Nephrol Dial Transplant (1996) 11: 1349-1351
Case Report
Nephrology
Dialysis
Transplantation
Kimura's disease and minimal-change nephrotic syndrome
K. Sud
1
, T. Saha
1
, A. Das
2
, N. Kakkar
2
, V. Jha
1
, H. S. Kohli
1
and V. Sakhuja
1
Departments of 'Nephrology and
2
Pathology, Postgraduate Institute of Medical Education and Research, Chandigarh, India
Key words: Kimura's disease; subcutaneous eosino-
philic lymphoid granuloma; nephrotic syndrome;
minimal-change disease; mesangial proliferative glom-
erulonephritis
Introduction
First described in 1937 by Kimm and Szeto in Chinese
literature as 'eosinophilic hyperplastic lymphogranul-
oma', this condition became widely known as Kimura's
disease after Kimura et al. reported similar cases in
Japan in 1948 (cited from reference [1]). This is an
angiolymphoid proliferative disorder of unknown
aetiology, presenting with subcutaneous tumorous
nodules, with a predilection for periauricular and sub-
mandibular regions. The disease occurs predominantly
in oriental males and is characterized by the presence
of eosinophilic lymphoid granulomas sometimes
appearing as eosinophilic abscesses with variable
degrees of fibrosis [1-3]. Kimura's disease has been
described under various synonyms such as subcutane-
ous eosinophilic lymphoid granuloma, eosinophilic fol-
liculosis of the skin, inflammatory angiomatous nodule,
pseudo- or atypical pyogenic granuloma and angio-
lymphoid hyperplasia with eosinophilia (ALHE);
however, recently ALHE has been proposed to be a
separate clinicopathological entity [1].
Renal abnormalities, notably proteinuria and
nephrotic syndrome have been found to be associated
with Kimura's disease [4,5]. A few reports describing
a steroid-responsive nephrotic syndrome have shown
reduction in the size of subcutaneous nodules with
steroids [6,7], implying a common aetiopathogenesis
of the renal lesion and Kimura's disease. We report a
patient with steroid-responsive minimal-change
nephrotic syndrome who had a steroid unresponsive
Kimura's disease requiring complete resection of the
tumour. This is also the first reported case of Kimura's
disease associated with nephrotic syndrome in a patient
from the Indian subcontinent.
Case report
A 24-year-old Indian housewife was referred for evalu-
ation of persistent proteinuria first noticed in the third
trimester of pregnancy. She did not have pre-eclampsia
and 6 weeks prior to her referral, she had delivered a
live fetus at 34 weeks of gestation. On examination,
she had anasarca and was normotensive. Investigations
revealed a haemoglobin of 12.1 g/dl, with normal total
and differential leukocyte counts. There was no eosino-
philia. Urinalysis revealed 4 + albuminuria and 2-3
RBCs/HPF. Her 24 h urinary protein excretion was
4.1 g/day and serum creatinine was 160umol/l. She
had a total serum protein of 35 g/1, a serum albumin
of 15 g/1, and serum cholesterol of 16.55 mmol/1. LE
cell preparation and ANF were negative and C3 levels
were 1 g/1 (normal 0.7-1.6 g/1). Renal biopsy was done
which showed 15 glomeruli all of normal morphology
on light-microscopy. There was no mesangial prolifera-
tion or expansion (Figure 1). There was no evidence
of capillary basement membrane thickening on PAS
stain and silver impregnation did not reveal any epi-
membranous spikes. Tubules showed hyaline casts and
the interstitium was normal. Immunofluorescence was
negative. The patient was treated with prednisolone
1 mg/kg/day for 8 weeks to achieve remission at which
time her serum creatinine was 90 umol/1 and the 24 h
Correspondence and offprint requests to: Professor V. Sakhuja, Head,
Department of Nephrology, Postgraduate Institute of Medical
Education and Research, Chandigarh 160012, India.
Fig. 1. Glomeruli showing normal morphology on light-microscopy
(H&Ex240).
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