Patient Report
Herpes simplex primo-infection in an immunocompetent host with
eosinophilic esophagitis
Orjena Žaja Franulovic ´,
1
Tatjana Lesar,
1
Nikolina Busic
3
and Goran Tešovic ´
2
1
Department of Pediatric Gastroenterology and Hepatology, University Hospital Centre ‘Sestre milosrdnice’,
2
School of
Medicine, University Hospital for Infectious Diseases, University of Zagreb, Zagreb, and
3
Department of Infectious Diseases,
General Hospital Varaždin, Varaždin, Croatia
Abstract Eosinophilic esophagitis and herpes simplex esophagitis are separately well-described entities, but their simultaneous
occurrence may pose a special challenge to the clinician, especially regarding the optimal therapeutic approach. The
following case report describes a patient with a history of cow’s milk and dairy products intolerance, but without an
underlying immunologic defect, in whom eosinophilic esophagitis was diagnosed in the course of primary herpes
simplex virus 1 (HSV1) infection that clinically presented as herpes labialis and severe esophagitis. The diagnosis was
confirmed by a polymerase chain reaction from cytological brush and by immunohistochemical staining that detected
the presence of HSV1 DNA in esophageal mucosa, and histologically by persistent eosinophil-predominant inflam-
mation, typical of eosinophilic esophagitis. Despite severe clinical presentation, the HSV1 infection was self-limited.
After a directed elimination diet was introduced, the clinical course was favorable, without the need for antiviral
therapy.
Key words eosinophilic, esophagitis, food allergy, hematemesis, herpes simplex.
Eosinophilic esophagitis (EoE) is thought to be a result of an
allergic response to food antigens or aeroallergens, possibly trig-
gered by environmental factors, including microorganisms.
1–3
Herpes simplex esophagitis (HSE) is a rare clinical manifestation
of herpes simplex virus 1 (HSV1) primary infection or reactiva-
tion, typically occurring in immunocompromised patients, par-
ticularly those with cellular immunodeficiencies; however, it is
being increasingly recognized in immunocompetent hosts, espe-
cially if there is an underlying esophageal lesion present.
4
Although both of the entities are separately well described, if
they occur simultaneously, clinicians have to deal with a variety
of challenges that often arise in the management of these patients,
from answering the question, “What happened first?”, to resolv-
ing the dilemma about the need for antiviral therapy in an immu-
nocompetent host.
In this article we report our experience in treating a patient
with a history of cow’s milk and dairy products intolerance,
without underlying immunologic defect, in whom EoE was
revealed during the HSV1 primary infection which clinically
presented as herpes labialis and severe esophagitis.
Case Report
A 17-year-old girl presented to our emergency department with
an acute onset of epigastric pain, heartburn and hematemesis. Her
personal history revealed cow’s milk allergy, which manifested
as vomiting and abdominal discomfort, but without allergy
testing confirmation. She had no history of gastroesophageal
reflux, non-steroidal anti-inflammatory drug intake, tobacco or
alcohol use, unusual ingestion, self-induced vomiting or having
been sexually active. No “cold sores” or episodes of gingivosto-
matitis had been previously registered either.
On admission, her vital signs were as follows: temperature
37.8°C, blood pressure 110/65 mmHg, pulse rate 80 b.p.m., res-
piratory rate 19 breaths per minute, and oxygen saturation 97%
on room air. She appeared pale and dehydrated, with febrile
blister on her upper lip, complaining of severe retrosternal and
epigastric pain. Her oropharynx had no lesions or exudate
and there was no skin rash or other lesions. Lungs, cardiac
and abdominal examination revealed normal physical findings
except epigastric discomfort on palpation.
C-reactive protein was slightly elevated (22.9 mg/L), while
the erythrocyte sedimentation rate, complete blood count and
results of other biochemical tests were all within normal values.
Esophagogastroduodenoscopy (EGD; Olympus GIF-Q180 8,8
videoendoscope; Olympus, Tokyo, Japan) was performed the
morning after admission. At the proximal part of the esophagus,
patchy white plaques were seen tending to merge toward the
distal part. Distal to the middle part, longitudinal deep ulcerations
Correspondence: Orjena Žaja Franulovic ´, MD PhD, Department of
Pediatric Gastroenterology and Hepatology, University Hospital
Centre ‘Sestre milosrdnice’, Vinogradska 29, Zagreb, Croatia. Email:
orjenazf@yahoo.com
Received 18 January 2012; revised 6 September 2012; accepted 26
October 2012.
Pediatrics International (2013) 55, e38–e41 doi: 10.1111/ped.12027
© 2013 The Authors
Pediatrics International © 2013 Japan Pediatric Society