https://doi.org/10.1177/1352458519868990
https://doi.org/10.1177/1352458519868990
MULTIPLE
SCLEROSIS MSJ
JOURNAL
journals.sagepub.com/home/msj 1
Multiple Sclerosis Journal
1–12
DOI: 10.1177/
1352458519868990
© The Author(s), 2019.
Article reuse guidelines:
sagepub.com/journals-
permissions
Introduction
Previous efforts to identify prognostic markers of sec-
ondary progressive multiple sclerosis (SPMS) have
used large natural history cohorts, limited to certain
geographic location and composed of mostly untreated
patients. As a result, they do not take into considera-
tion the impact that disease-modifying therapy (DMT)
has on delaying SPMS.
1
Furthermore, the compara-
bility of these studies is hampered by the use of vary-
ing methodologies and outcomes, including different
Risk of secondary progressive multiple
sclerosis: A longitudinal study
Adam Fambiatos, Vilija Jokubaitis, Dana Horakova, Eva Kubala Havrdova,
Maria Trojano, Alexandre Prat, Marc Girard, Pierre Duquette, Alessandra Lugaresi,
Guillermo Izquierdo, Francois Grand’Maison, Pierre Grammond, Patrizia Sola,
Diana Ferraro, Raed Alroughani , Murat Terzi, Raymond Hupperts, Cavit Boz,
Jeannette Lechner-Scott, Eugenio Pucci, Roberto Bergamaschi, Vincent Van Pesch,
Serkan Ozakbas, Franco Granella, Recai Turkoglu, Gerardo Iuliano, Daniele Spitaleri,
Pamela McCombe, Claudio Solaro, Mark Slee, Radek Ampapa, Aysun Soysal,
Thor Petersen, Jose Luis Sanchez-Menoyo, Freek Verheul, Julie Prevost, Youssef Sidhom,
Bart Van Wijmeersch, Steve Vucic, Edgardo Cristiano, Maria Laura Saladino, Norma Deri,
Michael Barnett, Javier Olascoaga, Fraser Moore, Olga Skibina, Orla Gray, Yara Fragoso ,
Bassem Yamout, Cameron Shaw, Bhim Singhal, Neil Shuey, Suzanne Hodgkinson, Ayse Altintas,
Talal Al-Harbi, Tunde Csepany, Bruce Taylor, Jordana Hughes, Jae-Kwan Jun,
Anneke van der Walt , Tim Spelman, Helmut Butzkueven and Tomas Kalincik
on behalf of the MSBase Study Group*
Abstract
Background: The risk factors for conversion from relapsing-remitting to secondary progressive multiple
sclerosis remain highly contested.
Objective: The aim of this study was to determine the demographic, clinical and paraclinical features that
influence the risk of conversion to secondary progressive multiple sclerosis.
Methods: Patients with adult-onset relapsing–remitting multiple sclerosis and at least four recorded dis-
ability scores were selected from MSBase, a global observational cohort. The risk of conversion to objec-
tively defined secondary progressive multiple sclerosis was evaluated at multiple time points per patient
using multivariable marginal Cox regression models. Sensitivity analyses were performed.
Results: A total of 15,717 patients were included in the primary analysis. Older age (hazard ratio
(HR) = 1.02, p < 0.001), longer disease duration (HR = 1.01, p = 0.038), a higher Expanded Disability Sta-
tus Scale score (HR = 1.30, p < 0.001), more rapid disability trajectory (HR = 2.82, p < 0.001) and greater
number of relapses in the previous year (HR = 1.07, p = 0.010) were independently associated with an
increased risk of secondary progressive multiple sclerosis. Improving disability (HR = 0.62, p = 0.039)
and disease-modifying therapy exposure (HR = 0.71, p = 0.007) were associated with a lower risk. Recent
cerebral magnetic resonance imaging activity, evidence of spinal cord lesions and oligoclonal bands in the
cerebrospinal fluid were not associated with the risk of conversion.
Conclusion: Risk of secondary progressive multiple sclerosis increases with age, duration of illness and
worsening disability and decreases with improving disability. Therapy may delay the onset of secondary
progression.
Keywords: SPMS, multiple sclerosis, disease modifying therapies, prediction, prognostics
Date received: 6 February 2019; revised: 6 May 2019; accepted: 12 June 2019.
Correspondence to:
T Kalincik
L4 Centre, Melbourne Brain
Centre at Royal Melbourne
Hospital, Grattan Street,
Parkville, VIC 3050,
Australia.
tomas.kalincik@unimelb.
edu.au
Adam Fambiatos
Jordana Hughes
Jae-Kwan Jun
CORe, Department of
Medicine, The University of
Melbourne, Melbourne, VIC,
Australia
Vilija Jokubaitis
Anneke van der Walt
Central Clinical School,
Monash University,
Melbourne, VIC, Australia
The Alfred, Melbourne, VIC,
Australia
Dana Horakova
Eva Kubala Havrdova
Department of Neurology
and Center of Clinical
Neuroscience, General
University Hospital and
Charles University in Prague,
Prague, Czech Republic
Maria Trojano
Department of Basic Medical
Sciences, Neuroscience and
Sense Organs, University of
Bari, Bari, Italy
Alexandre Prat
Marc Girard
Pierre Duquette
Hopital Notre-Dame,
Montreal, QC, Canada/
CHUM and Universite de
Montreal, Montreal, QC,
Canada
868990MSJ 0 0 10.1177/1352458519868990Multiple Sclerosis JournalA Fambiatos, V Jokubaitis
research-article2019 2019
Original Research Paper