Journal of Cranio-Maxillofacial Surgery (1997) 25, 153-157
© 1997 European Association for Cranio-Maxillofacial Surgery
Quintuple cancers: report of a case with triple cancers in the head and neck
R. Martin-Granizo 1, L. Naval 1, P. Castro 2, C. Goizueta 1, M. Mufioz 1
1Department of Oral & Maxillofacial Surgery (Head." F. J. Diaz), ZDepartment of OtoIaryngology
(Head." A. Hinojar), University "Hospital de la Princesa', School of Medicine, Aut6noma University of
Madrid, Spain
SUMMARY. The incidence of multiple primary cancers is increasing. We report a case of quintuple cancers, two
located in the genitourinary tract and three arising on the upper aerodigestive tract, two synchronous squamous
cell carcinomas of the oral mucosa and another on the larynx. We also present a brief review of the literature.
INTRODUCTION
Finding more than one cancer in a patient's lifetime
is not uncommon. Since Billroth (1879) in the last
century first described a second primary cancer in the
same patient, several authors have reported large
series of multiple malignancies in different organs or
even in the same area (Mallagray et al., 1987;
Robinson et al., 1991; Choy et al., 1992; Jones et al.,
1995; Nakahara et al., 1995; Sturgis and Miller, 1995;
Suryanarayana, 1996). However, triple, quadruple
and even quintuple cancers are extremely unusual,
although some cases have been reported (Tanaka
et al., 1994; Yoneyama et al., 1995; Sakashita et al.,
1996). Some authors have pointed out an increasing
incidence of these multiple primary tumours (Fijuth
et al., 1992; Jones et al., 1995; Robinson and Neugut,
1995; Sturgis and Miller, 1995).
CASE REPORT
A 61-year-old male consulted the department of Oral
& Maxillofacial Surgery at the University 'Hospital
de la Princesa', Madrid, Spain, complaining of a
lesion on the floor of his mouth. The patient had the
following medical history:
On physical examination, no cervical lymph nodes
were detected, so diagnosis of a T4, No, M o (stage IV)
SCC was made (American Joint Committee on Cancer,
1988). The patient underwent a total laryngectomy
with an ipsilateral (right) selective supra-omohyoid
neck dissection (levels I, II, and III) (Spiro et al.,
1988; Shah, 1990), and the histological report on the
specimen showed a moderately differentiated SCC
with no metastatic cervical lymph node involvement.
Second cancer
The patient stopped smoking, and 3 years later
presented to the emergency room complaining of
dysuria for 15 days with haematuria. He was treated
in the Urology Department at the same hospital. The
blood analysis showed a haemoglobin of 9.39 gr/dl
with a haematocrit of 27.29%. On urine analysis,
11-20 erythrocytes and 11-20 leucocytes per field
were found. Ultrasonography was carried out, which
revealed a vesical globus along with two masses
located on the lateral left surface and over the neck
of the urinary bladder. Therefore, the patient under-
went resection of the masses transurethrally. The
histopathological examination report showed vesical
urothelial papillary carcinoma grade II (stage 0).
First cancer
Three years previously, the patient, with a 2 month
history of slowly increasing hoarseness, consulted the
Otolaryngology Department. The patient had been a
heavy smoker (60 cigarettes per day) and drinker for
many years and his father had died of a laryngeal
cancer. Panendoscopy revealed oedema of both vocal
cords with an ulcerated lesion on the right cord that
invaded the laryngeal ventricle and surrounding tis-
sues. A biopsy was obtained and the histological
analysis showed a squamous cell carcinoma (SCC).
153
Third cancer
At the postoperative follow-up examination, a pros-
tatic enlargement was noticed. Biopsy revealed a well-
differentiated prostatic adenocarcinoma. A computed
tomography scan (CT) of the spinal cord was per-
formed which revealed several radiodense bone
lesions suggesting prostatic metastases inside the
lumbar vertebra. As a result, the patient is under
hormonal therapy with 750 mg/day oral flutamide,
an antiandrogen drug, with an optimal response.