LETTERS
Break-induced replication and telomerase-
independent telomere maintenance require Pol32
John R. Lydeard
1
, Suvi Jain
1
, Miyuki Yamaguchi
1
& James E. Haber
1
Break-induced replication (BIR) is an efficient homologous
recombination process to initiate DNA replication when only
one end of a chromosome double-strand break shares homology
with a template
1–5
. BIR is thought to re-establish replication at
stalled and broken replication forks and to act at eroding telo-
meres in cells that lack telomerase in pathways known as ‘alterna-
tive lengthening of telomeres’ (reviewed in refs 2, 6). Here we show
that, in haploid budding yeast, Rad51-dependent BIR induced by
HO endonuclease requires the lagging strand DNA Pola-primase
complex as well as Pold to initiate new DNA synthesis. Pole is not
required for the initial primer extension step of BIR but is required
to complete 30 kb of new DNA synthesis. Initiation of BIR also
requires the nonessential DNA Pold subunit Pol32 primarily
through its interaction with another Pold subunit, Pol31. HO-
induced gene conversion, in which both ends of a double-strand
break engage in homologous recombination, does not require
Pol32. Pol32 is also required for the recovery of both Rad51-
dependent and Rad51-independent survivors in yeast strains
lacking telomerase. These results strongly suggest that both types
of telomere maintenance pathways occur by recombination-
dependent DNA replication. Thus Pol32, dispensable for replica-
tion and for gene conversion, is uniquely required for BIR; this
finding provides an opening into understanding how DNA rep-
lication re-start mechanisms operate in eukaryotes. We also note
that Pol32 homologues have been identified both in fission yeast
and in metazoans where telomerase-independent survivors with
alternative telomere maintenance have also been identified
2,6,7
.
When a double-strand break (DSB) occurs in the middle of a
chromosome, it can be efficiently repaired by gene conversion, using
homologous sequences on a sister chromatid, a homologous chro-
mosome, or at an ectopic location
1,8,9
. However, if only one end of a
DSB shares homology with other sequences in the genome, cells rely
on recombination-dependent DNA replication (known as break-
induced replication, BIR) to restore genome integrity
2–5
(see also
Supplementary Fig. 1). Such events are believed to occur at stalled
replication forks, where endonuclease cleavage produces one par-
tially replicated chromatid and an intact chromatid
10,11
. BIR can re-
establish a unidirectional replication fork, which can proceed to the
end of the template chromatid or until it meets a converging replica-
tion fork.
BIR also could explain how rare survivors arise in Saccharomyces
cerevisiae cells lacking telomerase, in which chromosome ends become
eroded and recombinogenic
12
. Virtually all telomerase-deficient sur-
vivors require the key homologous recombination protein Rad52, but
there are two distinct survivor pathways that differ in their genetic and
substrate requirements
13,14
. Type I Rad51-dependent survivors result
from recombination between subtelomeric repeat sequences, whereas
Type II Rad51-independent—but Rad50- and Rad59-dependent—
survivors exhibit recombination between imperfect nucleotide
TG
1-3
sequences of the telomeres themselves. It is believed that these
events must involve DNA replication—possibly rolling circle replica-
tion of an excised circular template
2
—but there has not yet been any
direct demonstration of the involvement of leading- and lagging-
strand DNA polymerases in these repair events.
We developed a haploid system to study BIR in budding yeast,
where a galactose-inducible HO endonuclease creates a DSB adjacent
to the 59 part of the CAN1 gene (designated CA) in a nonessential
terminal region of chromosome V-left (Chr. V-L). The DSB shares
homology, only on the centromere-proximal side, with a 39 segment
of the CAN1 gene (called AN1) that is inserted on another chro-
mosome (Fig. 1a). Successful recombination results in a non-
reciprocal translocation, restoring an intact CAN1 gene that renders
the cells canavanine sensitive, but leads to the loss of the hygromycin-
resistance HPH-MX marker distal to the DSB. Interchromosomal
Rad51- and Rad52-dependent recombination yields BIR products,
the frequency of which increases from 21% to 31% as the length of
shared homology on Chr. XI increases from 1,157 to 2,977 base pairs
(bp) (Fig. 1b and Supplementary Table 1). BIR was more efficient in
1
MS029 Rosenstiel Centre, Brandeis University, Waltham, Massachusetts 02454-9110, USA.
a
A A
A
A
A
A
HO
Probe
Probe
Probe
AN1 LEU2
LEU2
LEU2
P2
P2
P2
P1
CAN1
Chr. XI
A A
CA HPH
P1
Probe
Chr. V
Chr. XI
Chr. V
AN1
0 1 3 6 8 10 12 24
Time (h)
Southern blot
PCR
Product (percentage
of maximum repair)
70
60
50
40
30
20
10
80
0
b 01368 S
Chr. XI
BIR
Cut
Chr. V
101224
Time
(h)
Figure 1 | Experimental system to study BIR and kinetics of DSB repair.
a, An HPH-MX marked HO endonuclease cut site (grey bars) integrated into
Chr. V-L deletes the 39 end of CAN1. The LEU2-marked AN1 donor sharing
1,157 bp of homology with CAN is integrated into Chr. XI. b, PCR with
primers P1 and P2 monitors initiation of new DNA synthesis. Southern blot
analysis of AvaI-digested DNA (marked by A) monitors completion of BIR.
Lane S contains DNA from a colony in which BIR occurred. Kinetics of
repair is shown for PCR and Southern blot assays of BIR induced in cycling
cells. Error bars represent s.d.
Vol 448 | 16 August 2007 | doi:10.1038/nature06047
820
Nature ©2007 Publishing Group