doi: 10.1111/j.1744-313X.2008.00817.x
© 2008 The Authors
Journal compilation © 2008 Blackwell Publishing Ltd, International Journal of Immunogenetics 36, 33–37 33
Blackwell Publishing Ltd
Analysis of ERCC2/XPD functional polymorphisms in systemic
lupus erythematosus
L. Wan,*† Y. J. Lin,*‡ J. J. Sheu,*† C. M. Huang,§ Y. Tsai,† C. H. Tsai,† W. Wong¶ & F. J. Tsai*†
Summary
Sunlight/ultraviolet (UV) irradiation has been recognized
as an important risk factor for developing systemic lupus
erythematosus (SLE). However, the interpretation of
genetic variations involved in UV-light sensitivity is largely
unknown. Recent studies indicated that two genetic
variations of ERCC2/XPD gene (rs1799793 in exon 10
and rs13181 in exon 23) have been found to exert
negative influences on nucleotide excision repair system.
To analyse the possible contribution of the ERCC2/XPD
functional single nucleotide polymorphisms in genetic
susceptibility to SLE, the rs13181 and rs1799793 SNPs in
ERCC2/XPD were genotyped by polymerase chain
reaction followed by restriction fragment length polymor-
phism analysis. Association was studied by case–control
analyses using samples from 172 SLE patients and 160
healthy controls. Haplotype analysis was performed to
detect the association with genetic predisposition to SLE
and the clinical features. Although these two functional
genetic variations are linked to several immune dysfunction-
induced diseases, no statistically significant differences in
allele or genotype frequencies were observed between SLE
patients and controls. Haplotype analysis showed that
none of ERCC2/XPD haplotypes was associated with the
incidence of SLE disease, nor the preference of clinical
features. In conclusion, the ERCC2/XPD functional
polymorphisms analysed in this study showed no associ-
ation in genetic susceptibility to SLE.
Introduction
Systemic lupus erythematosus (SLE) is a multisystem
inflammatory autoimmune disease with the prevalence
ranging from 36 to 375 cases per 100 000 population
worldwide (Molokhia & McKeigue, 2000). Clinical stud-
ies indicated that both genetic and environmental factors
contribute to the pathogenesis of SLE. For example, DNA
damaging agents, such as genotoxic chemicals and (UV)
ultraviolet (sunlight) irradiation, are potent inducers to
incur erythematous eruption. Recently, defective DNA
repair activity for DNA damage and the consequent
abnormal apoptosis have been implicated as causative
factors for SLE (Herrick et al., 1995; McCurdy et al., 1997;
Wong & Tsao, 2006). Elevated levels of circulating nucle-
osomal DNA from the dead cells are strong immunogens
to induce autoantibodies, which exacerbate lupus condi-
tions in patients (Bruns et al., 2000; Koutouzov et al., 2004;
Holdenrieder et al., 2006). Previous studies also indicated
that SLE patients with hypersensitivity to UV irradiation
as well as the disease animal models were found related
to limited cellular DNA repair capacity (Golan & Borel,
1984; Zamansky et al., 1985; Foltyn & Golan, 2001).
These studies suggested that DNA repair deficiencies may
result in accumulation of pathogenic immune complexes
during SLE development.
DNA repair systems in mammalian cells are evolution-
ally sophisticated machinery that can maintain DNA
integrity when cells are under exposure of genotoxic com-
pounds or oxidative attacks. At least four main repair
pathways were defined operating in mammals, including
base-excision repair (BER), nucleotide excision repair
(NER), recombinational repair and mismatch repair (Lin-
dahl & Wood, 1999; Hoeijmakers, 2001). Of all repair
systems, NER is the most versatile for lesion recognition
and DNA repair. Two subpathways, global genome NER
(GG-NER) and transcription-coupled NER (TC-NER),
are involved in NER system (de Laat et al., 1999; Tornal-
etti & Hanawalt, 1999; Batty & Wood, 2000). Hundreds
of polymorphisms in DNA repair genes have been identi-
fied; however, for many of these polymorphisms, the
impact on SLE susceptibility remains uncertain. ERCC2
gene (also known as XPD) was first found to be able to
correct the sensitivity to UV radiation and defective
nucleotide excision repair in a UV light sensitive cell line
(Flejter et al., 1992). This gene is also a key DNA helicase
L. Wan, Y.J. Lin and J.J. Sheu contributed equally to this work.
* Human Genetic Center, China Medical University Hospital, Taichung,
Taiwan, † Graduate Institute of Chinese Medical Science, China
Medical University, Taichung, Taiwan, ‡ Graduate Institute of
Acupuncture Science, China Medical University, Taichung, Taiwan,
§ Division of Immunology and Rheumatology, Department of Internal
Medicine, China Medical University Hospital, Taichung, Taiwan, and
¶ Rheumatology Department, Puli Christian Hospital, Nantou, Taiwan
Received 11 June 2008; revised 11 June 2008; accepted 9 October
2008
Correspondence: Fuu-Jen Tsai, Human Genetic Center, China Medical
University Hospital, 2 Yu-Der Rd., Taichung City 40447, Taiwan.
Tel: +886 4 2205 2121 ext. 7080; Fax: +886 4 2203 3295;
E-mail: d0704@mail.cmuh.org.tw
and Wai Wong, Rheumatology Department, Puli Christian Hospital,
1 Teh-Shan Rd, Puli, Nantou 545, Taiwan. Tel: +886 49 291 2151
ext. 3301; Fax: +886 49 291 6901; E-mail: chihkuei@mail.pch.org.tw