J Pediatr Adolesc Gynecol (2002) 15:151-152
© 2002 North American Society for Pediatric and Adolescent Gynecology 1083-3188/02/$22.00
Published by Elsevier Science Inc. PII S1083-3188(02)00146-8
Original Studies
Vaginal Adhesions Caused by Stevens-Johnson Syndrome
Roger Hart, MRCOG, Catherine Minto, MB ChB, and Sarah Creighton, MD, MRCOG
Reproductive Medicine Unit, Elizabeth Garrett Anderson Hospital, University College Hospitals, London, United Kingdom
Abstract. Stevens-Johnson syndrome is a rare, life-threatening
condition characterized by epidermal necrosis and involvement
of the mucosal surfaces. We report a case of Stevens-Johnson
syndrome with vaginal involvement in an 11-yr-old girl who
was treated conservatively in the acute stage of the disease. Af-
ter recovery from the profound systemic upset, she underwent
vaginoscopy, which demonstrated some adhesions, which
were divided. We recommend that all patients with Stevens-
Johnson syndrome with vaginal involvement undergo routine
follow-up to evaluate possible adhesions.
Key Words. Stevens-Johnson syndrome—Vaginal
adhesions—Vaginoscopy
Introduction
Stevens-Johnson syndrome is a life-threatening muco-
cutaneus condition usually precipitated by a drug. It is
rare, with an incidence of up to 6 cases per million
population per year.
1
The condition is characterized
by the rapid development of widespread epidermal ne-
crosis. The primary lesions are usually irregular target
lesions or flat purpuric macules involving the trunk,
face, and proximal limbs. The cutaneous necrosis is
associated with involvement of the mucosal surfaces
and severe constitutional disturbance.
2
In the majority of cases of patients presenting with
Stevens-Johnson syndrome, sulfonamides, anticonvul-
sant agents, nonsteroidal anti-inflammatory drugs, or al-
lopurinol are implicated.
1
Management consists of
stopping all medication and supportive treatment in ei-
ther a burn or intensive care unit. The supportive therapy
consists of rehydration, reducing heat loss, topical anti-
septic preparations, and infection survelliance. Nasogas-
tric feeding may be required. Prophylactic use of
antibiotics is controversial, as is the routine administra-
tion of steroids.
2
Death occurs in less than 5% of cases
and is usually due to sepsis. However, scarring of the
mucus membranes can lead to strictures of the esoph-
ageal, tracheal, genital, or anal mucosa.
3
We describe a
case of a young girl presenting after the acute episode of
Stevens-Johnson syndrome with intravaginal adhesions.
Case Report
An 11-yr-old girl presented with Stevens-Johnson
syndrome secondary to the administration of a cepha-
losporin prescribed to treat a chest infection two
weeks previously. She had not been prescribed a
cephalosporin before but had demonstrated a marked
reaction to penicillin several years previously, with a
skin rash and mild ulceration of the mouth.
In this episode she had a marked irregular purpuric
macular rash involving mainly her trunk and limbs with
conjunctivitis and oral, vulval, and vaginal ulceration.
In the acute phase of the disease she was treated with
acyclovir and intravenous hydrocortisone. This was
subsequently changed to oral prednisolone, acyclovir,
and topical Timovate cream (Glaxo-Wellcome, Mid-
dlesex, UK) and liquid paraffin cream until the lesions
healed. The lesions took approximately one month to
completely heal. Due to the marked vulvovaginal ulcer-
ation during the acute phase of her disease, it was felt
prudent to exclude any vaginal adhesions by perform-
ing examination under anesthesia and vaginoscopy ex-
actly six months after the acute episode.
At the time of examination under anesthesia, there
were visible fine adhesions at the introitus. There were
no other introital abnormalities, and she had not yet
started to menstruate and was appropriately Tanner
staged for her age. Using a 2-mm pediatric cystoscope
(Karl Storz, Tuttlingen, Germany) video vaginoscopy
was performed using saline as the distension medium.
Approximately 2 cm beyond the introitus there were sev-
eral small band-like adhesions (Fig. 1). These fine adhe-
sions could be easily broken down with the cystoscope.
No bleeding occurred, and a topical local anesthetic gel
was applied to the vagina (Instillagel, CliniFlex, High
Address reprint requests to: Mr. Roger Hart, Reproductive Medi-
cine Unit, Elizabeth Garrett Anderson Hospital, Huntley Street,
London WC1E 6DH, U.K.; E-mail: roger_hart1@yahoo.com