Neuron, Vol. 5, 373-381,September,1990,Copyright © 1990by Cell Press
VIP-Mediated Increase in cAMP Prevents
Tetrodotoxin-lnduced Retinal Ganglion
Cell Death In Vitro
Peter K. Kaiser and Stuart A. Lipton
Laboratory of Cellular and Molecular Neuroscience
Departments of Neurology
Children's Hospital
Beth Israel Hospital
Brigham and Women's Hospital
Boston, Massachusetts 02115
Program in Neuroscience
Harvard Medical School
Boston, Massachusetts 02115
Summary
Afferent influences on natural cell death were modeled
in retinal cultures derived from neonatal rats. Tetro-
dotoxin (TTX) blockade of electrical activity produced a
significant reduction in surviving retinal ganglion cell
(RGC) neurons during a critical period of development,
similar in magnitude to the reduction observed during
natural cell death in the intact retina at a similar de-
velopmental stage. The addition of vasoactive intestinal
peptide (VI P) protected the RGCs from the lethal action
of TTX. This effect was specific, since the related pep-
tides PHI-27 and secretin produced no significant in-
crease in RGC survival. Radioimmunoassay of cyclic
nucleotides showed that TTX decreased culture levels of
cAMP and that this trend was reversed by VI P. Decreases
in RGC survival associated with TTX electrical blockade
were prevented by 8-bromo:cAMP or forskolin. Fur-
thermore, VIPt0-28, the C-terminal fragment that in-
hibits VIP stimulation of adenylate cyclase, reduced the
number of surviving RGCs. Thus, our results suggest that
VIP, acting by increasing cAMP, has a neurotrophic ef-
fect on electrically blocked RGCs and may be an endog-
enous factor modulating normal cell death in the retina.
Introduction
An interesting facet in the normal development of the
vertebrate central nervous system (CNS) is the large
proportion of neurons that die naturally (Oppen-
heim, 1981). One example is found in the mammalian
visual system. Overproduction of retinal ganglion
cells (RGCs), neurons that project from the retina to
deeper centers of the brain, appears to be a fun-
damental characteristic of development (Land and
Lund, 1979; Thompson, 1979; Finlay et al., 1979; Rakic
and Riley, 1983, 1984; Insausti et al., 1984; Williams et
al., 1986). The death of RGCs is thought to serve at
least two purposes. First, the initial overproduction of
RGCs ensures that the target structures receive ade-
quate input and that the subsequent cell death quan-
titatively matches the projecting neuronal population
to the needs of their targets (for reviews see Oppen-
helm, 1981; Hamburger and Oppenheim, 1982; Co-
wan et al., 1984; Cowan and O'Leary, 1984). Second, it
eliminates those cells whose axons project into inap-
propriate regions either in the correct target fields or
in entirely incorrect areas (for reviews see Clarke,
1981; Cowan et al., 1984; O'Leary, 1987). In other
words, it effectively removes certain developmental
miscues that cause aberrant axonal projections or
neuronal targeting errors.
In adult rats, essentially all of the RGCs send axons
to the superior collicutus in a highly ordered projec-
tion. The RGCs differentiate between days 12 and 16
of gestation, and the axons reach the contralateral su-
perior colliculus as early as embryonic day 16 (E16;
Morest, 1970; Bunt et al., 1983). The number of axons
in the optic nerve reaches its peak at approximately
E20; thereafter there is a rapid loss of RGCs (Bunt et
al., 1983; Crespo et al., 1985; Williams et al., 1986). In
the pigmented rat at least half of the RGCs die natu-
rally, and this normal cell death proceeds for the first
1 1/2 weeks of postnatal development (Cunningham
et al., 1982; Perry et al., 1983). Although the exact cel-
lular sequence of events is still under debate, the loss
of neurons is thought to be caused by at least two
mechanisms: the intermingling and competition of
RGC axonal fibers from the same eye and from the
two eyes for their postsynaptic targets du ring the early
stages of development (the efferent influence; Cowan
et al., 1984; Fawcett et al., 1984; Rakic and Riley, 1984;
O'Leary et al., 1986b; Sretavan and Shatz, 1986; Wil-
liams et al., 1986), and the effect of local factors in the
retina from cells presynaptic to the RGCs (the afferent
influence; Perry and Linden, 1982; Cunningham, 1982;
Okado and Oppenheim, 1984; Clarke, 1985; Lipton,
1986; Furber et al., 1987). Several recent findings have
shown that competition, and the consequent cell
death, are centered around the blockade of electrical
activity during a critical period of development (Co-
wan et al., 1984; Fawcett et al., 1984; Lipton, 1986;
O'Leary et al., 1986b).
Previous experiments in this laboratory studied the
effects of electrical blockade on identified RGCs dis-
sociated from retinas of neonatal rats (Lipton, 1986).
On the second day in culture, 10%-15% of the RGCs
were found to be solitary neurons; the remainder ex-
isted in small clusters with other retinal cells. Electri-
cal recordings determined that 50% of the clustered
RGCs displayed spontaneous postsynaptic potentials
and action potentials, whereas the solitary RGCs did
not. Furthermore, the same population of clustered
RGCs that exhibited spontaneous activity died within
24 hr of exposure to either tetrodotoxin (-I-rx) or Iow-
Ca2+/high-Mg 2+ medium to block synaptic activity.
Similar to natural cell death, these effects occurred
only if the RGCs were at a particular stage of develop-
ment (postnatal day 2 to 10 [P2-P10] animals, but not
older) when they either possessed or were acquiring
electrical activity. Cell death was not found in the soli-
tary RGCs that lacked synaptic input and consequent