two eyes, the patients were cate-
gorized into three groups. In the first group, the best response
density was recorded from the central hexagon in both eyes,
producing a central peak surrounded by very low responses in
the three-dimensional presentation. In the second group of
patients, the best responses were found to correspond to the
central hexagon on only one side. In the fellow eye, however,
the best response density appeared to be in an eccentric
position. The patients in the third group did not present a
central peak in the mfERG on either side. In scattered parts of
the trace arrays, several acceptable responses were observed in
all three groups that might represent patches of functioning
retinal cone receptors.
CONCLUSIONS. The results suggest highly variable central re-
sponses and groups of cones with preserved function in areas
previously considered nonresponsive. The high variability of
the central responses could be a result of variable foveal cone
density, with differences in inheritance- and duration-related
cone degeneration at the time of the examination. The authors
stress the value of step-by-step analysis of the trace array of the
mfERGs, which can reveal the still-functioning groups of
cones. (Invest Ophthalmol Vis Sci. 2007;48:383–389) DOI:
10.1167/iovs.06-0661
R
etinitis pigmentosa (RP) is a hereditary, progressive retinal
photoreceptor dystrophy in which the final consequences
of cone degeneration on the central vision are rather variable.
Some patients maintain good visual acuity throughout life al-
though their full-field electroretinograms (ERGs) are not mea-
surable, and the visual field is constricted to 5° to 10°. Others,
however, lose central vision, even at a young age, and are
therefore much more disabled.
1
These observations are in line
with the widely held notion that RP is not a homogenous
disease; instead, it can reveal differing manifestations. Several
morphologic,
2–4
psychophysical,
5–7
and electrophysiologi-
cal
8,9
studies have been performed to reveal the course and
nature of the photoreceptor loss in RP. The relationship be-
tween visual abilities and electrophysiological indicators seems
to be an important practical problem in the follow-up of pa-
tients with RP.
It is well known that the full-field ERG (i.e., the gross
electrical response of the retina) can be extinguished in the
early stage of the disease, when the central visual acuity is still
entirely preserved.
10,11
Because the traditional ERG does not
seem to be sensitive enough to indicate the condition of the
central retina, other methods have been sought. First, several
attempts were made to use focal electroretinography for esti-
mation of the residual function of the central retina in RP.
9,12
These techniques, however, require special procedures to min-
imize the effect of stray light, and in addition it is rather
time-consuming to obtain responses from more than one re-
gion.
The multifocal (mf)ERG technique, which allows a high-
resolution mapping of the macular area of the retina,
13
initially
seemed to be a more promising method for detection of the
remaining foveal cone function in some patients with RP. The
first experiences obtained with this method, however, showed
that there were no detectable mfERG responses in a substantial
proportion of patients with RP, even if they had good visual
acuity.
14 –17
Most of the later investigators introduced rather
strict inclusion criteria for participation in their mfERG studies.
Nonetheless, mfERG alterations reflecting a progressive con-
striction of the visual field and generally regarded as typical of
RP were found in only a proportion of the recordings. For
example, only 27 (71%) of the selected 38 patients produced a
recordable, “typical” mfERG in the study performed by Seeliger
et al.
14
This result raises the question of the sensitivity of the
method. It is rather difficult to regard an alteration as typical if
it is found in only a proportion of patients with RP. Difficulty
in maintaining fixation during recording is unlikely to have
been the cause of the abnormal responses, because these
patients were young and had good visual acuity. Alternatively,
the insufficient sensitivity of the method could be responsible
for its ineffectiveness in detecting residual function in this
hereditary retinal degeneration. Finally, the solution of this
problem could lie in the peculiar characteristics of the degen-
erating cone receptors. In a search for the answers to these
questions, we analyzed the mfERG recordings of all our pa-
tients with RP who had sufficient visual acuity to maintain
fixation. To cover the whole patient population, we analyzed
the responses irrespective of whether they were of good or
poor quality. Another difference relative to the earlier studies is
that we repeated the stimulation monocularly in the cases in
which the best responses were not in the central position (31st
hexagon).
From the Departments of
1
Ophthalmology and
2
Physiology, Fac-
ulty of Medicine, University of Szeged, Szeged, Hungary.
Supported by Grant OTKA/Hungary T042610.
Submitted for publication June 15, 2006; revised August 23, 2006;
accepted October 16, 2006.
Disclosure: M. Jana´ky, None; A. Pa´lffy, None; A. Dea´k, None; M.
Szila´gyi, None; G. Benedek, None
The publication costs of this article were defrayed in part by page
charge payment. This article must therefore be marked “advertise-
ment” in accordance with 18 U.S.C. §1734 solely to indicate this fact.
Corresponding author: Ma ´rta Jana ´ky, Department of Ophthalmol-
ogy, H-6720 Szeged, Kora ´nyi rkpt. 10-11, Pf: 427, Hungary;
janaky@opht.szote.u-szeged.hu.
Investigative Ophthalmology & Visual Science, January 2007, Vol. 48, No. 1
Copyright © Association for Research in Vision and Ophthalmology 383
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