AJR:215, August 2020 1
The Imaging Question
What are the currently reported rates of
treatment outcomes (i.e., complications, de-
layed hemorrhage, obliteration rates, recur-
rence rates, all-cause mortality, and neuro-
logic status) after bAVM treatment and after
conservative management in children?
Background and Importance
Brain arteriovenous malformations are
vascular lesions formed from abnormal con-
nections between arteries and veins in the
brain, with a lack of capillaries between the
vascular connections [4]. The goal of bAVM
treatment is complete obliteration of the
bAVM to prevent hemorrhage with preserva-
Treatment Strategies and
Related Outcomes for Brain
Arteriovenous Malformations in
Children: A Systematic Review
and Meta-Analysis
Parneyan Pezeshkpour
1
Adam A. Dmytriw
1
Kevin Phan
2
Manohar M. Shroff
1
Peter Dirks
3
Abhaya V. Kulkarni
3
Prakash Muthusami
1
Pezeshkpour P, Dmytriw AA, Phan K, et al.
1
Department of Diagnostic Imaging, The Hospital for
Sick Children, University of Toronto, 555 University Ave,
Toronto, ON M5G 1X8, Canada. Address correspondence
to P. Muthusami (prakash.muthusami@sickkids.ca).
2
NeuroSpine Research Group, Liverpool Hospital,
Sydney, Australia.
3
Department of Surgery, Division of Neurosurgery,
University of Toronto, Toronto, ON, Canada.
Pediatric Imaging • Best Practices/Original Research
AJR 2020; 215:1–16
ISSN-L 0361–803X/20/2152–1
© American Roentgen Ray Society
Clinical Vignette and Images
In children, brain arteriovenous malfor-
mations (bAVMs) are responsible for most
cases of spontaneous intracranial hemor-
rhage [1–3]. There is a limited but growing
understanding regarding the long-term risk
of hemorrhage as well as successful oblit-
eration rates, case fatality, and complica-
tion risk after different therapeutic inter-
ventions or conservative management. In
this systematic review and meta-analysis,
we synthesize and summarize the avail-
able evidence in the literature with an aim
of providing practice guidelines to direct
treatment decisions and to highlight re-
search areas that need attention.
Keywords: brain arteriovenous malformation,
embolization, intracranial hemorrhage, pediatric
arteriovenous malformation, radiosurgery
doi.org/10.2214/AJR.19.22443
Received October 16, 2019; accepted after revision
December 18, 2019.
OBJECTIVE. The objective of this study was to assess the available evidence in the liter-
ature regarding treatment outcomes for pediatric patients with brain arteriovenous malforma-
tion (bAVM) with the aim of providing practice guidelines for treatment decisions and high-
lighting research areas that need attention.
MATERIALS AND METHODS. Keyword searches for studies published from Janu-
ary 1, 1981, to April 16, 2018, were performed in MEDLINE, Embase, and Web of Science.
Predefned inclusion criteria were used to identify studies. Poisson regression analysis for as-
sociations between patient and bAVM characteristics and treatment outcomes.
RESULTS. We identifed 34 articles comprising 2158 children with bAVM who under-
went treatment or observation. The mean age of the study cohort was 12.0 ± 1.6 (SD) years,
and 48.1% of the patients were female; 64.3% of bAVMs were hemorrhagic at presenta-
tion. The mean follow-up was 50.6 ± 32.3 months. Overall, the meta-analysis of pooled data
showed an obliteration rate of 69.8% (95% CI, 62.9–75.9%), recurrence rate of 2.2% (95%
CI, 1.1–4.3%), and mortality rate of 2.4%. The pooled complication rate was 22.5% (95% CI,
15.7–31.1%) after surgery, 26.4% (95% CI, 15.2–41.9%) after embolization, and 27.1% (95%
CI, 18.1–38.4%) after radiosurgery. Mortality was not associated with age, sex, or hemor -
rhage; however, recurrence after treatment was inversely associated with age. Complication
and mortality rates were reduced for multimodal treatments. For patients with bAVM treated
with observation only, complication and mortality rates were 35.9% and 23.5%, respectively.
CONCLUSION. Multimodality treatments for pediatric bAVM had lower mortality and
complication rates than individual treatments. However, there is a lack of evidence for long-
term outcomes. The mortality rate was highest in conservatively managed patients (i.e., ob-
servation only). Further research directly comparing different treatment modalities for recur-
rence and complications is warranted. Gathering data prospectively through multiinstitutional
registries will be key to provide strong evidence.
Pezeshkpour et al.
Treatments and Outcomes of bAVMs in Children
Pediatric Imaging
Best Practices/Original Research
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