ARTHRITIS & RHEUMATISM
Vol. 50, No. 3, March 2004, pp 882–891
DOI 10.1002/art.20093
© 2004, American College of Rheumatology
Sjo ¨gren’s Syndrome Associated With
Systemic Lupus Erythematosus
Clinical and Laboratory Profiles and Comparison With
Primary Sjo ¨gren’s Syndrome
Menelaos N. Manoussakis,
1
Chryssoula Georgopoulou,
1
Elias Zintzaras,
2
Marilyn Spyropoulou,
3
Aikaterini Stavropoulou,
3
Fotini N. Skopouli,
4
and Haralampos M. Moutsopoulos
1
Objective. To address the clinical, serologic,
pathologic, and immunogenetic features of sicca syn-
drome that occurs in systemic lupus erythematosus
(SLE), as well as its similarities to, and differences
from, sicca syndrome that occurs in primary Sjo ¨gren’s
syndrome (SS).
Methods. A cohort of 283 consecutive unselected
SLE patients was evaluated for the presence of associ-
ated SS using the American–European classification
criteria. Clinical and laboratory parameters in SLE
patients with SS (SLE–SS) were compared with those in
SLE patients without SS (SLE–no SS) and with a group
of 86 unselected patients with primary SS.
Results. SS was identified in 26 SLE patients
(9.2%); the SS preceded the development of lupus in 18
of them (69.2%). Compared with the SLE–no SS group,
patients with SLE–SS were significantly older, had a
higher frequency of Raynaud’s phenomenon, anti-Ro/
SSA, anti-La/SSB, and rheumatoid factor, but had a
significantly lower frequency of renal involvement,
lymphadenopathy, and thrombocytopenia. Compared
with the primary SS group, SLE–SS patients displayed
a clinically similar sicca syndrome, but were signifi-
cantly younger and had an increased frequency of
perivascular infiltrates in the salivary glands associated
with anticardiolipin antibodies in the serum. SLE–SS
patients had a high frequency of the DRB1*0301 allele.
This HLA profile distinguished the SLE–SS group from
the SLE–no SS group, who had an increased frequency
of DRB1*1501 and DQB1*0602 alleles, but was similar
to the HLA profile of the primary SS group, who had an
increased frequency of DRB1*0301.
Conclusion. SLE–SS appears to constitute a sub-
group of patients with distinct clinical, serologic, patho-
logic, and immunogenetic features, in whom SS is
expressed as an overlapping entity and is largely similar
to primary SS.
Sjo ¨gren’s syndrome (SS) is a chronic autoimmune
disorder of the exocrine glands with associated lympho-
cytic infiltration of the affected glands. Dryness of the
mouth and/or the eyes, resulting from involvement of
the salivary and lacrimal glands, is most often present
(1). The exocrinopathy may be encountered alone or in
the presence of another autoimmune disorder.
Features of SS may be found in almost every
autoimmune rheumatic disease, including rheumatoid
arthritis (RA), systemic lupus erythematosus (SLE),
scleroderma, and others (1). With regard to the patho-
genesis, it is unclear whether this form of SS associated
with another autoimmune rheumatic disease represents
a distinct overlapping entity or a manifestation in the
clinical spectrum of the accompanying rheumatic disor-
der (2). In fact, comparisons of the clinical, serologic,
and immunogenetic features of patients with SS who
have no evidence of another autoimmune disease and
1
Menelaos N. Manoussakis, MD, Chryssoula Georgopoulou,
MD, Haralampos M. Moutsopoulos, MD, FACP, FRCP (Edin):
School of Medicine, National University of Athens, Athens, Greece;
2
Elias Zintzaras, MSc, PhD: School of Medicine, Biomathematics
Unit, University of Thessaly, Larissa, Greece;
3
Marilyn Spyropoulou,
MD, Aikaterini Stavropoulou, MD: National Tissue Typing Center,
George Gennimatas General Hospital, Athens, Greece;
4
Fotini N.
Skopouli, MD: Harokopio University, Athens, Greece.
Address correspondence and reprint requests to Menelaos N.
Manoussakis, MD, Department of Pathophysiology, Medical School,
University of Athens, 75 Mikras Asias Street, Athens 115 27, Greece.
E-mail: menman@med.uoa.gr.
Submitted for publication October 8, 2002; accepted in re-
vised form December 3, 2003.
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