Microcystic Lymphatic Malformation: A Case Report
Yousif I Eltohami, Nour E Alim and Amal H Abuaffan
*
University of Khartoum, Al-Gamaa Ave, Khartoum 11111, Sudan
*
Corresponding author: Amal H Abuaffan, University of Khartoum, Faculty of dentistry, Sudan, Tel: +249917481188; E-mail: amalabuafan@yahoo.com
Received date: Feburary 20, 2017; Accepted date: March 06, 2017; Published date: March 13, 2017
Copyright: © 2017 Eltohami YI, et al. This is an open-access article distributed under the terms of the Creative Commons Attribution License, which permits unrestricted
use, distribution, and reproduction in any medium, provided the original author and source are credited.
Abstract
Lymphatic malformations appear in different parts of the body, but when it rises cervico-facially it would probably
be in the oral cavity, it is uncommon in adult, usually appear in infancy and early childhood. This is a case report of
lingual lymphatic malformation in a 32 years old Sudanese male treated with hot saline and intra lesion steroids.
Keywords: Lymphatic malformation; Lymphangioma; Tongue,
Adult; Hot saline; Ttriamcinolone acetnoide
Introduction
Lymphatic malformations are a congenital malformed lymphatic
vessels [1]. It is divided into; the macro cystic type, cysts more than 2
cm with clear margins, the microcystic type, consisting of cysts less
than 2 cm, which has difuse ill defned margins and the combined
type include. Micro cystic type usually found in the oral cavity, throat,
the tongue, sub-mandibular gland and parotid gland. It can cause
macroglossia, difculty in breathing and eating [2].
Most of the cases diagnosed directly afer delivery, and 90% are
developed before the age of two years [3]. Tey can appear at many
sites but the majority in the head and neck 75% of which occur in the
oral cavity, followed by the oropharynx and the parapharyngeal space
[4]. Intraoral, frequently found in the tongue, lips, mucosa buccally,
mouth foor and sof palate [5]. Lymphatic malformation appear as a
sof tissue tumor that grow slowly with no pain, that depends on the
lesion extension. Te outer ones appear as pebbly irregular surface
with pinkish color though it can be reddish or slight purple if
hemorrhages secondarily occur [6], while the deeper ones appear as
sof, difuse lesions with normal color [5].
Treatment of the lymphatic malformations ranged from surgery,
radio-therapy, sclerotherapy cryotherapy, steroid injection,
electrocautery, embolization, ligation, and laser surgery [7]. Tis is a
case report of lymphatic malformation of the tongue managed by intra
lesional steroid injection and hot saline.
Case Scenario
A 32 years old Sudanese male came to the private dental clinic
complaining from painless difuse frm tongue swelling. Te lesion
appeared shortly afer birth and increased gradually in size. Te past
medical history, the patient generally ft, without a history of habits
consumption. Clinical examination, non tender difuse frm tongue
swelling with rough pebbly telangiectatic surface with salmon egg
appearance. Tere were no hotness, thrills or bruits and no bloody
discharge (Figures 1 and 2). Incision biopsy result revealed classic
histopathological features of lymphatic malformation with scatter
endothelial cells. Treatment, hot normal saline and intra lesional
steroid (triamicelone acetnoid 40 mg) was prescribed one injection
weekly for 10 weeks.
Figure 1: Shows difuse tongue swelling with rough pebbly surface
and salmon eggs appearance.
Figure 2: Shows difuse frm swelling of the ventrum of the tongue
with telangiectatic pebbly surface.
Dentistry
Eltohami et al., Dentistry 2017, 7:3
DOI: 10.4172/2161-1122.1000416
Case Report OMICS International
Dentistry, an open access journal
ISSN:2161-1122
Volume 7 • Issue 3 • 1000416