Turkiye Klinikleri J Med Sci 2011;31(2) 464
arpenter syndrome or acrocephalopolysyndactyly type II was first
described by Carpenter in 1901, but it was not firmly established as
an entity until Temtamy’s report in 1966.
1
It is a rare autosomal re-
cessive disorder.
1,2
The cardinal features of this syndrome are acrocephaly
with variable synostosis of the sagittal, lambdoid, and coronal sutures; pe-
culiar facies; brachydactyly of hands with syndactyly; preaxial polidactyly
and syndactyly of the feet; congenital heart defects; growth retardation;
mental retardation; hypogenitalism and obesity.
1-5
Besides common clinical
manifestations, cerebral malformations, oral and dental abnormalities, co-
xa valga, genu valgum, hydronephrosis, precocious puberty and hearing loss
may be seen.
1-12
Variable rare abnormalities may also accompany the major
clinical findings.
1
However, to the best of our knowledge, situs inversus to-
talis has not been demonstrated previously in Carpenter syndrome. We re-
port a case of Carpenter syndrome associated with situs inversus totalis.
The Association of Carpenter
Syndrome and Situs Inversus Totalis:
First Case Report
ABSTRACT Carpenter syndrome (acrocephalopolysyndactyly type II) is a rare autosomal recessi-
ve disorder that classically consists of acrocephaly, facial dysmorphism, mental retardation, conge-
nital heart disease and hypogenitalism. To the best of our knowledge, situs inversus totalis has not
been demonstrated previously in Carpenter syndrome. We report here a 6- day- old boy with many
abnormalities diagnosed clinically and also having situs inversus totalis. As far as we know, this is
the first Carpenter syndrome case associated with situs inversus totalis in the literature.
Key Words: Situs inversus; craniosynostoses; mental retardation;
craniofacial abnormalities; syndactyly
ÖZET Carpenter sendromu (akrosefalopolisindaktili tip II) klasik olarak akrosefali, fasial dismor-
fizm, zeka geriliği, doğumsal kalp hastalığı ve hipogenitalizmden oluşan nadir bir otozomal resesif
hastalıktır. Bildiğimiz kadarıyla, Carpenter sendromunda daha once situs inversusu totalis tanım-
lanmamıştır. Burada klinik olarak tanı koyulan pek çok anomalisi olan ve aynı zamanda situs inve-
rus totalisi olan 6 günlük bir erkek bebeği sunuyoruz. Bildiğimiz kadarıyla, bu literatürde situs
inversus totalis ile birlikte görülen ilk Carpenter sendromu olgusudur.
Anahtar Kelimeler: Situs inversus; kranyosinostoz; mental retardasyon;
kafa yüz anormallikleri; sindaktili
Turkiye Klinikleri J Med Sci 2011;31(2):464-7
Hüseyin ALTUNHAN, MD,
a
Ali ANNAGÜR, MD,
a
Rahmi ÖRS, MD
a
a
Division of Neonatology,
Selçuk University
Meram Faculty of Medicine, Konya
Geliş Tarihi/Received: 15.06.2010
Kabul Tarihi/Accepted: 17.12.2010
Yazışma Adresi/Correspondence:
Ali ANNAGÜR, MD
Selçuk University
Meram Faculty of Medicine,
Division of Neonatology, Konya,
TÜRKİYE/TURKEY
aliannagur@yahoo.com
doi:10.5336/medsci.2010-19822
Copyright © 2011 by Türkiye Klinikleri
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