1 d'Orio P, et al. J Neurol Neurosurg Psychiatry 2018;0:1–6. doi:10.1136/jnnp-2018-318282
RESEARCH PAPER
Surgery in patients with childhood-onset epilepsy:
analysis of complications and predictive risk factors
for a severely complicated course
Piergiorgio d’Orio,
1
Michele Rizzi,
1,2
Valeria Mariani,
1
Veronica Pelliccia,
1
Giorgio Lo Russo,
1
Francesco Cardinale,
1
Michele Nichelatti,
3
Lino Nobili,
1,4
Massimo Cossu
1
Neurosurgery
To cite: d’Orio P, Rizzi M,
Mariani V, et al. J Neurol
Neurosurg Psychiatry Epub
ahead of print: [please
include Day Month Year].
doi:10.1136/jnnp-2018-
318282
1
"Claudio Munari" Epilepsy
Surgery Centre, Azienda Socio
Sanitaria Territoriale Grande
Ospedale Metropolitano
Niguarda, Milano, Italy
2
Department of Neuroscience,
University of Parma, Parma, Italy
3
Service of Biostatistics, Azienda
Socio Sanitaria Territoriale
Grande Ospedale Metropolitano
Niguarda, Milano, Italy
4
Child Neuropsychiatry Unit,
DINOGMI, University of Genoa,
Genoa, Italy, Istituto Giannina
Gaslini, Genova, Italy
Child Neuropsychiatry Unit,
Istituto Giannina Gaslini,
DINOGMI, University of Genoa,
Genoa, Italy
Correspondence to
Dr Massimo Cossu, “Claudio
Munari” Center for Epilepsy
Surgery, Azienda Socio Sanitaria
Territoriale Grande Ospedale
Metropolitano Niguarda, Milan
20162, Italy; massimo.cossu@
ospedaleniguarda.it
Received 21 February 2018
Revised 12 July 2018
Accepted 15 July 2018
© Author(s) (or their
employer(s)) 2018. No
commercial re-use. See rights
and permissions. Published
by BMJ.
ABSTRACT
Object To compare the occurrence of surgery-related
complications in patients with childhood-onset focal
epilepsy operated on in the paediatric or in the adult
age. To investigate risk factors for surgery-related
complications in the whole cohort, with special attention
to age at surgery and severe morbidity.
Methods A cohort of 1282 patients operated on
for childhood-onset focal epilepsy was retrospectively
analysed. Occurrence of surgery-related complications,
including a severely complicated course (SCC: surgical
complication requiring reoperation and/or permanent
neurological deficit and/or death), was compared
between patients operated on in the paediatric age (<16
year-old; 452 cases) and, respectively, in adulthood (≥16
year-old; 830 cases). The whole cohort of patients was
also evaluated for risk factors for a SCC.
Results At last contact (median follow-up 98 months),
74.5% of patients were in Engel’s class I (78.0% of
children and 73.0% of adults). One hundred patients
(7.8%) presented a SCC (6.4% for children and 8.6% for
adult patients). Postoperative intracranial haemorrhages
occurred more frequently in adult cases. At multivariate
analysis, increasing age at operation, multilobar surgery,
resections in the rolandic/perirolandic and in insulo-
opercular regions were independent risk factors for a
SCC.
Conclusions Surgery for childhood-onset focal
epilepsy provides excellent results on seizures and
an acceptable safety profile at any age. Nevertheless,
our results suggest that increasing age at surgery is
associated with an increase in odds of developing severe
surgery-related complications. These findings support
the recommendation that children with drug-resistant,
symptomatic (or presumed symptomatic) focal epilepsy
should be referred for a surgical evaluation as early as
possible after seizure onset.
INTRODUCTION
Surgery is recognised as a useful and effective treat-
ment option for drug-resistant focal epilepsy. Its
effectiveness and safety have been demonstrated
for both adults
1 2
and children.
3
Excellent results on
seizures have been reported also in more heteroge-
neous series for every age range.
4–6
Childhood-onset epilepsy is often refractory
to drug treatment, and the detrimental effects of
ongoing seizures, abnormal electrical activity and
antiepileptic drugs on brain development, cogni-
tive functions and psychosocial outcome have been
widely reported.
7
Furthermore, childhood-onset
drug-resistant epilepsy has been recognised as a
significant risk factor for epilepsy-related mortality.
8
For these reasons, early surgical treatment of chil-
dren with symptomatic focal epilepsy has been
advocated, in order to contrast the harmful impact
of epilepsy on health-related quality of life in the
paediatric age.
9
Nevertheless, despite a general increase in
volume of surgeries in children, including complex
and severe cases,
10
this treatment option appears to
be still largely underused.
11
As a consequence, many
ideal candidates for paediatric surgery are operated
on during adulthood after several years of disease
duration.
Potential morbidity associated with epilepsy
surgery has been claimed as one possible cause
of reluctance to refer for surgery of youngest
patients with intractable epilepsy.
12
Although
data concerning factors associated with a compli-
cated postoperative course, including age, are not
univocal, several recent studies reported a low rate
(5.5%–12%) of complications in the paediatric
age.
13–16
In this retrospective single-centre study, we have
addressed the issue of risk factors for surgery-re-
lated complications in a large series of patients with
childhood-onset epilepsy. Our main hypothesis was
that surgery performed during the paediatric age is
burdened by a lower surgical risk.
METHODS
Patients
We searched our institutional database and clin-
ical charts for patients with childhood-onset (<16
years) focal epilepsy treated surgically from 1996
to 2016.
All eligible patients were included in the present
cohort. Presurgical investigations and surgery were
performed only after the patients or their tutors
had given their informed consent. The local Ethical
Committee approved the present study.
Presurgical evaluation
A comprehensive presurgical workup included:
clinical history, neurological examination, interictal
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