Images From Headache
Migraine-Like Headache With Autonomic Symptoms in
Midbrain Malformation
Jay G. Capone, MD; Valentina Simioni, MD; Maria R. Tola, MD
We report a case of midbrain malformation characterized by right deviation of the medulla oblongata associated with
elongation and ectasia of the basilar and left vertebral arteries in a patient with a long history of migraine-like headache with
autonomic symptoms.
Key words: midbrain malformation, migraine, autonomic
Abbreviations: MRI magnetic resonance imaging, NSAIDs non-steroidal anti-inflammatory drugs, TACs trigeminal autonomic
cephalalgias
(Headache 2013;••:••-••)
A 69-year-old female presented with exacerba-
tion of a longstanding headache disorder. Since ado-
lescence, the patient had experienced recurrent, left
side-locked headache characterized by throbbing,
oppressive, retro-orbital, and temporal pain associ-
ated with photophobia, phonophobia, nausea, and,
rarely, vomiting. During attacks of great intensity, the
clinical picture was enriched by ipsilateral lacrima-
tion, conjunctival injection, nasal congestion, and rhi-
norrhea. Pain typically began gradually, reaching
maximal intensity within several hours, lasting from 6
to 24 hours; autonomic signs typically lasted for a few
hours. During headache, the patient preferred to
remain still, lying down in a dark and quiet room. The
mean frequency of headache attacks was 1-2/month,
becoming less frequent after menopause until the age
of 67 years, when the frequency gradually increased
again.
When the patient was observed at the age of 69,
she complained of a chronic daily headache associ-
ated with overuse of non-steroidal anti-inflammatory
drugs (NSAIDs). She denied any symptoms of aura,
premonitory features, autonomic symptoms, or pain
within the attacks. The patient suffered from blood
artery hypertension, following appropriate antihyper-
tensive therapy. Physical examinations, including neu-
rologic examination and detailed laboratory exams,
were entirely normal. A brain magnetic resonance
imaging (MRI) with gadolinium revealed a malfor-
mation of the midbrain characterized by right devia-
tion of the medulla oblongata associated with
elongation, sinuosity, and ectasia of the basilar and
the left vertebral arteries (Figure).
The patient was treated with β-blockers and ami-
triptyline with gradual reduction of intensity and fre-
quency of pain attacks and resolution of NSAIDs
overuse.
COMMENTS
The patient presented with a more than 50-year
history of recurrent attacks of strictly unilateral pain.
The attacks had some features of migraine without
aura but were associated with ipsilateral autonomic
signs. Duration and frequency of the attacks were
From the Department of Neuroscience and Rehabilitation,
University Hospital of Ferrara, Neurology Division, Ferrara,
Italy.
ISSN 0017-8748
doi: 10.1111/head.12243
Published by Wiley Periodicals, Inc.
Headache
© 2013 American Headache Society
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