Paraneoplastic and Idiopathic Ganglionopathy: Importance of Differential
Diagnosis
Guilherme Perassa Gasque
*
, Felipe da Rocha Schmidt, Diogo Matheus Terrana de Carvalho, Salim Balassiano, José Marcelo Ferreira Bezerra and Marcia
Rodrigues Jardim
Department of Neurology, Pedro Ernesto University Hospital, State University of Rio de Janeiro (UERJ), Rio de Janeiro, RJ, Brazil
*Corresponding author: Guilherme Perassa Gasque, Department of Neurology, Pedro Ernesto University Hospital, State University of Rio de Janeiro (UERJ), Rio de
Janeiro, RJ, Brazil, Tel: +552123340639; E-mail: guigasque_4@hotmail.com
Received date: Nov 10, 2015; Accepted date: Dec 11, 2015; Published date: Dec 18, 2015
Copyright: ©2015 Gasque GP, et al. This is an open-access article distributed under the terms of the Creative Commons Attribution License, which permits unrestricted
use, distribution, and reproduction in any medium, provided the original author and source are credited.
Abstract
Sensory ganglionopathies (SG) may occur in association with different diseases and are characterized by the
degeneration of the primary sensory neurons located in the dorsal root ganglia. The most important associated
conditions are paraneoplastic SG, HIV infection, Sjogren's syndrome, and cisplatin or pyridoxine toxicity. Even when
clinical criteria help differentiate SG from other neuropathies, an etiological diagnosis remains elusive. Thus, there is
a need to identify biological markers than can distinguish immune-mediated SG from other etiologies. Objectives:
The present study of two cases of SG compares their neurological outcomes with their treatment responses in
accordance with the etiology of each one. Methods: evaluate the clinical presentation and examination results to be
able to define the etiology and institute early treatment. Results: To differentiate paraneoplastic and idiopathic
causes, more precise imaging techniques and paraneoplastic antibody tests are required. These diagnostic tools
might be helpful in early diagnosis and treatment, thus affording the best chance of stabilizing the neurological
symptoms. Conclusions: The identification of paraneoplastic antibodies before the onset of cancer can reduce the
percentage of cases misdiagnosed as idiopathic, leading to early treatment and perhaps a more favorable
prognosis.
Keywords: Multiple sclerosis; Cognitive impairment; Tunisia
Introduction
Sensory ganglionopathies (SG), characterized by the degeneration
of the primary sensory neurons located in the dorsal root ganglia, may
occur in association with diferent diseases [1]. Te most important
associated conditions are paraneoplastic SG, HIV infection, Sjogren's
syndrome, and cisplatin or pyridoxine toxicity [2]. Half of all cases are
still labeled idiopathic. Te sensory defcits are usually multifocal,
involving the proximal and distal parts of the limbs; and all sensory
modalities - pain, temperature, sense position, and vibration - may be
compromised during the course of the disease [1,3]. Gait ataxia and
widespread arrefexia ofen occur [1,3,4]. Some patients have
pseudoathetotic hand movements. Injury to small and medium-sized
neurons can generate pain, a burning sensation, and allodynia [1,3,4]
while the motor system examination is usually unremarkable.
Nystagmus is not frequent, but autonomic dysfunction may be found.
Tere have been reports of tonic pupils, orthostatic hypotension,
gastrointestinal symptoms, and erectile dysfunction.
Nerve conduction studies are the most useful tests in evaluating SG
[3,5]. Te distinguishing characteristics between SG and other sensory
neuropathies are important to properly focus the etiological
investigation and the adoption of appropriate treatment [2]. However,
the diagnosis of SG is ofen challenging for the practicing neurologist.
Furthermore, there is evidence that, in some cases, the dorsal root
ganglia and peripheral nerves can be afected simultaneously such as in
Sjögren's syndrome [6]. Tus, reliable diagnostic criteria for SG are
urgently needed as a backdrop in clinical practice [6]. Even when
clinical criteria aid in diferentiating SG from other neuropathies, an
etiological diagnosis remains elusive. Tus, there is a need for
biological markers than can distinguish immune-mediated SG from
other etiologies [7].
Other tests, such as screening for occult tumors and searching for
paraneoplastic antibodies are essential for the establishment of an
etiological diagnosis since paraneoplastic SG may precede the tumor
within fve years of diagnosis [8].
Te present study examines two cases of SG by comparing and
highlighting the importance of the clinical presentation and laboratory
results mainly from the perspective of the presence of paraneoplastic
antibodies in the management of patients.
Case Report
Case 1
A 49y, single, mixed-race female and small business owner and
resident of Rio de Janeiro was admitted to the Pedro Ernesto
University Hospital in Rio de Janeiro, Brazil, due to hand paresthesias
and cooking difculties that, within a month, evolved into involuntary
movements of the hands and numbness in the forearms and feet. He
smoked a pack a day for 20 years and drank alcohol regularly. She was
then taking 25 mg/day amitriptyline. Te physical examination showed
the patient to be in generally good health and pale 1+/4+. Te
neurological examination showed sensory ataxic gait and a Romberg
sign, along with widespread arefexia, dysmetria, and
dysdiadocokinesia in the upper limbs (UL) that worsened with eye
closure, bilateral fexor plantar responses, tactile hypoesthesia, painful
asymmetric and multifocal, apalesthesia, and loss of proprioception
distal limbs and pseudoathetosis movements in the hands. He also
Gasque GP, et al., J Neurol Neurophysiol 2015, 6:6
DOI: 10.4172/2155-9562.1000339
Case Report Open Access
J Neurol Neurophysiol
ISSN:2155-9562 JNN, an open access journal
Volume 6 • Issue 6 • 339
Journal of Neurology & Neurophysiology
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