Personal, non-commercial use only. The Journal of Rheumatology. Copyright © 2004. All rights reserved.
Gilworth, et al: Quality of life and BD 931
From the Academic Unit of Musculoskeletal and Rehabilitation Medicine,
University of Leeds, Leeds; Hammersmith Hospital, London; and the
Arthritis and Rheumatism Council Epidemiology Research Unit,
Manchester Medical School, Manchester, United Kingdom.
Supported by the UK Arthritis Research Campaign (ARC).
G. Gilworth, MPhil, Senior Research Fellow; M.A. Chamberlain, FRCP,
Charterhouse Professor in Rehabilitation Medicine; B. Bhakta, FRCP,
Senior Lecturer in Rehabilitation Medicine; A. Tennant, PhD, Professor
of Rehabilitation Studies, Academic Unit of Musculoskeletal and
Rehabilitation Medicine, University of Leeds; D.O. Haskard, DM, Sir
John McMichael Professor of Cardiovascular Medicine and Honorary
Consultant Rheumatologist, Hammersmith Hospital; A. Silman, FRCP,
Professor of Rheumatic Disease Epidemiology, Arthritis and Rheumatism
Council Epidemiology Research Unit, Manchester Medical School.
Address reprint requests to Mrs. G. Gilworth, Academic Unit of
Musculoskeletal and Rehabilitation Medicine, University of Leeds, 36
Clarendon Road, Leeds LS2 9NZ, UK. E-mail: gilworths@aol.com
Submitted January 23, 2003; revision accepted October 21, 2003.
Behçet’s disease (BD) is a chronic multisystem disorder
characterized by vasculitis affecting small to medium size
blood vessels. Although the commonest symptoms of BD
relate to mucosal ulceration it can affect virtually every
organ system, causing a variety of clinical problems such as
arthritis, neurological impairments, pulmonary artery
aneurysm, and gastrointestinal symptoms. The commonest
severe manifestation is uveitis, which occurs in as many as
70% of patients. There is no uniformly accepted laboratory
test for diagnosis, and therefore classifying people as having
BD depends on the presence of internationally agreed
criteria
1
based on clinical features.
The complex pattern of signs and symptoms in BD can
lead to a variety of activity limitations (disability) and
restriction in participation in many areas of life (handicap).
A dilemma thus exists of the choice of outcome measure(s)
most likely to identify change as a consequence of clinical
intervention. To date the measurement of outcome in BD
has mainly focused on impairments. The absence of labora-
tory markers that correlated well with impairment led to the
development of a standardized proforma (the BD Current
Activity Form) to assess disease activity that is based on
history of specific clinical features
2
. This is an impairment-
based outcome measure useful in monitoring therapy.
However, it takes no account of the wider impact of the
condition on the individual’s lifestyle.
Generic outcome measures of health status such as the
Nottingham Health Profile (NHP)
3
and the Medical
Outcomes Study Short-Form 36 (SF-36)
4
can appear attrac-
tive as tools for measuring the influence of disease because
they often measure several domains and allow for compar-
isons between different conditions. However, condition-
specific measures have been shown to be more sensitive to
change
5
. Health utility measures, such as the EUROQoL,
tend to be even more restricted, as they include only a few
items concerning impairments and activity limitation and
Development of the BD-QoL: A Quality of Life
Measure Specific to Behçet’s Disease
GILL GILWORTH, M. ANNE CHAMBERLAIN, BIPIN BHAKTA, DORIAN HASKARD, ALAN SILMAN,
and ALAN TENNANT
ABSTRACT. Objective. Current outcome measures for patients with Behçet’s disease (BD) are impairment-
focused and do not necessarily take account of the wider impact of the condition on the individual’s
lifestyle. Our aim was to develop a disease-specific measure of quality of life (QoL) for BD.
Methods. The content of the BD-QoL was derived from qualitative interviews with patients using a
“needs-based” approach to identify items. A postal survey was used to test the scaling properties,
reliability, internal consistency, and validity of the new questionnaire using Rasch analysis. A second
postal survey was used to assess test-retest reliability and internal consistency and to provide further
evidence of the validity of the questionnaire.
Results. Main themes emerging from the qualitative interviews included relationships, emotions,
limitations in day to day activities, and self-image. From these themes 71 statements were chosen as
potential items for the BD-QoL. After analysis, 30 items of the BD-QoL emerged free of item bias
for age and sex. Fit to the Rasch model was excellent. In the second postal survey test-retest relia-
bility of the 30 item BD-QoL was 0.84.
Conclusion. The BD-QoL provides the clinician with a simple, reliable, and valid tool for assessing
the influence of interventions for BD and for evaluating models of service delivery. It is well
accepted by patients, and has excellent scaling and psychometric properties. The BD-QoL comple-
ments information obtained through BD-specific disease activity scales. (J Rheumatol
2004;31:931–7)
Key Indexing Terms:
BEHÇET’S DISEASE OUTCOME QUALITY OF LIFE QUESTIONNAIRE
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