INTRODUCTION
Polarity is a fundamental characteristic of most cells and
is essential for their proper function. Cellular polarity has
been intensively investigated, and significant progress has
been made in revealing the mechanisms that underlie the
establishment of cellular polarity. Another widespread, but less
understood, form of polarity is planar polarity (PP), which is
the organization of cells within the plane of the epithelium.
Intensive recent investigations have demonstrated that a
conserved PP pathway works to coordinate the polarity of
adjacent cells in such divergent systems as convergent
extension movements in zebrafish and frogs, and the polarity
of wing hairs in the fly (Axelrod and McNeill, 2002).
Studies primarily in the fly have implicated a Frizzled (Fz)
signaling pathway as being central to the control of PP (Adler
and Lee, 2001). Analysis of clones of fz mutant cells reveals
both cell autonomous and non-autonomous defects in PP.
This has led to the suggestion that Fz, a seven-pass
transmembrane receptor (Adler et al., 1990; Park et al., 1994)
is involved in both the reception of a PP signal and in its
transmission to adjacent cells. Recent work has demonstrated
that Fz is part of an asymmetrically localized signaling
complex, which also contains the signaling protein
Dishevelled and the atypical cadherin, Flamingo (Axelrod,
2001; Das et al., 2002; Strutt et al., 2002; Strutt, 2001; Tree
et al., 2002; Usui et al., 1999). How Fz signaling activity is
controlled is not clear.
A well-studied system for understanding the control of PP
is the fly eye (Wolff and Ready, 1993). The fly eye is composed
of ~800 photoreceptor clusters called ommatidia, each
composed of eight photoreceptors, R1-R8, as well as a number
of accessory cells (Fig. 1A). Ommatidia are organized into
dorsal and ventral fields of mirror-image planar polarity, which
meet at the equator (Fig. 1A,C). PP develops in the eye
imaginal disc shortly after ommatidial preclusters assemble.
Preclusters in the dorsal and ventral fields rotate 90° in
opposite directions away from the equator, producing mirror
image fields. Genetic studies have suggested that fz is
necessary for interpreting and communicating a PP signal that
is thought to emanate from the equator. fz has also been
implicated in controlling R3 cell fate (Zheng et al., 1995).
Intensive work has suggested that photoreceptors R3 and R4
are crucial in directing the rotation of preclusters. In addition
it has been shown that the member of the R3/R4 pair with
higher Notch activity will take on the R4 fate. This decision
directs precluster rotation (Cooper and Bray, 1999; Fanto and
Mlodzik, 1999; Tomlinson and Struhl, 1999).
The atypical cadherins Fat (Ft) and Dachsous (Ds) act
upstream of fz, and may control Fz activity during the
development of PP. Two separate models have been proposed
to explain how Fat and Ds control planar polarity in the eye.
763 Development 130, 763-774
© 2003 The Company of Biologists Ltd
doi:10.1242/dev.00304
Fat is an atypical cadherin that controls both cell growth
and planar polarity. Atrophin is a nuclear co-repressor that
is also essential for planar polarity; however, it is not known
what genes Atrophin controls in planar polarity, or how
Atrophin activity is regulated during the establishment of
planar polarity. We show that Atrophin binds to the
cytoplasmic domain of Fat and that Atrophin mutants
show strong genetic interactions with fat. We find that both
Atrophin and fat clones in the eye have non-autonomous
disruptions in planar polarity that are restricted to the
polar border of clones and that there is rescue of planar
polarity defects on the equatorial border of these clones.
Both fat and Atrophin are required to control four-jointed
expression. In addition our mosaic analysis demonstrates
an enhanced requirement for Atrophin in the R3
photoreceptor. These data lead us to a model in which fat
and Atrophin act twice in the determination of planar
polarity in the eye: first in setting up positional information
through the production of a planar polarity diffusible
signal, and later in R3 fate determination.
Key words: Planar polarity, Adhesion, Drosophila, Eye, Atrophin,
Fat
SUMMARY
The tumor-suppressor and cell adhesion molecule Fat controls planar polarity
via physical interactions with Atrophin, a transcriptional co-repressor
Manolis Fanto
1
, Lesley Clayton
1
, Jamie Meredith
1
, Kirsten Hardiman
1
, Bernard Charroux
2
,
Stephen Kerridge
2
and Helen McNeill
1,
*
1
Cancer Research UK (ICRF), London Research Institute, 44 Lincoln’s Inn Fields, London WC2A 3PX, UK
2
Laboratoire de Génétique et Physiologie du Développement, CNRS-INSERM-Université de la Méditerranée-AP de Marseille,
Campus de Luminy Case 907, F-13288 Marseille, Cedex 09, France
*Author for correspondence (e-mail: helen.mcneill@cancer.org.uk)
Accepted 7 November 2002