Genetic Variation in XPD, Sun Exposure, and Risk
of Skin Cancer
Jiali Han,
1,5
Graham A. Colditz,
1,2,4
Jun S. Liu,
3,6
and David J. Hunter
1,2,5
1
Channing Laboratory, Department of Medicine, Brigham and Women’s Hospital and Harvard Medical School;
2
Department of
Epidemiology,
3
Department of Biostatistics,
4
Harvard Center for Cancer Prevention, and
5
Program in Molecular and
Genetic Epidemiology, Harvard School of Public Health, Boston, Massachusetts and
6
Department of Statistics,
Harvard University, Cambridge, Massachusetts
Abstract
The XPD gene is involved in the nucleotide excision
repair pathway removing DNA photoproducts induced
by UV radiation. Genetic variation in XPD may exert a
subtle effect on DNA repair capacity. We assessed the
associations between two common nonsynonymous poly-
morphisms (Asp
312
Asn and Lys
751
Gln) with skin cancer
risk in a nested case-control study within the Nurses’
Health Study (219 melanoma, 286 squamous cell carci-
noma, 300 basal cell carcinoma, and 874 controls) along
with exploratory analysis on the haplotype structure of
the XPD gene. There were inverse associations between
the Lys
751
Gln and Asp
312
Asn polymorphisms and the risks
of melanoma and squamous cell carcinoma. No association
was observed between these two polymorphisms and
basal cell carcinoma risk. We also observed that the
association of the
751
Gln allele with melanoma risk was
modified by lifetime severe sunburns, cumulative sun
exposure with a bathing suit, and constitutional suscepti-
bility score (P for interaction = 0.03, 0.04, and 0.02
respectively). Similar interactions were also observed for
the Asp
312
Asn. Our data suggest these two XPD non-
synonymous polymorphisms may be associated with skin
cancer risk, especially for melanoma. (Cancer Epidemiol
Biomarkers Prev 2005;14(6):1539 – 44)
Introduction
Skin cancer is the most common neoplasm in Caucasians in
the United States. The genotoxic effect of sunlight exposure
has been clearly shown in the etiology of both melanoma and
nonmelanocytic skin cancer (1-3). One important defense
mechanism against skin cancer is the ability to repair DNA
damage induced by UV light. It has been suggested that
reduced DNA repair capacity (DRC) is a susceptibility factor
predisposing individuals to skin cancer (4-7). The predomi-
nant form of UV-induced DNA damage is DNA photo-
products caused by the direct absorption of UVB by DNA.
Cyclobutane pyrimidine dimers and pyrimidine (6-4) pyrimi-
done photoproducts constitute the two major DNA photo-
products (2). DNA photoproducts are mainly removed by
the nucleotide excision repair (NER). The NER is a versatile
repair system to remove a variety of bulky, helix-distorting
lesions, including UV photoproducts and bulky adducts (8, 9).
Individuals with xeroderma pigmentosum, deficient in the
NER, have a >1,000-fold increased risk of skin cancer.
Human XPD maps to chromosome 19q13.3 and spans f54
kb. It comprises 23 exons and is 761 amino acids in length. The
XPD gene encodes an ATP-dependent DNA helicase involved
in the NER and in basal transcription as part of the
transcription factor TFIIH. Disruption of the mouse Xpd gene
results in preimplantation lethality (10). Mutations in the XPD
gene lead to NER defects (11) and three clinical syndromes,
Cockayne syndrome, xeroderma pigmentosum, and tricho-
thiodystrophy, depending on the location of the mutation (9,
12). In addition, the XPD and p53 proteins can interact with
each other to modulate apoptosis and the NER. The p53 binds
and modulates the helicase activity of the TFIIH, and the repair
of UV-induced dimers was attenuated in Li-Fraumeni syn-
drome cells (heterozygote p53 mutant; ref. 13). A deficiency in
p53-mediated apoptosis was reported in XPD lymphoblastoid
cell lines and fibroblasts from xeroderma pigmentosum
patients with germ line mutations in the XPD gene (14, 15).
We evaluated two common nonsynonymous XPD poly-
morphisms (Asp
312
Asn and Lys
751
Gln) in relation to skin
cancer risk in a nested case-control study within the Nurses’
Health Study along with exploratory analysis on the haplotype
structure of the XPD gene. We further investigated the
hypothesis that XPD genetic variants modify the associations
of sunlight-related risk factors with skin cancer risk.
Materials and Methods
Study Population. The Nurses’ Health Study was estab-
lished in 1976, when 121,700 female registered nurses between
ages 30 and 55 years completed a self-administered question-
naire on their medical histories and baseline health-related
exposures. Updated information has been obtained by ques-
tionnaires every 2 years. Between 1989 and 1990, blood
samples were collected from 32,826 of the cohort members.
Eligible cases in this study consisted of women with incident
skin cancer from the subcohort who gave a blood specimen,
including squamous cell carcinoma (SCC) and basal cell
carcinoma (BCC) cases with a diagnosis anytime after blood
collection up to June 1, 1998 and melanoma cases (including
in situ cases) up to June 1, 2000 with no previously diagnosed
skin cancer. All available pathologically confirmed melanoma
and SCC cases and 300 self-reported BCC cases randomly
selected from f2,600 available self-reported BCC cases were
included. The validity of self-report of BCC is high in this
medically sophisticated population (90%; ref. 16). All the SCC
and BCC cases had no history of melanoma diagnosis. A
common control series (case/control, 1:1) was randomly
selected from participants who gave a blood sample and were
free of diagnosed skin cancer up to and including the
Cancer Epidemiology, Biomarkers & Prevention 1539
Cancer Epidemiol Biomarkers Prev 2005;14(6). June 2005
Received 11/16/04; revised 3/22/05; accepted 4/7/05.
Grant support: NIH grants CA97746 and CA87969 and Harvard Specialized Programs of
Research Excellence in Skin Cancer.
The costs of publication of this article were defrayed in part by the payment of page charges.
This article must therefore be hereby marked advertisement in accordance with 18 U.S.C.
Section 1734 solely to indicate this fact.
Requests for reprints: Jiali Han, Channing Laboratory, Harvard Medical School, 181
Longwood Avenue, Boston, MA 02115. Phone: 617-525-2098; Fax: 617-525-2008.
E-mail: jiali.han@channing.harvard.edu
Copyright D 2005 American Association for Cancer Research.
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