Health Policy 84 (2007) 112–122
Outcome measures for clinical genetics services: A comparison
of genetics healthcare professionals and patients’ views
Katherine Payne
a,b,*
, Stuart G. Nicholls
a,b
, Marion McAllister
a,c
,
Rhona MacLeod
c,b
, Ian Ellis
d,e,a
, Dian Donnai
c,b
, Linda M. Davies
b
a
The North West Genetics Knowledge Park (NOWGEN), Manchester, UK
b
The University of Manchester, Manchester, UK
c
Central Manchester and Manchester Childrens’ University Hospitals NHS Trust, Manchester, UK
d
Cheshire and Merseyside Clinical Genetics Service, Royal Liverpool
Children’s NHS Trust Alder Hey Hospital, Liverpool, UK
e
University of Liverpool, Liverpool, UK
Abstract
Objectives: To explore genetics professionals’ and patients’ views about which outcome domains are most appropriate to
measure the patient benefits of using a clinical genetics service.
Methods: A postal Delphi survey was sent to: 115 consultant geneticists; 162 genetic counsellors; 156 support group represen-
tatives; 106 patients. The survey contained 19 outcome domains and respondents assessed the usefulness of each for clinical
genetics services.
Results: The final professional panel comprised 115 genetics healthcare professionals and the patient panel comprised 72
patients. The outcome domains that achieved consensus (at least 75% of panel rated ‘useful’) for the patient and professional
panels were: decision-making; knowledge of the genetic condition; perceived personal control; risk perception; satisfaction;
meeting expectations; ability to cope; diagnosis accuracy; quality of life. Comparison of the ratings between the professional
panel and the patient panel showed there was no statistical difference (χ
2
, p < 0.01) between the ratings (‘useful’ compared to
‘not useful’) for 14 of the 19 outcome domains but found differences for the perceived usefulness of: level of depression; health
status; spiritual well-being; test accuracy; rate of termination.
Conclusions: This Delphi survey identified nine outcome domains which are good starting points to develop a core set of
outcome measures for evaluating clinical genetics services.
© 2007 Elsevier Ireland Ltd. All rights reserved.
Keywords: Outcome assessment; Delphi technique; Medical genetics
*
Corresponding author at: The North West Genetics Knowledge Park, The NOWGEN Centre, 29 Grafton Street, Manchester M13 9WU,
UK. Tel.: +44 161 276 8979; fax: +44 161 276 4058.
E-mail addresses: Katherine.payne@manchester.ac.uk (K. Payne), stuart.g.nicholls@manchester.ac.uk (S.G. Nicholls),
marion.mcallister@cmmc.nhs.uk (M. McAllister), rhona.macleod@cmmc.nhs.uk (R. MacLeod), ian.ellis@rlc.nhs.uk (I. Ellis),
dian.donnai@cmmc.nhs.uk (D. Donnai), linda.m.davies@manchester.ac.uk (L.M. Davies).
0168-8510/$ – see front matter © 2007 Elsevier Ireland Ltd. All rights reserved.
doi:10.1016/j.healthpol.2007.03.005