166 Current Pediatric Reviews, 2012, 8, 166-178
1573-7829/12 $58.00+.00 © 2012 Bentham Science Publishers
Long-Term Survivors of Cancer in Childhood and Adolescence
Stacey L. Urbach
1
, Sharon Guger
2
and Paul C. Nathan
*,3
Divisions of Endocrinology
1
and Hematology/Oncology
3
, Department of Pediatrics, Department of Psychology
2
, The
Hospital for Sick Children, 555 University Avenue, Toronto, ON M5G 1X8, Canada
Abstract: Significant improvements in the treatment of many pediatric malignancies have led to a growing population of
long-term survivors of childhood cancer. Many of these survivors are at significant risk for late physical and psychosocial
sequelae (“late effects”) as a result of their prior disease and its therapy. In some survivors (such as children treated for a
brain tumor), late effects including endocrine dysfunction and neurocognitive challenges can develop during therapy and
persist throughout life. In others (such as children and adolescents treated for Hodgkin’s lymphoma), late effects including
congestive heart failure, pulmonary fibrosis and secondary breast cancers may not occur for many years, often once
survivors have reached adulthood. During childhood, survivor care usually occurs at the pediatric cancer center, often in a
specialized long-term follow-up clinic. However, adult survivors are usually cared for by primary care practitioners in
their own communities. It is essential that the health care providers who will care for childhood cancer survivors as they
age be aware of each survivor’s treatment exposures, long-term risks, and the surveillance strategies suggested for
monitoring for these late effects. Strategies for effective transition from pediatric care and for ongoing communication
between primary care practitioners and pediatric cancer centers need to be implemented to ensure that childhood cancer
survivors receive appropriate care focused on their specific risks throughout their lifespan.
Keywords: Childhood cancer, late effects, endocrine and neurocognitive dysfunction.
INTRODUCTION
The evolution of therapy for childhood cancer represents
one of the major medical successes of the past half century.
Whereas only 10% of children diagnosed with cancer in the
1950s became long term survivors [1], over 80% of children
diagnosed today will survive their disease [2]. For acute
lymphoblastic leukemia, the most prevalent pediatric malig-
nancy, survival rates have risen from 60% in the 1970s to
almost 90% today [3]. Improved survival of childhood
cancer has been achieved by better stratification of therapy
(offering more intensive therapy to those children at higher
risk of relapse while decreasing toxic therapies in those
children at lower risk), improvements in supportive care that
allow for the delivery of intensive multi-modal therapies and
more recently, by the introduction of novel therapies such as
hematopoietic stem cell transplantation and molecularly
targeted agents [4, 5]. As a consequence of improved survi-
val, the population of survivors of childhood cancer is
growing steadily. In 2005, there were over 325,000 survivors
of childhood cancer alive in the United States (US) [6].
Although one quarter of these had survived 30 or more years
from their original cancer diagnosis, many were still in their
pediatric or adolescent years. When compared to diagnoses
of cancer during adulthood, childhood cancer is relatively
uncommon. Of the estimated 1,529,560 new cases of cancer
that will be diagnosed in the US in 2010, only 10,700 (0.7%)
will occur in children aged 0 to 14 years [7]. However, since
children who survive their cancer have the potential for
many future years of life, childhood cancers (as a group)
impact more person-years than all adult malignancies except
breast and lung cancer [8].
*Address correspondence to this author at the Divisions of
Hematology/Oncology, The Hospital for Sick Children, 555 University
Avenue, Toronto, ON M5G 1X8, Canada; Tel: 416-813-8795; Fax: 416-
813-5327; E-mail: paul.nathan@sickkids.ca
Unfortunately, cure of cancer during childhood fre-
quently comes at a cost to the patient. In addition to the acute
(usually reversible) side effects of therapy (e.g. alopecia,
nausea and vomiting, immune suppression), survivors are at
risk for chronic sequelae of therapy that may develop during
treatment (“long-term effects”) or months to years after the
conclusion of therapy (“late effects”). Cytotoxic chemo-
therapy agents, radiation therapy, surgery and the local effect
of the tumor are all associated with chronic morbidities in
childhood cancer survivors. The Childhood Cancer Survivor
Study (CCSS), a longitudinal cohort study of over 10,000
adult survivors of childhood cancer treated between 1970
and 1986, revealed that 62% of survivors had developed one
or more chronic physical health conditions, and that 28% had
developed a severe or life threatening condition [9]. When
compared to their siblings, survivors were more than three
times as likely to have developed a chronic health condition.
Childhood cancer survivors diagnosed and treated more
recently appear to be at similar risk for chronic morbidity
[10], although an understanding of long-term outcomes in
children treated in the current era will require further follow-
up. The more common physical sequelae of cancer and its
therapy include endocrine, cardiac, neurologic, renal and
pulmonary dysfunction (Table 1) [10]. In addition to an
increased risk of morbidity, childhood cancer survivors are
at increased risk for early mortality. Among survivors who
have lived for five or more years after their cancer diagnosis,
there is a nine-fold increased risk of early mortality com-
pared to their peers. This elevated risk does not diminish
over time [11]. Although death from recurrence or progres-
sion of the original cancer is the leading cause of early
mortality in 5-year cancer survivors, this population is also at
increased risk of death from treatment-related causes such as
new neoplasms, cardiac and pulmonary disease [12]. The
impact of specific therapies is modified by patient factors
(e.g. age at treatment, gender) and lifestyle factors (e.g.