Brief Report
haematologica | 2010; 95(7) 1221
A large series of plasma cell dyscrasias (n=2207) was exam-
ined for translocations which deregulate the MAF genes,
t(14;20)(q32;q12) and t(14;16)(q32;q23), and their disease
behavior was compared to a group characterized by the
t(4;14)(p16;q32) where CCND2 is also up-regulated. The
t(14;20) showed low prevalence in myeloma (27/1830, 1.5%)
and smoldering myeloma (1/148, <1%) with a higher inci-
dence in MGUS (9/193, 5% P=0.005). Strong associations
with del(13) (76%), non-hyperdiploidy (83%) and gain of 1q
(58%) were seen but no association with an IgA M-protein
or absence of bone disease was noted. All three transloca-
tions were associated with poor outcome in myeloma, but
strikingly all t(14;20) MGUS/smoldering myeloma cases
(n=10) had stable, low level disease. In contrast, the 10
t(14;16) and 25 t(4;14) MGUS/smoldering myeloma cases
were associated with both evolving and non-evolving dis-
ease. None of the associated genetic abnormalities helped to
predict for progression from MGUS or smoldering myeloma.
(Clinicaltrials.gov identifier: ISRCTN 68454111; UKCRN ID
1176)
Key words: plasma cell, myeloma, MGUS, chromosome
abnormality, disease progression.
Citation: Ross FM, Chiecchio L, Dagrada G, Protheroe RKM,
Stockley DM, Harrison CJ, Cross NCP, Szubert AJ, Drayson
MT, Morgan GJ on behalf of the UK Myeloma Forum.The
t(14;20) is a poor prognostic factor in myeloma but is associated
with long-term stable disease in monoclonal gammopathies of
undetermined significance. Haematologica 2010;95:1221-1225.
doi:10.3324/haematol.2009.016329
©2010 Ferrata Storti Foundation. This is an open-access paper.
Introduction
Approximately half of myeloma (MM) cases are character-
ized by translocations into the immunoglobulin heavy chain
locus (IgH). Each translocation subgroup is associated with
deregulation of a D group cyclin either directly, such as occurs
with the t(11;14) (cyclin D1) and t(6;14) (cyclin D3) or indi-
rectly, such as occurs with the t(4;14) or in the MAF translo-
cation group.
1
The MAF translocation group includes the
t(14;16) and t(14;20), both of which are rare in myeloma, but
are thought to be associated with poor prognosis.
2
The
mechanism of this poor outcome is thought to involve the
consequences of MAF upregulation, which include upregula-
tion of cyclin D2, effects on cell interaction and upregulation
of apoptosis resistance.
3
As upregulation of cyclin D2 is also
seen in the t(4;14) group where poor prognosis is well estab-
lished,
4-8
it may be deregulation of this D group cyclin which
is important in this respect. MM cases with t(4;14) show an
excess of IgA M-protein type
9
and have been reported to be
less likely to present with bone disease (1) but it is not clear
whether this also applies to the other cyclin D2 dysregulating
translocations, t(14;16) and t(14;20) cases.
MGUS is a benign premylomatous condition lacking the
clinical sequelae of myeloma, but with a rate of transforma-
tion to myeloma of approximately 1% per year.
10
This rela-
tionship has led to the generation of disease models of
myeloma based on the multistep progression of normal to
MGUS through to myelomatous plasma cells.
11
In these mod-
els, initial genetic hits result in an immortalized plasma cell
clone and additional changes lead to its transformation to
clinical myeloma. With the recent recognition that essential-
ly all myeloma cases have a pre-existing asymptomatic
phase,
12-13
it becomes even more important to recognize
which abnormalities affect the rate of progression.
The t(4;14) has been reported to be rare in MGUS and
smoldering/asymptomatic MM (SMM), leading to the sug-
gestion that it is associated with an aggressive disease process
effectively bypassing this stage.
9,14
However, there are reports
The t(14;20) is a poor prognostic factor in myeloma but is associated
with long-term stable disease in monoclonal gammopathies
of undetermined significance
Fiona M. Ross,
1
Laura Chiecchio,
1
GianPaolo Dagrada,
1
Rebecca K.M. Protheroe,
1
David M. Stockley,
1
Christine J. Harrison,
2
Nicholas C.P. Cross,
1
Alex J. Szubert,
3
Mark T. Drayson,
4
Gareth J. Morgan
5
on behalf of the UK Myeloma Forum
1
LRF UKMF Cytogenetic Database, University of Southampton, Wessex Regional Genetics Laboratory, Salisbury, Wilts;
2
Northern
Institute of Cancer Research, Newcastle University, Newcastle;
3
Clinical Trials Research Unit, University of Leeds, Leeds, and
4
Division of Immunity and Infection, University of Birmingham, and
5
the Institute of Cancer Research, Royal Marsden Hospital,
Sutton, Surrey, UK
ABSTRACT
Acknowledgments: we thank Leukaemia Research for funding this work, Catherine Stacey-Richardson and the referring clinicians and their research nurs-
es who have provided clinical details, and Faith Davies, Sue Bell and Walter Gregory for various aspects of the Myeloma IX trial.
Funding: this work was funded by Leukaemia Research.
Manuscript received on August 27, 2009. Revised version arrived on December 18, 2009. Manuscript accepted on January 7, 2010.
Correspondence: Fiona Ross, Wessex Regional Genetics Laboratory, Salisbury District Hospital, Salisbury, Wilts, SP2 8BJ, UK.
E-mail: fiona.ross@salisbury.nhs.uk