TRENDS in Immunology Vol.22 No.12 December 2001
http://immunology.trends.com 1471-4906/01/$ – see front matter © 2001 Elsevier Science Ltd. All rights reserved. PII: S1471-4906(01)02052-X
653 Research Update
Meeting Report
In conjunction w ith the 11th International
Congress of Immunology in Stockholm,
Sweden, the satellite meeting on B cells and
Autoimmunity: New Concepts and
Therapeutic Perspectives was held in
Bergen, Norway from 19–21 July 2001.
The origin of autoimmune diseases
remains enigmatic. For several years,
attention was centered largely on the study
of T cells. Over the past few years, however,
there has been a revival of interest in the
role of B cells in autoimmune diseases,
with evidence from different studies
showing that the pathogenesis of
autoimmune diseases cannot be accounted
for solely by the action of T cells
1–4
. The
major goal of the organizers was to view
and discuss recent advancements in our
knowledge of B-cell biology that will aid in
the understanding of autoimmunity. As the
meeting progressed among the fjords of
Norway, several major themes crystallized.
Receptor editing and autoimmunity
As one of the mechanisms involved in
maintaining B-cell tolerance to self,
receptor editing exploits the capacity of Ig
variable-region (V) genes to undergo
successive rearrangements, allowing
B cells to avoid high-affinity
autorecognition
5
. Hence, receptor editing
has implications with regard to the
maintenance of B-cell tolerance and,
possibly, the induction of pathogenic
autoimmunity. M. Nussenzweig (New
York, NY, USA) has developed two mouse
models, in which mice express one mouse
κ locus and the human constant region Cκ
locus, allowing direct examination of
receptor editing by flow cytometry. The
mouse B cells are targeted for editing
during a two-hour delay in development at
the pre-B-cell stage. As many as 25–33% of
mature B cells exhibited evidence of
receptor editing, implying that editing
plays a major role in shaping the
peripheral antibody repertoire.
M. Weigert (Princeton, NJ, USA)
discussed the role of various molecular
mechanisms of receptor editing and/or
revision in preventing the development of
autoimmunity. In some circumstances,
re-expression of a second light chain,
without editing of the first light chain
V region (V
L
), might prevent the action of
the ‘master editor’ (the light-chain gene
product that prevents autoimmunity) and
permit the re-emergence of specificities
that bind to autoantigen. Weigert
described the existence of B cells that
express dual receptors in the marginal
zone of lymph nodes, and suggested that
restriction of these cells to this location
might prevent them from developing into
fully autoreactive B cells. It will be
important to elucidate how these
multireactive B cells might contribute to
autoimmunity. In his studies of receptor
editing in the MRL mouse model of lupus,
M. Monestier (Philadelphia, PA, USA)
found an increased frequency of diversity
region (D–D) fusions and evidence of
secondary heavy-chain (H) diversity and
joining region (D–J
H
) rearrangements in
newborn autoimmune mice. This was not
found in pre-B cells, suggesting that
secondary V
H
gene rearrangements in the
periphery of MRL mice might contribute
to the emergence of autoimmunity. In
humans, P. Lipsky (Bethesda, MD, USA)
described the V
H
and V
L
repertoire in
normal individuals compared with those
suffering from autoimmunity. Evidence of
marked B-cell hyperactivity was found in
patients with lupus, including increased
somatic mutation and receptor editing,
and abnormal selection in the periphery.
B-cell memory and homing
Interest in the role of B-cell memory and
the germinal-center reaction in
autoimmunity is growing. C. Berek
(Berlin, Germany) described the
characteristics of the inflammatory foci
that form at affected sites in rheumatoid
arthritis (RA) patients. These foci
comprise immunocompetent cells
[follicular dendritic cells (FDCs) and
B cells (Ki67
+
CD79
+
CD20
+
CD38
+
)] that
form fully functional germinal centers.
Proliferating B cells from synovial fluid
exhibit evidence of somatic hypermutation
in their V-region genes. In the peripheral
blood of many RA patients, she found that
an increased frequency of B cells with a
memory phenotype (CD19
+
CD27
+
) that are
hypermutated. A population (up to 48%) of
CD19
+
CD27
high
plasma cells was present
also in the patients, a reflection of chronic
activation. In Sjögren Syndrome, the data
of J. Bohnhorst (Oslo, Norway) showed
decreased numbers of CD27
+
memory
B cells in SS patients and increased levels
of soluble CD27 in the serum. Studying
salivary glands from primary SS patients,
S. Bowman (Birmingham, UK) found that
the expression of chemokines and
chemokine receptors reflects the
distribution of inflammatory cells in this
tissue
6
. Stromal-cell-derived factor 1
(SDF-1) was expressed highly in ductal
epithelial cells, and its ligand,
CXC-chemokine receptor 4 (CXCR4), was
expressed on periductal inflammatory
cells. B-lymphocyte chemoattractant was
expressed in a diffuse fashion, and its
ligand, CXCR5, was expressed by a portion
of B cells in structures resembling
germinal centers.
Animal models and genetic susceptibility
In autoimmune research, geneticists are
expending great efforts to identify the
genes that might confer susceptibility. In
humans, J.B. Harley (Oklahoma City, OK,
USA) discussed linkage studies of human
lupus in at least five centers in Europe and
North America. The data are consistent
with the ‘established’ linkages found at
chromosomes 1q41, 2q37, 4p16, 6p21 and
16q13. In the mouse, A. Theofilopoulos
(La Jolla, CA, USA) reported genome-wide
mapping efforts to define loci for the lupus-
prone mouse strains New Zealand Black
(NZB), NZ white (NZW),
lymphoproliferative MRL–Fas–lpr and
BXSB. With this framework in place,
identification of the specific genetic
alterations and mechanisms is now
proceeding through the generation of
interval congenic lines, and precise
mapping and screening of candidate genes.
In an experimental model of arthritis, R.
Holmdahl (Lund, Sweden) identified the
major genetic regions involved using F2
crosses of different mouse strains. Two loci
associated with arthritis were identified:
one on chromosome 2, at the location of the
B-lymphocyte selection and autoimmunity
Roland Jonsson, Karl Albert Brokstad, Peter E. Lipsky and Moncef Zouali