A novel mutation in the albumin gene (c.1A>C) resulting in analbuminemia Gianluca Caridi * , Monica Dagnino * , Francesca Lugani * , Stavit A. Shalev , Monica Campagnoli , Monica Galliano , Ronen Spiegel and Lorenzo Minchiotti * Laboratory on Pathophysiology of Uremia, Istituto Giannina Gaslini IRCCS, Genoa, Italy, Department of Pediatrics A’ and Genetic Institute, Ha’Emek Medical Center, Afula, Rappaport Faculty of Medicine, Technion, Haifa, Israel, Department of Molecular Medicine, University of Pavia, Pavia, Italy ABSTRACT Background Analbuminemia (OMIM # 103600) is a rare autosomal recessive disorder manifested by the absence or severe reduction of circulating serum albumin in homozygous or compound heterozygous subjects. The trait is caused by a variety of mutations within the albumin gene. Design We report here the clinical and molecular characterisation of two new cases of congenital analbumin- emia diagnosed in two members of the Druze population living in a Galilean village (Northern Israel) on the basis of their low level of circulating albumin. The albumin gene was screened by single-strand conformation poly- morphism and heteroduplex analysis, and the mutated region was submitted to DNA sequencing. Results Both the analbuminemic subjects resulted homozygous for a previously unreported c.1 A>C transver- sion, for which we suggest the name Afula from the hospital where the two cases were investigated. This muta- tion causes the loss of the primary start codon ATG for Met1, which is replaced by a – then untranslated – triplet CTG for Leu. (p.Met1Leu). The use of an alternative downstream ATG codon would probably give rise to a com- pletely aberrant polypeptide chain, leading to a misrouted intracellular transport and a premature degradation. Conclusions The discovery of this new ALB mutation, probably inherited from a common ancestor, sheds light on the molecular mechanism underlying the analbuminemic trait and may serve in the development of a rapid genetic test for the identification of a-symptomatic heterozygous carriers in the Druze population in the Galilee. Keywords Analbuminemia, DNA sequence, Druze community, human serum albumin, missense mutation, start codon. Eur J Clin Invest 2013; 43 (1): 72–78 Introduction Human serum albumin (ALB; UniProt ID: P02768) is encoded on chromosome 4q13.3 by an autosomal gene (ALB; GenBank accession no. NC_000004.11 74269972..74287129) composed of 15 exons, the last of which is untranslated [1]. The messenger RNA (GenBank coding reference sequence NM_000477.5) in liver cells encodes a precursor protein (preproalbumin) of 609 amino acid residues. Cleavage of the 18 residue signal peptide and of the 6 residue propeptide yields the mature ALB, which consists of a single unglycosylated chain of 585 amino acids. The protein is then secreted in the bloodstream, where it accounts for about 60% (reference range 35–45 g L) of total serum proteins. [2]. Its main functions are to act as a transport and depot protein for a wide variety of endogenous and exogenous ligands, including fatty acids, hormones, steroids, bilirubin and heme, and to maintain the oncotic pressure and volume of blood [2]. ALB also binds heavy metal ions and many drugs, which is why a decrease in its serum level can have important pharmacokinetic consequences. In addition, the protein plays a role as a circulating antioxidant and is reported to possess some enzymatic properties. Analbuminemia (OMIM # 103600) is an autosomal recessive disorder manifested by the absence or severe reduction of cir- culating ALB. The condition should be suspected when more common causes of low ALB levels, such as renal or intestinal loss (glomerular nephritis, nephrotic syndrome and protein- losing gastroenteropathy), redistribution into extravascular compartments (septicaemia and other inflammatory states), and insufficient production rate (severe hepatic cirrhosis) can 72 European Journal of Clinical Investigation Vol 43 DOI: 10.1111/eci.12019 ORIGINAL ARTICLE