The prevalence and predictors of anencephaly and spina bifida
in Texas
Mark A. Canfield
a
, Lisa Marengo
a
, Tunu A. Ramadhani
a
, Lucina Suarez
a
, Jean D. Brender
b
and Angela Scheuerle
c
a
Birth Defects Epidemiology and Surveillance Branch, Texas Department of State Health Services, Austin,
b
Department of Epidemiology and
Biostatistics, Texas A&M Health Science Center, School of Rural Public Health, College Station, and
c
Tesserae Genetics, Dallas, TX, USA
Summary
Correspondence:
Mark A. Canfield, PhD, Birth
Defects Epidemiology and
Surveillance Branch, Texas
Department of State Health
Services, 1100 W. 49th Street,
Austin 78756, TX, USA.
E-mail:
mark.canfield@dshs.state.tx.us
Canfield MA, Marengo L, Ramadhani TA, Suarez L, Brender JD, Scheuerle A. The
prevalence and predictors of anencephaly and spina bifida in Texas. Paediatric and
Perinatal Epidemiology 2009; 23: 41–50.
Texas shares a 1255-miles border with Mexico and encompasses a variety of ecosys-
tems, industries and other potential environmental exposures. The Texas Birth Defects
Registry is an active surveillance system which covers all pregnancy outcomes (live-
births, fetal deaths and elective pregnancy terminations). This study describes the
occurrence and the predictors of neural tube defects (anencephaly and spina bifida) in
Texas between 1999 and 2003. Birth prevalence, crude and adjusted prevalence ratios
and 95% confidence intervals were calculated using Poisson regression, for each defect,
by fetal/infant sex, delivery year and maternal sociodemographic characteristics.
Among approximately 1.8 million livebirths, a total of 1157 neural tube defects cases
were ascertained by the Registry, resulting in an overall prevalence of 6.33 cases per
10000 livebirths. The prevalences of anencephaly and spina bifida were 2.81 and 3.52
per 10000 livebirths respectively. Prevalences of both defects were highest in Hispan-
ics, among mothers living along the border with Mexico, among women of higher
parity and among mothers who were 40+ years of age. In addition, the prevalence of
each defect was higher among women with no record of prenatal care and among
women with less than 7 years of education. Hispanic ethnicity was an important
predictor for anencephaly, along with sex, maternal age, parity and border residence.
However, only border residence and delivery year were significant predictors for spina
bifida.
Keywords: neural tube defects, anencephaly, spina bifida, ethnic background, maternal age,
parity, geographic area, maternal education.
Introduction
Neural tube defects (NTD) are major congenital mal-
formations resulting from the maldevelopment of the
brain (anencephaly) and the spine (spina bifida). Pre-
vious studies have shown that the occurrence of anen-
cephaly and spina bifida is multifactorial, influenced
by a number of maternal and sociodemographic
factors. In studies that have included sizeable Hispanic
or Mexican-origin populations in the US, the preva-
lence of anencephaly, spina bifida or NTD combined
has consistently been higher in Hispanics, relative to
non-Hispanics or non-Hispanic whites.
1–12
Other
factors that have been associated with one or both
NTDs in these populations include residence on the
border with Mexico,
13,14
Mexican maternal birth-
place,
1,4,5,8,10,12
infant sex,
1,3,6,7,15
pregnancy history,
1,3,7
maternal age,
1,3,7,15
parity,
3,4
timing of prenatal care ini-
tiation
7,16
and socio-economic status.
6–8,17
In 1991, a large cluster of anencephalic deliveries
occurred in Brownsville, a Texas city bordering
Mexico.
18
As a result of this significant event and other
cluster concerns across the state, the Texas Birth
Defects Registry was established in 1993.
19
Targeted
surveillance efforts during the 1990s revealed that
41 doi: 10.1111/j.1365-3016.2008.00975.x
Paediatric and Perinatal Epidemiology, 23, 41–50. © 2008 The Authors, Journal Compilation © 2008 Blackwell Publishing Ltd.