Colorectal duplication with prostatorectal fistulae
☆,☆☆
Mamta Sengar, Chhabi R. Gupta, Vishesh Jain
⁎
, Anup Mohta
Department of Pediatric Surgery, Chacha Nehru Bal Chikitsalaya, Delhi, India 110031
Received 28 September 2012; revised 25 November 2012; accepted 15 December 2012
Key words:
Colonic duplication;
Tubular colonic
duplication;
Prostatorectal fistula;
Gastrointestinal
duplication
Abstract Tubular colonic duplications are rare malformations and its association with prostatorectal
fistula is extremely rare with only one case reported to date. We report the successful management
of an 8 year old child with communicating tubular colonic duplication with prostatorectal fistulae.
Tubular colonic duplications may be difficult to diagnose due to varied presentations, therefore a
high degree of suspicion should be present while managing children with isolated congenital recto
urinary fistulas.
© 2013 Elsevier Inc. All rights reserved.
Gastrointestinal tract duplications are rare congenital
anomalies which can occur anywhere along the alimentary
canal from the tongue to the anus [1]. Duplication of colon
accounts for 13% of all gastrointestinal tract duplication [1].
We present an unusual case of communicating colorectal
duplication with prostatorectal fistulae successfully managed
by us.
1. Case history
An 8 year old boy presented to us for the first time with
the complaint of constipation since birth. Constipation was
relieved partially after episodes of fecaluria. The child also
suffered from recurrent urinary tract infections and rectal
prolapse. There was no history of trauma or inflammatory
disease in the perineum. On general examination, patient was
found to have minimal scoliosis and an extra thumb in his left
hand. There were no abnormal findings on abdominal,
perineal and digital rectal examination.
Based on history and examination, a provisional diagno-
sis of H/N shaped recto urethral fistula was made. A high
loop sigmoid colostomy was performed for the symptomatic
relief till patient could be investigated prior to definitive
management. After performing the colostomy, the episodes
of fecaluria ceased, however, the patient started passing urine
through rectum.
Voiding cystourethrogram (VCUG) revealed presence of
two lateral diverticulae in the posterior urethra. Distal
colostogram with water soluble contrast was suggestive of
a prostatorectal communication. Cystourethroscopy revealed
two large diverticulae in prostatic urethra just lateral to the
verumontanum on either side of it (Fig. 1). When the
cystoscope was negotiated into the diverticulae, multiple
openings were noted. Passage of fine ureteric stents into
these openings confirmed their communication with the
rectum. After leaving a stent in one of the fistulae, the patient
was turned prone in jack knife position with the plan of
dividing the recto urethral fistula though the posterior sagittal
approach. On examination under anesthesia, multiple large
fistulous openings were seen in the anterior wall of the
rectum, approximately one centimeter from the anal verge.
There was another opening in the colorectum on the posterior
☆
Source(s) of support: Nil.
☆☆
Conflicting Interest (If present, give more details): Nil.
⁎
Corresponding author. Tel.: + 91 09540951519; 01132531393.
E-mail address: dr.vishesh79@gmail.com (V. Jain).
www.elsevier.com/locate/jpedsurg
0022-3468/$ – see front matter © 2013 Elsevier Inc. All rights reserved.
http://dx.doi.org/10.1016/j.jpedsurg.2012.12.032
Journal of Pediatric Surgery (2013) 48, 869–872