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pliance with gluten-flee diet in adolescents with
' !iiiiscreenm -detected celiac disease: A 5-year follow-up
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Elisabetta Fabiani, MD, Luciana Maria Taccar~ MD, Ilse-Maria Rdtsch, MD, Silvia Di Giuseppe, PhD,
Giovanni Valentino Coppa, MD, and Carlo Catass4 MD
After 5 years of treatment, 22 patients with celiac disease, diagnosed by
means of serologic mass screening (mean age, 17.9 years), showed a lower
compliance with a gluten-free diet and frequent positivity of serum anti-en-
domysium antibodies (32%) in comparison with a group of 22 age-matched
patients diagnosed because of "typical" symptoms during childhood. (J Pe-
diatr 2000; 136:841-3)
Patients affected with celiac disease do
not always comply with the gluten-free
diet, especially during adolescence. ]
The percentage of patients with CD
who do not strictly adhere to the GFD
ranges from 7% to 55%2; this variabili-
ty is related to factors such as age at di-
agnosis, sex, school grade, self-esteem,
family social class, and education
level. 1,3,4No data are available regard-
ing long-term compliance with the
GFD in patients diagnosed in a mass
screening program. This is an impor-
tant piece of information when evaluat-
ing the cost-effectiveness ratio of the
screening. We previously performed
serologic screening for CD in 5280
teenagers, which led to the identifica-
tion of 28 patients affected with "silent"
From the Department of Paediatrics, Urffversity of
Ancona, Ancona, Italy.
Submitted for publication July 28, 1999;
revision receivedNov 12, 1999; acceptedDec
28, 1999.
Reprint requests: Carlo Catassi, MD, Uni-
versity Department of Paediatrics, Via F Cor-
ridoni 11, 60123 Ancona, Italy.
Copyright © 2000 by Mosby, Inc.
0022-3476/2000/$12.00 + 0 9/22/105351
doi:10.1067/mpd.2000.105351
or "atypical" CD. 5 The aim of this study
was to evaluate the compliance with the
GFD in these patients with screening-
detected CD after 5 years from the
diagnosis in comparison with an age-
matched group of patients diagnosed
because of typical symptoms of CD.
PATIENTS AND
METHODS
During the period from June to Octo-
ber 1998, 2 groups of patients with CD
were recalled for evaluation: (1) subjects
aged 11 to 14 years who were diagnosed
in a mass serologic screening program
carried out in central Italy from 1992 to
1994 (group A) and (2) patients with
CD diagnosed in our department in
1985 and 1986 because of typical symp-
toms such as poor growth, chronic diar-
rhea, and anemia (group B). All patients
received a biopsy-proven diagnosis of
CD in our department, according to the
criteria of the European Society of Pae-
diatric Gastroenterology and Nutrition. 6
All were advised to start a strict GFD
and to return for yearly follow-up visits
in our clinic.
Each patient underwent the follow-
ing investigations: (1) clinical and an-
thropometric assessment, (2) dietary
interview (food frequency question-
naire) conducted by a dietitian, (3)
psychologic testing with the self-evalu-
ation questionnaires for anxiety (Insti-
tute for Personality and Ability Test-
ing, Anxiety Questionnaire) and
depression (Institute for Personality
and Ability Testing, Clinical Depres-
sion Questionnaire)/and (4) routine
hematologic tests and serologic tests
for CD markers (IgA- and IgG-anti-
gliadin antibody and IgA-anti-en-
domysium antibody),
IgA-AGA and IgG-AGA were mea-
sured by an enzyme-linked immunosor-
bent assay (Alfa-gliatest; Eurospital,
Trieste, Italy); IgA-AEA was detected
by indirect immunofluorescence, with
the distal portion of monkey esophagus
as the antigenic substrate (Endomisio,
Eurospital),
The results were compared by the
Mann-Whitney test.
RESULTS
Of the 27 subjects in group A, 22
agreed to participate in this study. Rea-
sons for dropout were change of resi-
dence (2 patients) and refusal to par-
ticipate (3 patients who were said to be
healthy on a normal diet). Of the 24
841