Short Communication
Detection of HEY1-NCOA2 fusion by fluorescence in-situ
hybridization in formalin-fixed paraffin-embedded tissues as a
possible diagnostic tool for mesenchymal chondrosarcoma
Robert Nakayama,
1
Yasuhiro Miura,
2
Jiro Ogino,
2
Michiro Susa,
1
Itsuo Watanabe,
1
Keisuke Horiuchi,
1
Ukei Anazawa,
3
Yoshiaki Toyama,
1
Hideo Morioka,
1
Makio Mukai
4
and Tadashi Hasegawa
2
1
Department of Orthopaedic Surgery, Keio University School of Medicine, Tokyo, Japan,
2
Department of Surgical
Pathology, Sapporo Medical University School of Medicine, Sapporo, Japan,
3
Department of Orthopaedic Surgery,
Tokyo Dental College Ichikawa General Hospital, Ichikawa, Japan, and
4
Division of Diagnostic Pathology, Keio
University School of Medicine, Tokyo, Japan.
Mesenchymal chondrosarcoma (MC) is an extremely rare
subtype of chondrosarcoma. A tumor specific fusion gene,
HEY1-NCOA2 fusion, was recently identified in this tumor.
The finding raises the possibility that the diagnosis of MC
can be improved by examining the fusion gene. In the
present study, we aimed to evaluate the efficacy of fluores-
cence in situ hybridization (FISH) in detecting HEY1-NCOA2
fusion for the diagnosis of MC. Specimens from 10 patients
diagnosed with MC were used for the study. Dual-color FISH
was performed using two different probes that specifically
hybridize to HEY1 and NCOA2, respectively. Fusion signals
were identified in all but two specimens, in which no signal
was detected, presumably because of inadequate sample
preparation. In accordance with results of a previous study,
FISH analysis was highly sensitive in detecting HEY1-
NCOA2 fusion in adequately prepared MC samples. The
current study adds further support for the use of HEY1-
NCOA2 fusion as a valid diagnostic marker for MC.
Key words: fluorescence in situ hybridization, fusion gene,
mesenchymal chondrosarcoma
Mesenchymal chondrosarcoma (MC) is an extremely rare
subtype of chondrosarcoma, comprising less than 10% of all
chondrosarcoma cases (7.2% in the Bone and Soft Tissue
Tumor Registry at Keio University Hospital, Tokyo, Japan).
1–3
It commonly affects young adults
1,4,5
and arises not only in
the bone,
6–8
but also at a wide variety of sites including the
soft tissue, central nervous system and meninges.
9–11
Histo-
logically, it is characterized by a bimorphic pattern composed
of highly undifferentiated small round cells (Ewing sarcoma-
like area) and islands of well-differentiated hyaline cartilage
(chondroid area) (Fig. 1).
1,8
Histological diagnosis of MC
can be challenging since the proportion of these two compo-
nents vary widely among cases and, therefore, chondroid
matrix formation is often inconspicuous under microscopic
analysis.
12–16
Recently, a chimera gene, HEY1-NCOA2
fusion, was identified by a genome-wide bioinformatic screen
in MC.
17
HEY1 and NCOA2 are located on 8q21and 8q13,
respectively, spanning approximately 10 Mb from one
another. The chimeric transcript, HEY1-NCOA2, is derived
from a chromosomal deletion between exon 4 of HEY1 and
exon 13 of NCOA2. The resulting fusion gene gives rise to a
chimeric protein bearing the DNA-binding domain of HEY1
and the C-terminal transcriptional activation domains of
NCOA2.
17
This finding is expected to improve pathological
diagnosis and to facilitate further investigation of the patho-
genesis of this tumor. In this study, 10 paraffin-embedded
samples were analyzed to evaluate the efficacy of fluores-
cence in situ hybridization (FISH) in detecting HEY1-NCOA2
fusion for the diagnosis of MC.
MATERIALS AND METHODS
Case selection
A search of our database for the period from 1995 to 2012
yielded 10 cases which had been diagnosed with MC
(Table 1). Each tumor specimen was histologically reviewed
Correspondence: Tadashi Hasegawa, Md, PhD, Department of Sur-
gical Pathology, Sapporo Medical University School of Medicine,
South 1, West 16, Chuo-ku, Sapporo 060-8543, Japan. Email:
hasetada@sapmed.ac.jp
Received 3 September 2012. Accepted for publication 23
November 2012.
© 2012 The Authors
Pathology International © 2012 Japanese Society of Pathology and
Wiley Publishing Asia Pty Ltd
Pathology International 2012; 62: 823–826 doi:10.1111/pin.12022