Molecularand CellularProbes (1995) 9, 121-128
New members of the 3fl-hydroxysteroid dehydrogenase gene
family
Martin W. McBride, Alan J. Russell, Keith Vass,' Victoria Forster,
Sandra M. Burridge, Norma Morrison, 2 Elizabeth Boyd, 2 Bruce A. J. Ponder ~
and Roger G. Sutcliffe*
Institute of Genetics, Glasgow University, Church Street, Glasgow G I 1 5JS, ~CRC Beatson
Laboratories, Garscube Estate, Switchback Road, Bearsden, Glasgow G61 1BD,
2Department of Medical Genetics, Duncan Guthrie Institute, Yorkhill Hospitals, Glasgow,
and 3CRC Human Cancer Genetics Research Group, Department of Pathology, University
of Cambridge, Tennis Court Road, Cambridge CB2 1QP
(Received 19 August 1994, Accepted I September 1994)
Several bands of hybridization are detected when southern blots of human genomic DNA are
probed with cDNA of 3/3-hydroxysteroid dehydrogenase (3/~-HSD) type I. Two experimental
approaches were adopted to estimate the size of the 3/3-HSD gene family. Firstly, primers designed
to amplify 3/3-HSD type I and II genes were found on occasion to amplify DNA products of
appropriate length but which were resolved as distinct sequences by denaturing gradient gel
electrophor'esis (DGGE). Five of these novel bands were cloned and their sequences were found
to be closely related to 3/3-HSD types I and II. Secondly, 57 genomic clones were selected from
two 2 genomic libraries by hybridization with exonic probes of 3/3-HSD type I. These were
screened for novel members of the gene family by PCR amplification using various combinations
of PCR primers to the type I and II genes, particularly those primers that previously amplified.
novel PCR products from genomic DNA. Amplification products from ). clones were screened for
novel sequences by DGGE. As a result of these approaches, at least five new members of the 3/~-
HSD gene family were found, one of which locates to the 3/3-HSD type I and II gene cluster on
lp13. The existence of additional closely related but distinct members of the gene family should
be recognized as a potential complication when screening PCR fragments for mutations in the
type I and II genes. DGGE was found to be an exceedingly rapid means of screening amplification
products from 2 clones to search for novel members of the gene family.
KEYWORD$" 3/3-hydroxysteroid dehydrogenase, pseudohermaphroditism, gene family,
denaturing gradient gel electrophoresis.
INTRODUCTION
The steroidogenic enzyme 3/3-hydroxysteroid de-
hydrogenase (3/3-HSD) converts 3/~-hydroxy-As pre-
cursors to 3-keto-zJ 4 products and initiates the
pathways of mineralocorticoid, glucocorticoid and
sex hormone biosynthesis.' Two forms of 3/3-HSD
have been described to date in humans; the type I
enzyme is expressed principally in placenta and skin
and type II in adrenals and gonads. 2~ The type I and
II genes are very similar in structure, consisting of a
5' untranslated exon and three coding exons (Fig. 1)
* Author to whom correspondenceshould be addressed.
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121 © 1995 Academic Press Limited