e54
Journal of Thoracic Oncology • Volume 8, Number 6, June 2013
T
he presence of bilateral pulmonary nodules in lung cancer
usually means distant metastases (M1a).
1
We present an
extraordinary example that challenged us to look beyond this
classification, illustrating the potential benefits of a multidis-
ciplinary re-evaluation in such a case.
CASE REPORT
A 70-year-old male, former smoker, and current mara-
thon runner was diagnosed in September 2005 with a prob-
able squamous cell carcinoma of the right upper lobe (RUL)
with (possible) small satellite lesions, a nodule in the right
middle lobe (RML), and a nodular structure in the left upper
lobe (LUL) on computed tomography (CT) scan, and 18-fluo-
rodeoxyglucose positron emission tomography (FDG-PET)
scan. This was considered to be a primary lung cancer with
intrapulmonary metastases (stage IV, histology confirmed).
The patient received six cycles of chemotherapy doublet (cis-
platinum 150 mg on day 1 and gemcitabine 2000 mg on days
1 and 8), which resulted in a slight reduction in size of the
lesion in the RUL, and a clear reduction of the lesion in the
LUL, although the RML remained unchanged (Fig. 1). Eleven
months later, the lesion in the RUL increased in size. A second
opinion was arranged.
After reviewing all data and images with repeated PET
and CT, the possibility of multiple primary tumors was con-
sidered. A video-assisted thoracoscopy, diagnostic wedge
excision of the LUL, and a transthoracic biopsy of the RUL
were performed, revealing two papillary adenocarcinomas. A
wedge excision of the RML, a lobectomy of the RUL, and
mediastinal lymph-node dissection showed a 1.8-cm diam-
eter papillary adenocarcinoma of the LUL, a 3.3-cm diameter
mixed papillary adenocarcinoma/adenocarcinoma in situ of
the RUL, and a 1.1-cm diameter adenocarcinoma in situ of the
RML, all radically resected. All nodes were negative. Array-
comparative genomic hybridization analysis revealed that all
these lesions showed different patterns of gains and losses,
consistent with three primary tumors (Fig. 2).
2
In December 2007, a recurrence in the operation
scar of the LUL, and a new abnormality in the left lower
lobe (LLL) were observed on CT scan, both 18-FDG-PET
positive. Diagnostic wedge excisions of the LUL and LLL
and a mediastinal lymph-node dissection were performed.
Pathological examination showed two invasive papillary
adenocarcinomas (LUL and LLL of 1.5 cm and 0.6 cm
diameter, respectively), with free resection margins, with-
out lymph-node metastases. The postoperative course was
Copyright © 2013 by the International Association for the Study of Lung
Cancer
ISSN: 1556-0864/13/0806-0e54
Beneit of a Second Opinion
Intrapulmonary Metastases or Multiple Primary Tumors?
Marleen J. ter Avest, BSc,* Romane M. Schook, MD,* Pieter E. Postmus, MD, PhD,*
Katrien Grünberg, MD, PhD,† Bauke Ylstra, PhD,‡ and Marinus A. Paul, MD, PhD§
Departments of *Pulmonary Diseases, and †Pathology, VU University
Medical Center, Amsterdam, The Netherlands; ‡Micro Array Facility, VU
University Medical Center-Cancer Center, Amsterdam, The Netherlands;
and §Department of Thoracic Surgery, VU University Medical Center,
Amsterdam, The Netherlands.
Disclosure: The authors declare no conflict of interest.
Address for correspondence: Romane M. Schook, MD, Department of
Pulmonary Diseases, VU University Medical Center, De Boelelaan 1117,
1007 MB Amsterdam, The Netherlands. E-mail: r.schook@vumc.nl
FIGURE 1. Computed tomography scan at time of irst
presentation and after six cycles of chemotherapy. A, Shows
a reduction of the lesion in the right upper lobe. B, Shows an
unchanged right middle lobe lesion. C, Shows a clear reduc-
tion of the left upper lobe lesion.
CASE REPORT