Targeting PIM Kinases Impairs Survival of Hematopoietic Cells
Transformed by Kinase Inhibitor–Sensitive and Kinase
Inhibitor–Resistant Forms of Fms-Like Tyrosine
Kinase 3 and BCR/ABL
Myriam Adam,
1
Vanda Pogacic,
2
Marina Bendit,
2
Richard Chappuis,
1
Martijn C. Nawijn,
3
Justus Duyster,
4
Casey J. Fox,
5
Craig B. Thompson,
5
Jan Cools,
6
and Juerg Schwaller
1,2
1
Department of Pathology, Geneva Medical School, Geneva, Switzerland;
2
Department of Research, University Hospital Basel, Basel,
Switzerland;
3
Division of Molecular Genetics, the Netherlands Cancer Institute, Amsterdam, the Netherlands;
4
Department of Internal
Medicine III, Technical University of Munich, Munich, Germany;
5
Abramson Family Cancer Research Institute, Philadelphia; and the
6
Center for Human Genetics and Flanders Interuniversity Institute for Biotechnology, University of Leuven, Leuven, Belgium
Abstract
Previous studies have shown that activation of the signal
transducer and activator of transcription 5 (STAT5) plays an
essential role in leukemogenesis mediated through constitu-
tive activated protein tyrosine kinases (PTK). Because PIM-1
is a STAT5 target gene, we analyzed the role of the family of
PIM serine/threonine kinases (PIM-1 to PIM-3) in PTK-
mediated transformation of hematopoietic cells. Ba/F3 cells
transformed to growth factor independence by various
oncogenic PTKs (TEL/JAK2, TEL/TRKC, TEL/ABL, BCR/ABL,
FLT3-ITD, and H4/PDGFBR) show abundant expression of
PIM-1 and PIM-2. Suppression of PIM-1 activity had a
negligible effect on transformation. In contrast, expression
of kinase-dead PIM-2 mutant (PIM-2KD) led to a rapid decline
of survival in Ba/F3 cells transformed by FLT3-ITD but not by
other oncogenic PTKs tested. Coexpression of PIM-1KD and
PIM-2KD abrogated growth factor–independent growth of
Ba/F3 transformed by several PTKs, including BCR/ABL.
Targeted down-regulation of PIM-2 by RNA interference
(RNAi) selectively abrogated survival of Ba/F3 cells trans-
formed by various Fms-like tyrosine kinase 3 (FLT3)–
activating mutants [internal tandem duplication (ITD) and
kinase domain] and attenuated growth of human cell lines
containing FLT3 mutations. Interestingly, cells transformed
by FLT3 and BCR/ABL mutations that confer resistance to
small-molecule tyrosine kinase inhibitors were still sensitive
to knockdown of PIM-2, or PIM-1 and PIM-2 by RNAi. Our
observations indicate that combined inactivation of PIM-1
and PIM-2 interferes with oncogenic PTKs and suggest that
PIMs are alternative therapeutic targets in PTK-mediated
leukemia. Targeting the PIM kinase family could provide a
new avenue to overcome resistance against small-molecule
tyrosine kinase inhibitors. (Cancer Res 2006; 66(7): 3828-35)
Introduction
A high percentage of acute leukemias express functional class III
receptor protein tyrosine kinase (PTK) Fms-like tyrosine kinase 3
(FLT3). Approximately 25% of acute myeloid leukemia (AML)
patients have activating FLT3 mutations, either internal tandem
duplications (ITD) or mutations in the activation loop of the
tyrosine kinase domain (1). Overexpression and/or activating point
mutations have also been found in acute lymphoblastic leukemia
(ALL) from infants associated with rearrangement of the MLL
gene. Activating mutations of the FLT3 tyrosine kinase are the
most common somatic genetic alterations in acute leukemia, and
there is evidence that patients with FLT3-ITD may be associated
with poorer prognosis. The biological effects of activating FLT3
mutations have been tested in several in vitro and in vivo
experimental systems, indicating that activating FLT3 mutants
provide growth factor–independent proliferation and survival to
hematopoietic cells in vitro and in vivo (2).
Several new compounds with activity against FLT3 by compet-
ing with ATP binding have been recently characterized (3). These
drugs were shown to be selectively cytotoxic to cells either
transfected with FLT3-ITD or to primary AML samples carrying
FLT3-ITD. In vivo application of three different compounds (CEP-
701,PKC-412,andMLN-518)hasbeenshowntoprolongsurvivalof
mice transplanted either with FLT3-ITD–expressing marrow or
FLT3-ITD–transfected Ba/F3 cells (4). However, these compounds
show limited activity against activation loop FLT3 mutations (5, 6),
and resistance to these inhibitors can develop rapidly (7, 8). The
molecular mechanisms of hematopoietic transformation by
mutated FLT3 are not well understood. Significant differences
have been observed in downstream signaling either induced by
wild type (WT) or by constitutive active mutated FLT3. First,
restoration of the apoptosis inhibitor Bcl-XL was critical for
survival of hematopoietic cells by FLT3-ITD but not WT-FLT3.
Second, hematopoietic cells transformed by activating FLT3
mutants showed constitutive activation of the signal transducer
and activation of transcription 5 (STAT5), whereas transfectants
with WT-FLT3 showed only weak or transient activation of STAT5
when exposed to FLT3 ligand (9). Moreover, STAT5 phosphoryla-
tion and activation is inhibited by selective FLT3 PTK inhibitors.
These findings suggest that regulation of antiapoptotic proteins
like Bcl-XL in conjunction with activation of STAT5 may be critical
for the leukemogenic effects of oncogenic FLT3 mutants.
Constitutive activation of STAT5 has been shown to be a critical
mediator for transformation by several PTK fusion genes,
including BCR/ABL, FLT3 , or TEL/JAK2 associated with chronic
myeloproliferative disorders (10). Several downstream STAT5
target genes (such as SOCS1, BCL-XL , and PIMs ) were shown to
play a role in cancer. The PIM family of serine/threonine kinases
Note: J. Cools is a postdoctoral researcher of the ‘‘FWO-Vlaanderen.’’
Requests for reprints: Juerg Schwaller, Department of Research, Basel University
Hospital, ZLF, Lab 318, Hebelstrasse 20, CH-4031 Basel, Switzerland. Phone: 41-61-265-
3504; Fax: 41-22-37-24920; E-mail: J.Schwaller@unibas.ch.
I2006 American Association for Cancer Research.
doi:10.1158/0008-5472.CAN-05-2309
Cancer Res 2006; 66: (7). April 1, 2006 3828 www.aacrjournals.org
Research Article
Research.
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