Open Journal of Pediatrics, 2014, 4, 76-78
Published Online March 2014 in SciRes. http://www.scirp.org/journal/ojped
http://dx.doi.org/10.4236/ojped.2014.41010
How to cite this paper: Jihene, B., et al. (2014) Diagnosis of Fucosidosis through Cutaneous Manifestations. Open Journal of
Pediatrics, 4, 76-78. http://dx.doi.org/10.4236/ojped.2014.41010
Diagnosis of Fucosidosis through Cutaneous
Manifestations
Bouguila Jihene
1*
, Mabrouk Sameh
1
, Ben Turkia Hadhemi
2
, Mokni Mourad
3
,
Boughammoura Lamia
1
1
Department of Pediatrics, Hospital Farhat Hached, Sousse, Tunisia
2
Department of Pediatrics, Hospital La Rabta, Tunis, Tunisia
3
Department of Dermatology, Hospital La Rabta, Tunis, Tunisia
Email: jbouguila@yahoo.fr
Received 1 September 2013; revised 2 October 2013; accepted 18 October 2013
Copyright © 2014 by authors and Scientific Research Publishing Inc.
This work is licensed under the Creative Commons Attribution International License (CC BY).
http://creativecommons.org/licenses/by/4.0/
Abstract
Angiokeratoma corporis diffusum is a dermatological hallmark of several inherited lysosomal
storage disorders including Anderson-Fabry disease and other enzyme deficiencies such as fuco-
sidosis. We report a 4-year-old boy with neurodevelopment delay who was diagnosed as having
fucosidosis following recognition of dermatological signs, angiokeratoma and telangiectasies. The
diagnosis was confirmed by leukocyte oligosaccharide enzyme analysis.
Keywords
Angiokeratoma; Telangiectasies; Child; Fucosidosis
1. Background
Fucosidosis is a rare autosomal recessive lysosomial storage disease resulting from α-L-fucosidase deficiency
[1]. Multiple angiokeratoma is the main dermatological feature of Fucosidosis [2]. We report a new case of fu-
cosidosis with variable dermatological signs: angiokeratomas, telangiectasies and nail bands.
2. Case Report
A boy aged 4 years, born of a consanguineous couple, hospitalized for several times with recurrent chest infec-
tions since 18 months. He has a family history of mental retardation in the brother in whom an oligosaccharido-
sis was suspected but not confirmed as he died at 5 years.
*
Corresponding author.