Introduction
Sarcoidosisisacomplexsystemicinflammatory
disorder of unknown etiology characterized patho-
logicallybynoncaseatinggranulomasthatcanman-
ifest in virtually any organ system (1). Extra-pul-
monarysarcoidosisrepresentsasignificantchallenge
bothinitsdiagnosisandmanagement.Itmayalsobe
amajorcauseofmorbidityandmortality,aswell(2).
Racial and gender differences are reported in pa-
tientswithextra-pulmonarysarcoidosisandtheclin-
icalcourseisunpredictable(2-4).
The exact immunopathogenesis of sarcoidosis
still remains an enigma despite there has been
tremendous evolution in the past decade. The hy-
pothesis is that; some antigen(s) enter the host and
are phagocytosed by antigen presenting cells
Could HLA-DR B1*11 allele be a clue for predicting extra-
pulmonary sarcoidosis?
Ezgi Ozyilmaz
1
, Ozlem Goruroglu Ozturk
2
, Dilek Yunsel
1
, Ali Deniz
3
, Ismail Hanta
1
, Sedat Kuleci
1
,
Gulsah Seydaoglu
4
, Eren Erken
5
, Ali Kocabas
1
1
Cukurova University Faculty of Medicine, Department of Pulmonary Disease, 01330, Adana,Turkey;
2
Cukurova University Faculty of
Medicine,DepartmentofMedicalBiochemistry,01330,Adana,Turkey;
3
CukurovaUniversityFacultyofMedicine,DepartmentofCardi-
ology, 01330, Adana,Turkey;
4
Cukurova University Faculty of Medicine, Department of Biostatistics, 01330, Adana,Turkey;
5
Cukurova
UniversityFacultyofMedicine,DepartmentofRheumatologyandImmunology,01330,Adana,Turkey
Abstract. Background: Several HLA-DR alleles have been described as a potential risk factor for sarcoidosis be-
tween distinct ethnic groups however the relationship between HLA-DR alleles and extra-pulmonary sarcoidosis
(EPS)isstillscarce. Objectives: Theaimofthisprospectivestudyistoinvestigatetherelationshipbetweenextra-pul-
monaryinvolvementandHLA-DRgeneticanalysisinTurkishpatientswithsarcoidosis. Methods: Inthisstudy,we
HLA-typedsarcoidosispatientswithandwithoutextra-pulmonaryinvolvement,andcomparedwithhealthycontrol
subjects.ThepresenceofEPSwasevaluatedwithpreviouslydefinedstandardcriteria(ACCESS)andonlypatients
withdefiniteandprobableinvolvementwereacceptedaspositive.SequenceSpecificOligonucletideProbesmethod
was used for typing of HLA-DRB1 alleles from DNA samples in both groups. Results: The frequency of HLA
DRB1*15 allele was more frequent in patients with sarcoidosis than controls (% 20.4 vs % 9.6)(pcorr=0.017). Ac-
cordingtomultivariateanalysis(MVA),thepresenceofHLADRB1*15wasindicatedasanindependentriskfactor
for sarcoidosis (OR:2.37; 95% CI: 1.31-4.30, p=0.004). Extra-pulmonary involvement was present in 39 patients
(42.9%).Whenthepatientswithandwithoutextra-pulmonaryinvolvementcompared,HLADRB1*11allelewas
significantlyhigherinpatientswithoutextra-pulmonarysarcoidosiswhichmaybeconcludedasaprotectiveallelefor
systemic involvement (%30.8 vs. %15.4)(p<0.05).This result was also confirmed with the MVA (OR:0.35, %95
CI:0.15-0.84,p=0.018). Conclusions: WedemonstratedastrongpositivelinkbetweenthehaplotypeHLADRB1*15
andsarcoidosisinaTurkishCaucasianpopulationandapotentialprotectiveeffectofHLADRB1*11fromextra-
pulmonaryinvolvementofdisease. (Sarcoidosis Vasc Diffuse Lung Dis 2014; 31: 154-162)
Key words: Sarcoidosis,HLA-DRalleles,extra-pulmonaryinvolvement
Received:18October2013
Correspondence:Dr.EzgiOzyilmaz
CukurovaUniversityFacultyofMedicine
DepartmentofPulmonaryDisease,Balcali,Adana,Turkey
Phone:00905053841435
E-mail:ezgiozyilmaz@hotmail.com
Original article: Clinical Research
SARCOIDOSISVASCULITISANDDIFFUSELUNGDISEASES2014;31;154-162 ©Mattioli1885