The Journal of Rheumatology 2002; 29:9 2000
From the Pediatric Rheumatology Unit, Department of Pediatrics,
Children’s Institute, and the Division of Urology Clinic, University of São
Paulo, São Paulo, Brazil.
C.A.A. Silva, MD, PhD, Head, Pediatric Rheumatology Unit, Department
of Pediatrics; J. Hallak, MD, PhD, Attending Physician, Division of
Urology Clinic; F.F. Pasqualotto, MD, Postgraduate student, Division of
Urology Clinic; M.F. Barba, MD, PhD, Attending Physician, Department
of Pediatric Radiology; M.I. Saito, MD, PhD, Head, Adolescent Unit;
M.H.B. Kiss, MD, PhD, Associate Professor of Pediatrics.
Address reprint requests to Dr. C.A.A. Silva, Rua Raul Pompéia,
303/43-Pompéia, São Paulo SP, Brazil CEP 05025-010.
E-mail: clovisaas@icr.hcnet.usp.br
Submitted October 17, 2001; revision accepted March 7, 2002.
Systemic lupus erythematosus (SLE) is a multisystem
autoimmune disease of unknown etiology and is more preva-
lent in women than in men (F:M = 5:1)
1
. The annual incidence
of juvenile onset SLE in childhood is roughly 0.4 per 100,000.
The prognosis for children and adolescents with SLE con-
tinues to improve as better access to medical care and diag-
nostic testing have provided better detection of children with
SLE
2
. With antiinflammatory therapy as well as sophisticated
pediatric care, 10-year survival rates are now found in over
80% of patients with SLE
3,4
. However, clinical attention has
begun to shift away from the problems of cure and toward
refinements in quality of life among the survivors. Despite the
number of adolescents and young adults with SLE, few stud-
ies have reported the gonadal function of these patients.
Oligospermia or azoospermia in patients with SLE may
have several causes including adolescence, the disease itself,
drugs used to treat the illness, disease of the genital system
5,6
,
hypothalamic-pituitary-axis dysfunction
7,8
, autoimmunity,
activity of the disease
9
, and especially the drugs used as
immunosuppressors, particularly cyclophosphamide
10-15
and
chlorambucil
12-15
.
We studied gonadal function in 4 male adolescents and
young men with SLE.
MATERIALS AND METHODS
Patients. Four male patients who fulfilled 4 or more 1982 American College
of Rheumatology (ACR) classification criteria for SLE
16
, followed at the
Pediatric Rheumatology Unit of the Children’s Institute of our university hos-
pital, were studied. Informed consent was obtained from all participants.
Their actual ages ranged from 16 years and 9 months to 22 years and 10
months.
Clinical evaluation. SLE disease activity and cumulative damage at the time
of study entry were measured in all patients, using the SLE Disease Activity
Index (SLEDAI)
17
and the Systemic Lupus International Collaborating
Clinics/ACR (SLICC/ACR) Damage Index
18
. SLE activity was classified into
3 patterns: relapsing-remitting (RR), chronic active (CA), and long quiescent
Gonadal Function in Male Adolescents and Young
Males with Juvenile Onset Systemic Lupus
Erythematosus
CLOVIS A.A. SILVA, JORGE HALLAK, FABIO F. PASQUALOTTO, MÁRIO F. BARBA, MARIA I. SAITO,
and MARIA H.B. KISS
ABSTRACT. Objective. To evaluate gonadal function in male adolescents and young men with juvenile onset sys-
temic lupus erythematosus (SLE).
Methods. Four young men with SLE underwent clinical and laboratory evaluation, testicular ultrasound,
follicle stimulating hormone, luteinizing hormone, prolactin, testosterone, and anti-sperm antibody
determination. The semen analyses were performed according to the WHO guidelines and Kruger strict
criteria. All patients were asked to provide 3 semen samples over a period of 2 months. A new sample
was collected 6 months later.
Results. The median disease duration was 6.6 years. The median age at initial ejaculation was 13.5
years. All 4 patients had severe disease with renal involvement (WHO class IV or V). The SLICC/ACR
damage index at the time of study entry ranged between 0 and 3. The patients’ Tanner stage was P5G5;
all reported normal erection and libido. Gonadal evaluation by thorough examination of the genitalia
and ultrasound was normal. Anti-sperm antibodies were negative in all patients. Only one patient
showed high FSH and LH levels. The initial and final semen evaluations of the 4 patients were abnor-
mal (azoospermia, oligoastenoteratospermia, or teratospermia). One patient was receiving azathioprine
and 2 were receiving cyclophosphamide at the time of study entry.
Conclusion. Although these patients had normal sexual activity and normal external genitalia, their fer-
tility was decreased based on the sperm abnormalities. Serial semen analyses in larger study populations
will be necessary to clarify the degree and duration of sperm abnormalities in male patients with SLE
in general. (J Rheumatol 2002;29:2000–5)
Key Indexing Terms:
LUPUS MALE GONADAL SEMEN HORMONE ADOLESCENT
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