haematologica vol. 87(12):december 2002
Background and Objectives. This multinational retrospective
study compares the outcomes of patients with primary medi-
astinal large B-cell lymphoma (PMLBCL) with sclerosis after
first-generation (dose-intensive regimens), third-generation
(alternating regimens) and high-dose chemotherapy strate-
gies, frequently with adjuvant radiation therapy.
Design and Methods. Between August 1981 and December
1999, a total of 426 previously untreated patients with con-
firmed diagnosis were enrolled in 20 institutions to receive
combination chemotherapy with either first generation
(CHOP or CHOP-like) regimens, third generation (MACOP-
B, VACOP-B, ProMACE CytaBOM) regimens or high-dose
chemotherapy (HDS/ ABMT).
Results. With chemotherapy, complete response (CR) rates
were 49% (50/ 105), 51% (142/ 277) and 53% (23/ 44)
with first generation, third generation and high-dose
chemotherapy strategies, respectively; partial response (PR)
rates were 32%, 36% and 35%, respectively. All patients
who achieved CR and 124/ 142 (84%) with PR had radia-
tion therapy on the mediastinum. The final CR rates became
61% for CHOP/ CHOP-like regimens, 79% for MACOP-B and
other regimens, and 75% for HDS/ ABMT. After median fol-
low-ups from attaining CR of 48.5 months for CHOP/ CHOP-
like regimens, 51.7 months for MACOP-B type regimens and
32.4 months for HDS/ ABMT, relapses occurred in 15/ 64
(23%), 27/ 218 (12%) and 0/ 33 (0%) patients, respec-
tively. Projected 10-year progression-free survival rates were
35%, 67% and 78%, respectively ( p=0.0000). Projected
10-year overall survival rates were 44%, 71% and 77%,
respectively ( p=0.0000), after median follow-ups from diag-
nosis of 52.3 months, 54.9 months and 35.8 months,
respectively.
Interpretation and Conclusions. In patients with PMLBCL
with sclerosis, MACOP-B plus radiation therapy may be a
better strategy than other treatments; these retrospective
data need to be confirmed by prospective studies. The
I
n the new Revised European American Lym-
phoma (R.E.A.L.) classifi cation,
1
primary medi-
astinal large B-cell lymphoma (PMLBCL) with
sclerosis is listed as a specific clinical and patho-
logic entity. Histologically, this lymphoma is char-
acterized by a diffuse proliferation of large B-cells
with clear cytoplasm and by the presence of a vari-
able degree of sclerosis, which causes the typical
compartmentalization pattern.
2,3,4
Clinically, there
is a predominant female to male ratio, and patients
are commonly in the 25- to 40-year age group.
PMLBCL with sclerosis presents as a rapidly grow-
ing invasive tumor with contiguous spread within
mediastinal masses. Chest pain, cough, and dyspnea
are common. B symptoms are frequently present,
and 30% to 40% of patients have superior vena
cava obstruction. Pleural and pericardial invasion
with effusion are common. The lesion is frequently
bulky and often involves the thymus. Although
PMLBCL with sclerosis was originally believed to
have a particularly adverse prognosis, the outcome
of patients who receive chemotherapy or combined
modality treatment is now considered equivalent
to that of patients with other large cell lymphomas
of equivalent stage. Treatment with first-generation
Induction chemotherapy stategies
for primary mediastinal large B-cell
lymphoma with sclerosis:
a retrospective multinational study
on 426 previously untreated patients
PIER LUIGI ZINZANI , M AURIZIO M ARTELLI , M ARILENA BERTINI ,
ALESSANDRO M. GIANNI , LILIANA DEVIZZI , M ASSIM O FEDERICO,
GERASSIM OS PANGALIS, J ORG M ICHELS, EM ANUELE ZUCCA,
M ARIA CANTONETTI , SERGIO CORTELAZZO, ANDREW
WOTHERSPOON, ANDRÉS J.M. FERRERI , FRANCESCO ZAJA,
FRANCESCO LAURIA, AM ALIA DE RENZO, M ARINA A. LIBERATI ,
BRUNANGELO FALINI , M ONICA BALZAROTTI , ANTONELLO
CALDERONI , ALFONSO ZACCARIA, PATRIZIA GENTILINI ,
PIER PAOLO FATTORI , ENZO PAVONE,
M ARIA K. ANGELOPOULOU, LAPO ALINARI ,
M AURA BRUGIATELLI , NICOLA DI RENZO, FRANCESCA BONIFAZI ,
STEFANO A. PILERI , FRANCO CAVALLI FOR THE I NTERNATIONAL
EXTRANODAL LYM PHOM A STUDY GROUP (IELSG)
Correspondence: Pier Luigi Zinzani, M.D., Istituto di Ematologia e
Oncologia Medica “Seràgnoli” Policlinico S.Orsola, via Massarenti 9,
40138 Bologna, Italy. Phone: international +39.051.390413.
Fax: international +39.051.398973. E-mail: plzinzo@med.unibo.it
Malignant Lymphomas
research paper
haematologica 2002; 87:1258-1264
http://www.haematologica.org/2002_12/1258.htm
Institute of Hematology and Medical Oncology “Seràgnoli”,
University of Bologna, Italy; Department of Cell Biotechnology,
“La Sapienza” University, Rome, Italy;
Division of Hematology, Molinette Hospital, Turin, Italy;
National Institute of Tumor, Milan, Italy; G.I.S.L., Italy;
Department of Internal Medicine, National and Kapodistrian
University of Athens, Greece; The Wessex Medical Oncology
Unit, Southampton University, United Kingdom; Division of
Oncology, S.Giovanni Hospital, Bellinzona, Switzerland;
Chair of Hematology, University “Tor Vergata”, Rome, Italy;
Division of Hematology, Bergamo Hospital, Italy; The Royal
Marsden Hospital, London, United Kingdom; S.Raffaele
Hospital Scientific Institute, Milan, Italy; Chair of Hematology,
University of Udine, Italy; Chair of Hematology, Siena Universi-
ty, Italy; Chair of Hematology, University of Naples, Italy; Insti-
tute of Internal Medicine, University of Perugia, Italy; Chair of
Hematology, University of Perugia, Italy; Division of Oncology,
Humanitas Institute, Rozzano, Italy; Institute of Medical
Oncology, University of Berne, Switzerland; Division
of Hematology, Ravenna Hospital, Italy; Division of Oncology,
Forlì Hospital, Italy; Division of Oncology, Rimini Hospital, Italy;
Chair of Hematology, University of Bari, Italy
encouraging survival results after high dose chemotherapy
require confirmation in selected high-risk patients.
© 2002, Ferrata Storti Foundation
Key words: PMLBCL, chemotherapy, radiotherapy,
response rate, combined modality treatment.