Vasculitis from the Pediatric Perspective
P. A. Brogan, MD and M. J. Dillon, MD
Address
The Institute of Child Health, 30 Guildford Street, London W C1N 1EH,
United Kingdom.
E-mail: m.dillon@ ich.ucl.ac.uk
Current Rheumatology Reports 2000, 2:411–416
Current Science Inc. ISSN 1523–3774
Copyright © 2000 by Current Science Inc.
Introduction
Vasculitis occurs in many different diseases and syndromes
in childhood [1]. It is the predominant manifestation of
the disorder in some; in others, however it may be one
aspect of a more widespread disease [2,3]. A classification
that has been proven useful based on that of Fink [4] is
outlined in Table 1.
Polyarteritis Nodosa, Microscopic
Polyangiopathy, and Cutaneous Polyarteritis
The classic form of polyarteritis, polyarteritis nodosa (PAN),
is a necrotizing vasculitis associated with aneurysmal nod-
ules along the walls of medium-sized muscular arteries [5].
Although there is an overlap with smaller vessel disease, it is
distinct from microscopic polyangiopathy and occurs more
commonly in childhood than this latter disorder [5]. The
main clinical features are malaise, fever, skin rash, abdominal
pain, and arthropathy [5,6]. Other features include testicular
pain, myalgia, hypertension, neuropathy, renal failure,
organic psychosis, and myocardial ischemia [5–7]. Visceral
angio graphy plays a key ro le in the diagno sis [8–10].
Microscopic polyarteritis differs from classic PAN by
the presence of extensive glomerular involvement, and
may be defined as small-vessel vasculitis with focal seg-
mental glomerulonephritis but without granulomatous
disease of the respiratory tract [11]. Clinically, it can be dif-
ficult to distinguish from Wegener’s granulomatosis, and it
often presents with rapidly progressive glomerulonephritis
[12] in association with perinuclear antineutrophil cyto-
plasmic antibody (pANCA) positivity.
Treatment for both macroscopic and microscopic pol-
yarteritis consists of steroids, antiplatelet agents, and an
additional cytotoxic agent (ordinarily cyclophosphamide)
[13•,14]. Cyclophosphamide is usually administered
orally for 2 to 3 months at 2 mg/kg/d to induce remission
[15•]. Pulsed intravenous cyclophosphamide may have
advantages over the oral route in reducing the total cumu-
lative dose and hence side effects, but it may not be as
effective as the daily oral regimen in aggressive disease for
the prevention of relapses [16]. Maintenance therapy is
usually with oral azathioprine at a dose of 2 mg/kg/d, with
low-dose alternate day prednisolone (0.2–0.5 mg/kg), and
antiplatelet agents. If remission with this regimen is not
maintained, then cyclosporin or mycophenolate mofetil
may prove useful, although the published evidence for the
use of these agents in this context is lacking. Currently, the
mortality for polyarteritis nodosa at Great Ormond Street
Hospital, London is about 10%, which compares favorably
with many adult series [5,15•].
Cutaneous polyarteritis is a syndrome associated with
crops of painful skin nodules, livedo reticularis, and often
with a story of preceding upper respiratory tract infection
[17–19]. The condition responds to nonsteroidal anti-
inflammatory drugs but can require steroids. If the condi-
tion is streptococcus induced, prophylactic penicillin has a
role. Cutaneous vasculitis usually runs a benign course,
although in some patients the cutaneous features evolve
into systemic polyarteritis nodosa. Relapses, particularly in
association with recurrent streptococcal infection are seen
in up to 25% of cases. Clinicians seeing this condition usu-
ally advise continuing penicillin prophylaxis throughout
childhood to prevent relapses because it is among the
relapsing group that systemic vasculitis tends to occur.
Kawasaki Disease
This systemic childhood vasculitis was first described by
Tomisaku Kawasaki in Japan in 1967 [20]. More than
116,000 cases have subsequently been reported from that
country alone [21], but the disease is of world-wide distri-
bution and mainly affects infants and young children
This article reviews the spectrum of vasculitic illness affect-
ing children. Apart from the relatively common vasculitides
(H enoch-Schönlein purpura, Kawasaki disease, and in
worldwide terms Takayasu disease) there are a number
of important but comparatively rare disorders affecting
children. As in adults, there is a considerable degree of
overlap between the various vasculitic syndromes in child-
hood. W ith modern therapeutic agents, the prognosis for
many of the childhood vasculitides has improved; however,
in spite of this, there remains a not inconsequential morbid-
ity and mortality. It is anticipated that as our knowledge of
the immunopathogenesis of this group of disorders
expands, classification and treatment of vasculitis in both
children and adults will improve.