Research Article
Gremlin, a Bone Morphogenetic Protein Antagonist, Is a Crucial
Angiogenic Factor in Pituitary Adenoma
Kenta Koketsu, Daizo Yoshida, Kyongsong Kim, Yudo Ishii, Shigeyuki Tahara,
Akira Teramoto, and Akio Morita
Department of Neurosurgery, Nippon Medical School, Tokyo 113-8602, Japan
Correspondence should be addressed to Kenta Koketsu; kenta7240031@nms.ac.jp
Received 27 September 2014; Revised 10 February 2015; Accepted 16 February 2015
Academic Editor: Amelie Bonnefond
Copyright © 2015 Kenta Koketsu et al. his is an open access article distributed under the Creative Commons Attribution License,
which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited.
Gremlin is an antagonist of bone morphogenetic protein (BMP) and a major driving force in skeletal modeling in the fetal stage.
Several recent reports have shown that Gremlin is also involved in angiogenesis of lung cancer and diabetic retinopathy. he
purpose of this study was to investigate the role of Gremlin in tumor angiogenesis in pituitary adenoma. Double luorescence
immunohistochemistry of Gremlin and CD34 was performed in pituitary adenoma tissues obtained during transsphenoidal surgery
in 45 cases (7 PRLoma, 17 GHoma, 2 ACTHoma, and 2 TSHoma). Gremlin and microvascular density (MVD) were detected by
double-immunoluorescence microscopy in CD34-positive vessels from tissue microarray analysis of 60 cases of pituitary adenomas
(6 PRLoma, 23 GHoma, 22 NFoma, 5 ACTHoma, and 4 TSHoma). In tissue microarray analysis, MVD was signiicantly correlated
with an increased Gremlin level (linear regression: < 0.005,
2
= 0.4958). In contrast, Gremlin expression showed no correlation
with tumor subtype or Knosp score. he high level of expression of Gremlin in pituitary adenoma tissue with many CD34-positive
vessels and the strong coherence of these regions indicate that Gremlin is associated with angiogenesis in pituitary adenoma cells.
1. Introduction
Angiogenesis is a complex multistep process that has a crucial
role in tumor growth, invasion, and metastasis. Improved
understanding of angiogenesis will provide insights into
tumor stage and the response of tumor vessels to antian-
giogenic therapy and may lead to more personalized cancer
therapy [1, 2]. Current attempts to disrupt tumor blood vessel
formation are predominantly focused on targeting the VEGF-
VEGFR signaling pathway [2]. Pituitary tumors are highly
vascular neoplasms, which suggests an important role of
angiogenesis in pituitary tumor growth, but the mechanisms
that underlie tumorigenesis in pituitary adenomas are uncer-
tain [3, 4]. In particular, the mechanism that controls tumor
angiogenesis and whether this process is required for tumor
growth have been the subject of much discussion.
Microvascular density (MVD) has been studied in a
number of neoplasia and generally there is a close relationship
between angiogenesis and tumor progression. hus, MVD
may be a predictive factor for disease progression and
response to treatment. Zhang et al. found that cervical cancer
progression is correlated with MVD and VEGF [5], and
Zhao et al. showed that VEGF and MVD are decreased by
siRNA silencing of c-Src, a predictor of a poor prognosis in
pancreas cancer [6]. Norcantharidin, an angiogenic inhibitor
in gallbladder cancer, has been shown to inhibit cancer
cell proliferation, migration, and invasion and to reduce
angiogenesis based on decreased MVD and VEGF expression
[7].
VEGF is likely to have a role in tumor angiogenesis
in pituitary adenomas that is similar to that in other neo-
plasms, and VEGF also regulates the growth of pituitary
tumor cells through its receptors VEGFR-1, VEGFR-8, and
VEGFR-9. Onofri et al. [8, 9] showed that ligands of VEGF
receptors inluence angiogenesis in pituitary adenomas and
afect growth of pituitary tumor cells through VEGFR-1,
and that VEGF and VEGFR-3 immunostaining in pituitary
tumors was higher than in normal pituitary tissue. hese
results indicate that the VEGF-C/VEGFR-3 system might
be involved in controlling tumor angiogenesis in pituitary
Hindawi Publishing Corporation
International Journal of Endocrinology
Volume 2015, Article ID 834137, 7 pages
http://dx.doi.org/10.1155/2015/834137