International Journal of Research in Medical Sciences | April 2017 | Vol 5 | Issue 4 Page 1388
International Journal of Research in Medical Sciences
Ali FT et al. Int J Res Med Sci. 2017 Apr;5(4):1388-1395
www.msjonline.org pISSN 2320-6071 | eISSN 2320-6012
Original Research Article
The spectrum of MEFV gene mutations and genotype-phenotype
correlation in Egyptian patients with familial Mediterranean fever
Fahmy T. Ali
1
, Mostafa M. Elhady
1
*, Hanan H. Abbas
1
, AbdAllah Y. Mandouh
2
INTRODUCTION
Familial Mediterranean fever (FMF) is the most
widespread and best-characterized monogenic Auto-
inflammatory disease, affecting mainly ethnic groups
originating in or around the Mediterranean basin. This
disease is characterized by irregular, self-limited febrile
episodes of inflammation of serous membranes and
marked elevation of acute-phase proteins. Amyloidosis,
the most significant complication of FMF, is the major
cause of serious long-term morbidity and mortality.
1
Its first definition as a disease was based on a case report,
published under the title “benign paroxysmal peritonitis”
by the allergy specialist Siegel from New York, as a
compilation of Jewish patients with similar complaints.
In 1992, it was reported that the abnormality associated
with FMF is found on chromosome 16, and the gene
responsible for the disease was identified in 1997. The
disease is accompanied by a marked decrease in quality
of life due to the effects of attacks and subclinical
inflammation in the period between attacks.
2
ABSTRACT
Background: Familial Mediterranean fever (FMF) is an autosomal recessive disease mainly affecting subjects of the
Mediterranean origin. It is an auto-inflammatory periodic disorder that is caused by mutations in the Mediterranean
fever gene (MEFV) located on chromosome 16.
Methods: The current study was designed to assess the prevalence and frequency of different MEFV gene mutations
among 104 FMF clinically diagnosed Egyptian patients and to evaluate the change extent in the values of some
biochemical markers (ESR, CRP, Fibrinogen-C, SAA and IL1) in different participants with different FMF severity
scores.
Results: According to allele status 28 patients (27%) were homozygous mutation carriers, 38 (36.5%) were with
compound heterozygous mutations and 38 (36.5%) were identified as heterozygous for one of the studied mutations.
Of the studied mutations, M694I, E148Q, V726A, M680I, and M694V accounted for 28.1%, 26.8%, 16.9%, and
11.3% of mutations respectively. The R761H and P369S mutations were rarely encountered mutations (1.4%). The
clinical features with M694I were associated with more severe clinical course. There is a drastic elevation in the
levels of estimated parameters as their levels were increased as long as the severity of the disease increased.
Conclusions: The diagnosis of FMF cannot be performed on the basis of genetic testing or clinical criteria alone. So,
we recommended the combination between clinical and molecular profiling for FMF diagnosis and scoring.
Keywords: Allele frequency, ASO-PCR, Egyptian population, FMF, MEFV gene
1
Department of Biochemistry, Faculty of Science, Ain Shams University, Egypt
2
Department of Molecular Biology and Cytogenetic, Armed Forces Central Laboratories and Blood Bank, Egypt
Received: 25 December 2016
Accepted: 02 February 2017
*Correspondence:
Dr. Mostafa M. Elhady,
E-mail: m_elhady@sci.asu.edu.eg
Copyright: © the author(s), publisher and licensee Medip Academy. This is an open-access article distributed under
the terms of the Creative Commons Attribution Non-Commercial License, which permits unrestricted non-commercial
use, distribution, and reproduction in any medium, provided the original work is properly cited.
DOI: http://dx.doi.org/10.18203/2320-6012.ijrms20171233