Strong Primary Selection for the Dw4
Subtype of DR4 Accounts for the
HLA-DQw7 Association with
Felty's Syndrome
Jerry S. S. Lanchbury, Emma E. M. Jaeger,
David M. Sansom, Margaret A. Hall, Paul Wordsworth,
Judith Stedeford, John I. Bell, and Gabriel S. Panayi
ABSTRACT: Felty's syndrome (FS) is a rare complica-
tion of rheumatoid arthritis (RA) previously shown to be
strongly associated with HLA.DR4 and less significantly
with HLA-DQw7. To map more precisely the HLA locus
responsible for suzceptibility to FS, we have examined
HLA-DR4 and DQ fl-chain polymorphisms in FS pa-
tients and controls using restriction fragment length poly-
mnrphism analysis and polymerase chain reaction amplifi-
cation in conjunction with oligonuclemide probing. The
increased frequency of DR4 in FS (93% vs. 32% con-
trols) was due almost entirely to enrichment for the Dw4
subtlrpe (88% vs. 20% controls) with a secondary in-
crease of the Dw14 subtype. Dwl0 and Dwl 3 subtypes
ABBREVIATIONS
FS Felty's syndrome
MHC major histocompatibility complex
PCR polymerase chain reaction
INTRODUCTION
Approximately I% of patients with rheumatoid arthritis
(RA) develop Felty's syndrome (FS). There is strong
evidence for the importance of a genetic component in
the development of FS since the disease is associated
From the Molecular lmmunogenetics and Rheumatologv Unit~, Divi-
sion of Medicine, UMDS, Gay's Hospital (LS.S.L.; E.E.Md.; M.A.H.;
G.S.P.h London, Bath lmtitate for Rheumatic DiJeam fD.M.$.), Trim
Bridge, Bath, and Institute of Moluular Medicine, Univenity of Oxford,
John Radcliffe Hospital (P.W.;J.S.; J.I.BJ, Oxford, United Kingdom.
Addressreprint requestJto Dr.Jerry$.S. Lanehbury, Division of Medi-
cine, UMDS, 4th Floor Hunt's House, Guy's Hospital, London. SEl 9RT.
United Kingdom.
Ruei~d Februar~ 12, 1991; accepted April 17. 1991.
56
0198-8859191153.50
of DR4 were absent from the patient group. Increase in
DQw7 frequency among DRZi FS patients could be ac-
counted for by linkage disequilibrium between Dw4 and
DQw7 alleles. Whereas susceptibility to RA is strongly
associated with a conserved HLA-DR~ epimpe associ-
ated with several DRBI alleles, it is primarily the Dw4
allele which is associated with progression to Felty's syn-
drome. The finding that amino acid sequence variation at
the DR4B1 locus rather than DQBI is associated with
development of FS will have important implications for
the development of novel immunotherapies which are
major histocompadbility complex allele-dependent. Hu-
man Immunology 32, 56-64 (1991)
KFLP restriction fragment length polymocphism
RA rheumatoid arthritis
HVR3 third hypervariahle region
with polymorphic markers of the HLA complex. HLA-
DR4 is strongly associated with Pelty's syndrome, being
present in 92% to 95% of patients compared to approx-
imately 30% of healthy controls [1-3]. This contrasts
with the moderate DR4 association found with RA [4].
Identification of primary disease associations in the ma-
jor histocompatibilitT complex (MHC) is complicated
by strong linkage disequilibrium but the step is essential
in defining precise susceptibility loci and therefore in
developing specific immunotherapeutic strategies. Ap-
plication of molectflar techniques to the dissection of
DR4 haplotypes has revealed considerable complexity.
HLA-DR4 is a serological determinant encoded by a
Humen Immunology 32, 56-64 (L991)
© American Society for Hismcompatibility and lmmuaogenetics, L99!