Usefulness of myocardial strain imaging in Duchenne muscular dystrophy
A. Fayssoil
Cardiologie, Hôpital Européen Georges Pompidou, AP-HP, Paris, France
Received 3 May 2008; accepted 1 November 2008
Available online 26 November 2008
Abstract
Duchenne muscular dystrophy is an X-linked recessive disorder caused by the absence of dystrophin. Heart involvement is a classical
complication in this disease and leads progressively to heart failure. Detecting latent myocardial involvement is essential in this disease
because early use of drugs like angiotensin - converting enzyme inhibitors may delay the progression of heart disease. Myocardial strain
imaging is an application of the tissue Doppler imaging. By assessing regional myocardial function, this tool might help clinicians to detect
latent myocardial involvement in DMD patients.
© 2008 Elsevier Ireland Ltd. All rights reserved.
Keywords: Duchenne muscular dystrophy; Dystrophin; Cardiomyopathy; Strain and strain rate imaging
E-mail address: fayssoil2000@yahoo.fr .
Duchenne muscular dystrophy (DMD) is an X-linked
recessive disorder caused by the absence of dystrophin [1].
This disease affects 1 of 3500 male births and is characterized
on pathologic evaluation by skeletal and cardiac muscle
degeneration with fibrous tissue replacement and fatty
infiltration [1]. Dystrophin is located on the inner sides of
the skeletal and cardiac muscle cells. It links the cytoskeleton
to the extracellular matrix by interacting with a large number
of membrane proteins and it might also play a role in the
regulation or localization of signal transduction molecules
[2]. The lack of dystrophin in cardiac muscle leads to
progressive cardiomyocyte degeneration and fibrosis [1].The
posterior basal segment of the left ventricle is the first site
affected on echocardiography [3].The incidence of cardio-
myopathy in DMD increases with age, affecting 30% of
patients by the age of 14 years, 50% by the age of 18 years,
and all older patients [3]. The onset of this disease occurs in
early childhood, and most patients die of respiratory failure,
congestive heart failure or sudden death at approximately
20 years of age. Heart involvement is initially asymptomatic
and most DMD patients remain asymptomatic for years in
spite of the progression of cardiac dysfunction because of
their limited daily activities. Overt symptoms due to heart
failure appear in about 30% of cases [4]. Therefore, patients
may have profound cardiac dysfunction when they initially
experience slight cardiac symptoms. Hence, detection of
early presymptomatic cardiac involvement in DMD patients
is important. Moreover, early detection of latent myocardial
involvement and early use of drugs such as angiotensin-
converting enzyme inhibitors or beta-blockers would be
beneficial for delaying progression of heart failure in DMD
patients [5]. Traditionally, tissue Doppler imaging (TDI) is
used for detecting infraclinical cardiomyopathy. However,
analysis of myocardial velocity profiles using conventional
TDI cannot distinguish regional velocity from translational
motion of the heart and the tethering effect of adjacent
myocardial segments. To overcome these problems, ultra-
sound-derived strain rate and strain were developed and are
interesting in DMD patients [6]. Myocardial strain imaging, a
echocardiographic technique using the tissue Doppler
method, is useful for quantitative assessment of regional
wall motion of the left ventricle. It has been recognized as a
sensitive method to detect regional abnormalities in various
heart diseases [7]. Strain rate measures the rate of deforma-
tion of a tissue segment and is measured in 1/s. Peak systolic
strain rate represents the maximal rate of deformation in
systole. According to Ogata et al. [1], the strain profile is
modified at the postero-lateral wall of the left ventricle in
DMD patients. Postero-lateral wall abnormalities have been
reported to be a common region for cardiac involvement in
DMD, before overt cardiomyopathy's development [1]. In a
recent study [8], myocardial strain imaging in DMD patients
was characterized by decreased peak systolic strain of the
posterior wall despite normal standard echocardiographic
findings. Myocardial radial strain of the left ventricle was
measured in 25 DMD patients (age: 14.8 ± 3.1 years) with a
normal left ventricular shortening fraction and 25 age-
matched healthy controls. Echocardiography with strain tools
will help clinicians for early therapeutic intervention. It has
been demonstrated that early therapeutic administration
would be beneficial for high-risk patients with DMD to
prevent heart failure.
114 Letters to the Editor