Suggestive Evidence of a Locus on Chromosome
10p Using the NIMH Genetics Initiative Bipolar
Affective Disorder Pedigrees
Tatiana Foroud,
1
* Peter F. Castelluccio,
1
Daniel L. Koller,
1
Howard J. Edenberg,
1
Marvin Miller,
1
Elizabeth Bowman,
1
N. Leela Rau,
1
Carrie Smiley,
1
John P. Rice,
2
Alison Goate,
2
Christopher Armstrong,
2
Laura J. Bierut,
2
Theodore Reich,
2
Sevilla D. Detera-Wadleigh,
3
Lynn R. Goldin,
3b
Judith A. Badner,
3a
Juliet J. Guroff,
3
Elliot S. Gershon,
3a
Francis J. McMahon,
4a
Sylvia Simpson,
4
Dean MacKinnon,
4
Melvin McInnis,
4
O. Colin Stine,
4c
J. Raymond DePaulo,
4
Mary C. Blehar,
5
and John I. Nurnberger, Jr.,
6
1
Department of Medical and Molecular Genetics, Indiana University School of Medicine, Indianapolis, Indiana
2
Department of Psychiatry, Washington University School of Medicine, St. Louis, Missouri
3
Clinical Neurogenetics Branch, National Institute of Mental Health, National Institutes of Health,
Bethesda, Maryland
4
Department of Psychiatry, Johns Hopkins University Medical School, Baltimore, Maryland
5
Mood, Anxiety, and Personality Disorders Research Branch, National Institute of Mental Health, National Institutes
of Health, Rockville, Maryland
6
Department of Psychiatry, Indiana University School of Medicine, Indianapolis, Indiana
As part of a four-center NIMH Genetics Ini-
tiative on Bipolar Disorder, a genome
screen using 365 markers was performed on
540 DNAs from 97 families, enriched for af-
fected relative pairs. This is the largest uni-
formly ascertained and assessed linkage
sample for this disease, and includes 232
subjects diagnosed with bipolar I (BPI), 32
with schizo-affective, bipolar type (SABP),
72 with bipolar II (BPII), and 88 with unipo-
lar recurrent depression (UPR). A hierar-
chical set of definitions of affected status
was examined. Under Model I, affected indi-
viduals were those with a diagnosis of BPI
or SABP, Model II included as affected those
fitting Model I plus BPII, and Model III in-
cluded those fitting Model II plus UPR. This
data set was previously analyzed using pri-
marily affected sib pair methods. We report
the results of nonparametric linkage analy-
ses of the extended pedigree structure using
the program Genehunter Plus. The strong-
est finding was a lod score of 2.5 obtained on
chromosome 10 near the marker D10S1423
with diagnosis as defined under Model II.
This region has been previously implicated
in genome-wide studies of schizophrenia
and bipolar disorder. Other chromosomal
regions with lod scores over 1.50 for at least
one Model Included chromosomes 8 (Model
III), 16 (Model III), and 20 (Model I). Am. J.
Med. Genet. (Neuropsychiatr. Genet.) 96:18–
23, 2000 © 2000 Wiley-Liss, Inc.
KEY WORDS: bipolar affective disorder; ge-
netics; linkage; nonparamet-
ric analysis; genomic survey
INTRODUCTION
Bipolar affective disorder (BP) is a disabling condi-
tion involving dysregulation of multiple physiologic
functions, including mood, appetite, sleep, and activity
[Goodwin and Jamison, 1990]. It occurs in about 1% of
the population, usually with onset in early adulthood.
BP has been observed to aggregate within families
[Nurnberger et al., 1994b], with evidence from twin and
adoption studies suggesting a significant genetic con-
tribution to risk [Bertelsen et al., 1977; Mendlewicz
Contract grant sponsor: NIMH; Contract grant numbers: U01
MH46282, U01 MH54794, U01 MH46280, U01 MH54723, U01
MH46274, and U01 MH54701.
a
Present address: Department of Psychiatry, Biological Sci-
ences Division, University of Chicago, Chicago, IL.
b
Present address: Genetic Epidemiology Branch, DCEG, NCI,
Bethesda, MD.
c
Present address: Center for the Genetics of Asthma and Com-
plex Diseases, School of Medicine, University of Maryland, Bal-
timore, MD.
*Correspondence to: Tatiana Foroud, Ph.D., Department of
Medical and Molecular Genetics, Indiana University School of
Medicine, 975 W. Walnut Street IB-155, Indianapolis, IN 46202.
E-mail: tforoud@iupui.edu
Received 30 July 1999; Accepted 26 August 1999
American Journal of Medical Genetics (Neuropsychiatric Genetics) 96:18–23 (2000)
© 2000 Wiley-Liss, Inc.