Arch Pediatr Infect Dis. 2014 January; 2(1):e16471. DOI: 10.5812/pedinfect.16471
Published online 2014 January 18. Case Report
Diagnostic Dilemma in a Patient With Chronic Fistulating Nonhealing Ulcer
Sedigheh Rafiei Tabatabaei
1
, Abdollah Karimi
1
, Ali Amanati
1,*
, Maryam Kazemi Aghdam
2
,
Bibi Shahin Shamsian
3
, Javad Ghoroubi
4
1
Pediatric Infections Research Center, Mofid Children's Hospital, Shahid Beheshti University of Medical Sciences, Tehran, IR Iran
2
Pediatric Pathology Research Center, Shahid Beheshti University of Medical Sciences, Tehran, IR Iran
3
Pediatric Congenital Hematologic Disorders Research Center, Shahid Beheshti University of Medical Sciences, Tehran, IR Iran
4
Pediatric Surgery Research Center, Shahid Beheshti University of Medical Sciences, Tehran, IR Iran
*Corresponding author: Ali Amanati, Pediatric Infections Research Center, Department of Pediatric Infectious Diseases, Mofid Children's Hospital, Dr. Shariati Ave., P.O.BOX:
1546815514, Tehran, IR Iran. Tel/Fax: +98-2122226941, E-mail: ali_amanati_1356@yahoo.com.
Received: November 29, 2013; Revised: December 24, 2013; Accepted: January 8, 2014
Here, we report on a ten-year-old girl with chronic draining nonhealing ulcer in her neck and unilateral cervical chronic lymphadenopathy.
Her ulcer had poor clinical response to broad spectrum antibiotics and anti-tuberculosis treatment. She had undergone several wound
biopsies with no conclusive results. She was otherwise healthy with no known underlying disease. Final wound excisional biopsy with
specific immunohistochemistry (IHC) staining confirmed her diagnosis. Histopathology report and IHC were compatible, indicating an
anaplastic large cell lymphoma.
Keywords: Wounds and Injuries; Neck; Lymphatic Diseases; Lymphoma, Large-Cell, Anaplastic
Implication for health policy/practice/research/medical education:
We hoped to emphasize to all clinicians that close follow up of chronic disease is an important part of accurate management. Attention to any possible
underlying cause, which could contribute to poor clinical response, should always be kept in mind. As in our case repeated biopsy may be needed to at-
tain diagnosis.
Copyright © 2014, Pediartric Infections Research Center; Published by Kowsar Corp. This is an open-access article distributed under the terms of the Creative Com-
mons Attribution License, which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited.
1. Introduction
A chronic nonhealing wound is described as a wound
failing to heal within three months and it is extremely
complex to manage and diagnose contributing factors
of poor healing (1, 2). Complications of these wounds
are risk of severe pain, septicemia, hospitalization, and
in some cases severe morbidity. Exact identification of
pathogenic organisms in chronic wounds is difficult
and varies depending on the modes of sampling and the
diagnostic methods (culturing or molecular methods).
The most common bacteriological dilemma in chronic
wounds is differentiation between nonpathogenic colo-
nization and other pathogenic organisms. The most
common bacterial isolates on wounds are Staphylococcus
aureus, coagulase-negative staphylococci, Enterococcus
faecalis, Proteus species, anaerobic bacteria, and Pseudo-
monas aeruginosa, yet other significant pathogens such
as tuberculosis, atypical mycobcteria, nocardiosis, actinomy-
cosis and fungal infection should always be considered.
On the other hand, when chronic nonhealing wounds
are difficult to treat with antibiotics, consideration of
biofilm formation, which necessitates overcoming in-
creased minimal inhibitory concentrations (MICs) of bio-
film growing organisms such as Pseudomonas aeruginosa,
is warranted (3, 4). Another significant issue in managing
these wounds is investigation of the underlying predis-
posing factors contributing to failure in wound healing
such as ischemia, venous insufficiency, diabetes, neurop-
athy, malnutrition, corticosteroids therapy, vasculitis,
immune suppression and malignancy (2, 5).
2. Case Report
A ten-year-old girl was admitted to our center with a
chronic fistulating nonhealing wound. In the initial
physical examination she had a large (about 5 × 7 centi-
meters) draining deep ulcer in the anterior cervical trian-
gle below her right mandible and surrounded swelling.
As her mother notified, she had a unilateral neck swell-
ing since three months ago. She had been hospitalized 2
times before admission to our ward. The neck sonogra-
phy performed in the primary center revealed unilateral
multiple lymph nodes on the right side. She was put on
anti-tuberculosis treatment after discovery of acid-fast
bacilli (AFB) in the lymph nodes fine needle aspiration in
her first admission to that center. She stopped her medi-
cations after about 3 weeks and was admitted to another
center for excisional lymph nodes biopsy because of
poor clinical improvement after the primary treatment.
In first pathology report only necrosis with inflamma-
tion without evidence of tuberculosis were noted. She
was also examined for bone marrow aspiration which
revealed no evidence of malignancy and tuberculosis. Fi-
nally, because of no remarkable change in her neck swell-
ing and draining wound despite previous treatment, she