Personal, non-commercial use only. The Journal of Rheumatology. Copyright © 2004. All rights reserved.
The Journal of Rheumatology 2004; 31:3 442
From the Arthritis and Rheumatism Campaign Epidemiology Unit and the
Centre for Integrated Genominc Medical Research, University of
Manchester, Manchester, UK.
Supported by the UK Arthritis Research Campaign.
A. Barton, MRCP, Clinical Lecturer; H. Platt, BSc, Experimental Officer;
F. Salway, MSc, Experimental Officer; D. Symmons, FRCP, Professor of
Rheumatology and Musculoskeletal Epidemiology; M. Lunt, PhD,
Research Fellow; J. Worthington, PhD, Reader in Genetic Epidemiology,
A. Silman, FRCP, Professor of Rheumatic Disease Epidemiology.
Address reprint requests to Dr. ABarton, ARC-EU, Stopford Building,
University of Manchester, UK. E-mail: ABarton@fs1.ser.man.ac.uk
Submitted March 24, 2003; revision accepted September 26, 2003.
Twin studies suggest a substantial genetic contribution to
rheumatoid arthritis (RA) susceptibility and family studies
have shown that first-degree relatives of patients with RA
are at increased risk
1
. However, the increased risk in
probands recruited from a community based setting is
modest compared with hospital-recruited patients
2
. As
hospital-based patients are likely to have more severe
disease, this suggests that genetic factors may play a greater
role in determining disease severity and outcome.
Mannose binding lectin (MBL) is involved in the innate
immune system and it has been suggested that impairment
of innate immunity as a result of MBL deficiency may lead
to increased presentation of antigens to the host, a reduction
in self-tolerance, and susceptibility to autoimmunity
3
. There
are a number of single nucleotide polymorphisms (SNP) of
the MBL gene (MBL) and haplotypes have been defined,
some of which encode high and others low levels of MBL
protein production. The wild type MBL allele is referred to
as A. Structural polymorphisms exist at 3 positions: in
codon 52*C/T, codon 54*G/A and codon 57*G/A, and the
presence of such a variant allele at any of these sites is
referred to as O. MBL protein levels are higher in individ-
uals with an A/A than A/O genotype and MBL levels are
virtually undetectable in individuals with O/O genotype. In
addition, 2 promoter variants exist: the MBL-550*C/G
(H/L) SNP, which has little effect on levels, and the MBL-
221*G/C (Y/X) SNP, which has a profound lowering effect
when 2 copies are present.
Studies have reported association of MBL polymor-
phisms with susceptibility to RA but the results have been
conflicting
4-11
. The variation in these reports may result
from differences in the patient cohorts investigated, particu-
larly if MBL polymorphisms are more important in deter-
mining disease severity rather than susceptibility. Several
studies have therefore attempted to address this issue and
have reported association of MBL polymorphisms,
including haplotypes known to encode low MBL protein
production, with development of erosions in RA
6,7,9,10
.
Furthermore, studies have also investigated MBL protein
levels with outcome in RA
6,7,9,11,12
, including 2 prospective
studies of RA patients in which low MBL protein levels
were associated with development of erosions
9,12
.
Polymorphisms in the Mannose Binding Lectin (MBL)
Gene Are Not Associated with Radiographic Erosions
in Rheumatoid or Inflammatory Polyarthritis
ANNE BARTON, HAZEL PLATT, FIONA SALWAY, DEBORAH SYMMONS, MARK LUNT, JANE WORTHINGTON,
and ALAN SILMAN
ABSTRACT. Objective. To investigate the association between the mannose binding lectin gene (MBL) promoter
and structural single nucleotide polymorphisms (SNP) with development of erosions in a primary
care inception cohort of patients with inflammatory polyarthritis (IP).
Methods. DNA was available from 438 patients with IP and radiographic data were available for all
patients at 5 years. Four SNP [MBL-550*C/G (H/L), MBL-221*G/C (Y/X), MBL codon 52*C/T, and
MBL codon 54*G/A] mapping to the MBL gene were genotyped using primer extension techniques.
Allele frequencies were compared between IP cases with erosions by 5 years and those without.
Results. None of the SNP were associated with erosive outcomes by 5 years. Furthermore there was
no association with Larsen score by 1 or 5 years or with the change in Larsen score between 1 and
5 years. Similarly, the genotype combinations known to encode for low MBL protein production
were not associated with erosive outcome in the IP cohort as a whole or in those with rheumatoid
arthritis (RA) by 5 years.
Conclusion. Polymorphism within the MBL gene is not associated with presence or extent of
erosions by 5 years in patients with RA or IP. (J Rheumatol 2004;31:442–7)
Key Indexing Terms:
MBL RHEUMATOID ARTHRITIS GENETICS
INFLAMMATORY ARTHRITIS EROSIONS
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